Genome scans of facial features in East Africans and cross-population comparisons reveal novel associations.


Journal

PLoS genetics
ISSN: 1553-7404
Titre abrégé: PLoS Genet
Pays: United States
ID NLM: 101239074

Informations de publication

Date de publication:
08 2021
Historique:
received: 14 11 2020
accepted: 02 07 2021
entrez: 19 8 2021
pubmed: 20 8 2021
medline: 19 11 2021
Statut: epublish

Résumé

Facial morphology is highly variable, both within and among human populations, and a sizable portion of this variation is attributable to genetics. Previous genome scans have revealed more than 100 genetic loci associated with different aspects of normal-range facial variation. Most of these loci have been detected in Europeans, with few studies focusing on other ancestral groups. Consequently, the degree to which facial traits share a common genetic basis across diverse sets of humans remains largely unknown. We therefore investigated the genetic basis of facial morphology in an East African cohort. We applied an open-ended data-driven phenotyping approach to a sample of 2,595 3D facial images collected on Tanzanian children. This approach segments the face into hierarchically arranged, multivariate features that capture the shape variation after adjusting for age, sex, height, weight, facial size and population stratification. Genome scans of these multivariate shape phenotypes revealed significant (p < 2.5 × 10-8) signals at 20 loci, which were enriched for active chromatin elements in human cranial neural crest cells and embryonic craniofacial tissue, consistent with an early developmental origin of the facial variation. Two of these associations were in highly conserved regions showing craniofacial-specific enhancer activity during embryological development (5q31.1 and 12q21.31). Six of the 20 loci surpassed a stricter threshold accounting for multiple phenotypes with study-wide significance (p < 6.25 × 10-10). Cross-population comparisons indicated 10 association signals were shared with Europeans (seven sharing the same associated SNP), and facilitated fine-mapping of causal variants at previously reported loci. Taken together, these results may point to both shared and population-specific components to the genetic architecture of facial variation.

Identifiants

pubmed: 34411106
doi: 10.1371/journal.pgen.1009695
pii: PGENETICS-D-20-01742
pmc: PMC8375984
doi:

Types de publication

Comparative Study Journal Article Research Support, N.I.H., Extramural Research Support, Non-U.S. Gov't Research Support, U.S. Gov't, Non-P.H.S.

Langues

eng

Sous-ensembles de citation

IM

Pagination

e1009695

Subventions

Organisme : Wellcome Trust
ID : 217065/Z/19/Z
Pays : United Kingdom
Organisme : NIDCR NIH HHS
ID : R01 DE027023
Pays : United States
Organisme : NIDCR NIH HHS
ID : U01 DE020054
Pays : United States
Organisme : NIDCR NIH HHS
ID : R01 DE016148
Pays : United States
Organisme : NHLBI NIH HHS
ID : HHSN268201200008I
Pays : United States
Organisme : Howard Hughes Medical Institute
Pays : United States
Organisme : NIDCR NIH HHS
ID : U01 DE020078
Pays : United States

Déclaration de conflit d'intérêts

The authors have declared that no competing interests exist.

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Auteurs

Chenxing Liu (C)

Department of Human Genetics, University of Pittsburgh, Pittsburgh, Pennsylvania, United States of America.

Myoung Keun Lee (MK)

Department of Oral and Craniofacial Sciences, Center for Craniofacial and Dental Genetics, University of Pittsburgh, Pittsburgh, Pennsylvania, United States of America.

Sahin Naqvi (S)

Department of Chemical and Systems Biology, Stanford University School of Medicine, Stanford, California, United States of America.
Department of Genetics, Stanford University School of Medicine, Stanford, California, United States of America.

Hanne Hoskens (H)

Medical Imaging Research Center, Katholieke Universiteit Leuven, Leuven, Belgium.
Department of Human Genetics, Katholieke Universiteit Leuven, Leuven, Belgium.

Dongjing Liu (D)

Department of Human Genetics, University of Pittsburgh, Pittsburgh, Pennsylvania, United States of America.

Julie D White (JD)

Department of Anthropology, Pennsylvania State University, State College, Pennsylvania, United States of America.

