EEG Patterns in Patients with Prader-Willi Syndrome.

EEG Prader–Willi syndrome epilepsy genetics sleep wakefulness

Journal

Brain sciences
ISSN: 2076-3425
Titre abrégé: Brain Sci
Pays: Switzerland
ID NLM: 101598646

Informations de publication

Date de publication:
06 Aug 2021
Historique:
received: 28 06 2021
revised: 29 07 2021
accepted: 03 08 2021
entrez: 27 8 2021
pubmed: 28 8 2021
medline: 28 8 2021
Statut: epublish

Résumé

Prader-Willi syndrome (PWS) is a rare disease determined by the loss of the paternal copy of the 15q11-q13 region, and it is characterized by hypotonia, hyperphagia, obesity, short stature, hypogonadism, craniofacial dysmorphisms, and cognitive and behavioral disturbances. The aims of this retrospective study were to analyze interictal EEG findings in a group of PWS patients and to correlate them with genetic, clinical, and neuroimaging data. The demographic, clinical, genetic, EEG, and neuroimaging data of seventy-four patients were collected. Associations among the presence of paroxysmal EEG abnormalities, genotype, and clinical and neuroimaging features were investigated. Four patients (5.4%) presented drug-sensitive epilepsy. Interictal paroxysmal EEG abnormalities-focal or multifocal-were present in 25.7% of the cases, and the normalization of the EEG occurred in about 25% of the cases. In 63.2% of the cases, the paroxysmal abnormalities were bilaterally localized over the middle-posterior regions. Brain magnetic resonance imaging (MRI) was performed on 39 patients (abnormal in 59%). No relevant associations were found between paroxysmal EEG abnormalities and all of the other variables considered. Interictal paroxysmal EEG abnormalities-in particular, with a bilateral middle-posterior localization-could represent an important neurological feature of PWS that is not associated with genotype, cognitive or behavioral endophenotypes, MRI anomalies, or prognosis.

Identifiants

pubmed: 34439664
pii: brainsci11081045
doi: 10.3390/brainsci11081045
pmc: PMC8391179
pii:
doi:

Types de publication

Journal Article

Langues

eng

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Auteurs

Maurizio Elia (M)

Oasi Research Institute-IRCCS, 94018 Troina, Italy.

Irene Rutigliano (I)

Pediatric Unit, Casa Sollievo della Sofferenza, San Giovanni Rotondo, 71013 Foggia, Italy.

Michele Sacco (M)

Pediatric Unit, Casa Sollievo della Sofferenza, San Giovanni Rotondo, 71013 Foggia, Italy.

Simona F Madeo (SF)

Pediatric Unit, Department of Medical and Surgical Sciences of Mother, Children and Adults, University of Modena and Reggio, 41124 Modena, Italy.

Malgorzata Wasniewska (M)

Department of Human Pathology of the Adult and of the Developmental Age "Gaetano Barresi", University of Messina, 98124 Messina, Italy.

Alessandra Li Pomi (A)

Department of Human Pathology of the Adult and of the Developmental Age "Gaetano Barresi", University of Messina, 98124 Messina, Italy.

Giuliana Trifirò (G)

Cardiogenetic and Vascular Center, IRCCS Policlinico San Donato Milanese, 20097 Milan, Italy.

Paolo Di Bella (P)

Division of Child Neurology and Psychiatry, "G. Martino" Hospital, University of Messina, 98124 Messina, Italy.

Silvana De Lucia (S)

I-Motion-Pediatric Clinical Trials Department, Trousseau Hospital, 75012 Paris, France.

Luigi Vetri (L)

Oasi Research Institute-IRCCS, 94018 Troina, Italy.

Lorenzo Iughetti (L)

Pediatric Unit, Department of Medical and Surgical Sciences of Mother, Children and Adults, University of Modena and Reggio, 41124 Modena, Italy.

Maurizio Delvecchio (M)

Metabolic Diseases and Genetics Unit, Giovanni XXIII Children's Hospital, 70126 Bari, Italy.

Classifications MeSH