Karlijne Indencleef (K)

Medical Imaging Research Center, Katholieke Universiteit Leuven, Leuven, Belgium.
Processing Speech & Images, Department of Electrical Engineering, Katholieke Universiteit Leuven, Leuven, Belgium.

Harold Matthews (H)

Medical Imaging Research Center, Katholieke Universiteit Leuven, Leuven, Belgium.
Department of Human Genetics, Katholieke Universiteit Leuven, Leuven, Belgium.
Murdoch Children's Research Institute, Melbourne, Victoria, Australia.

Ryan J Eller (RJ)

Department of Biology, Indiana University Purdue University Indianapolis, Indianapolis, Indiana, United States of America.

Jiarui Li (J)

Medical Imaging Research Center, Katholieke Universiteit Leuven, Leuven, Belgium.
Processing Speech & Images, Department of Electrical Engineering, Katholieke Universiteit Leuven, Leuven, Belgium.

Jaaved Mohammed (J)

Department of Chemical and Systems Biology, Stanford University School of Medicine, Stanford, California, United States of America.
Department of Developmental Biology, Stanford University School of Medicine, Stanford, California, United States of America.

Tomek Swigut (T)

Department of Chemical and Systems Biology, Stanford University School of Medicine, Stanford, California, United States of America.
Department of Developmental Biology, Stanford University School of Medicine, Stanford, California, United States of America.

Stephen Richmond (S)

Applied Clinical Research and Public Health, School of Dentistry, Cardiff University, Cardiff, United Kingdom.

Mange Manyama (M)

Anatomy in Radiology, Weill Cornell Medicine-Qatar, Doha, Qatar.

Benedikt Hallgrímsson (B)

Department of Anatomy and Cell Biology, Alberta Children´s Hospital Research Institute, University of Calgary, Calgary, Canada.

Richard A Spritz (RA)

Human Medical Genetics and Genomics Program, University of Colorado School of Medicine, Aurora, Colorado, United States of America.

Eleanor Feingold (E)

Department of Human Genetics, University of Pittsburgh, Pittsburgh, Pennsylvania, United States of America.

Mary L Marazita (ML)

Department of Human Genetics, University of Pittsburgh, Pittsburgh, Pennsylvania, United States of America.
Department of Oral and Craniofacial Sciences, Center for Craniofacial and Dental Genetics, University of Pittsburgh, Pittsburgh, Pennsylvania, United States of America.

Joanna Wysocka (J)

Department of Chemical and Systems Biology, Stanford University School of Medicine, Stanford, California, United States of America.
Department of Developmental Biology, Stanford University School of Medicine, Stanford, California, United States of America.
Howard Hughes Medical Institute, Stanford University School of Medicine, Stanford, California, United States of America.

Susan Walsh (S)

Department of Biology, Indiana University Purdue University Indianapolis, Indianapolis, Indiana, United States of America.

Mark D Shriver (MD)

Department of Anthropology, Pennsylvania State University, State College, Pennsylvania, United States of America.

Peter Claes (P)

Medical Imaging Research Center, Katholieke Universiteit Leuven, Leuven, Belgium.
Department of Human Genetics, Katholieke Universiteit Leuven, Leuven, Belgium.
Processing Speech & Images, Department of Electrical Engineering, Katholieke Universiteit Leuven, Leuven, Belgium.
Murdoch Children's Research Institute, Melbourne, Victoria, Australia.

Seth M Weinberg (SM)

Department of Human Genetics, University of Pittsburgh, Pittsburgh, Pennsylvania, United States of America.
Department of Oral and Craniofacial Sciences, Center for Craniofacial and Dental Genetics, University of Pittsburgh, Pittsburgh, Pennsylvania, United States of America.
Department of Anthropology, University of Pittsburgh, Pittsburgh, Pennsylvania, United States of America.

John R Shaffer (JR)

Department of Human Genetics, University of Pittsburgh, Pittsburgh, Pennsylvania, United States of America.
Department of Oral and Craniofacial Sciences, Center for Craniofacial and Dental Genetics, University of Pittsburgh, Pittsburgh, Pennsylvania, United States of America.

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