Survival Analysis in Primary Progressive Apraxia of Speech and Agrammatic Aphasia.


Journal

Neurology. Clinical practice
ISSN: 2163-0402
Titre abrégé: Neurol Clin Pract
Pays: United States
ID NLM: 101577149

Informations de publication

Date de publication:
Jun 2021
Historique:
received: 19 12 2019
accepted: 07 04 2020
entrez: 6 9 2021
pubmed: 7 9 2021
medline: 7 9 2021
Statut: ppublish

Résumé

To compare survival among patients with different combinations of apraxia of speech (AOS) and agrammatic aphasia, including those with isolated AOS (primary progressive AOS, PPAOS), both AOS and agrammatic aphasia (AOS + progressive agrammatic aphasia [PAA]), and isolated agrammatic aphasia (PAA). One hundred nine patients were recruited who had any combination of AOS and agrammatic aphasia (42 PPAOS, 56 AOS + PAA, and 11 PAA) and were followed longitudinally, with 57 patients having since died. Cox proportional hazard models were used to quantify the relative risk of death across diagnoses. Adjusted survival curves are presented based on this model. We also assessed the influence of AOS and aphasia severity on survival. PPAOS had the longest survival (median survival of 5.97 years from the baseline visit), followed by PAA (5.26 years) and then AOS + PAA (4.33 years). AOS + PAA had a greater risk of death than PPAOS, with a hazard ratio of 3.01 (lower/upper confidence interval = 1.66/5.46, Individuals with PPAOS have better survival and reduced risk of death compared with individuals with AOS + PAA. This finding will help improve prognostic estimates for these patients and supports the value of distinguishing PPAOS from AOS + PAA.

Identifiants

pubmed: 34484892
doi: 10.1212/CPJ.0000000000000919
pii: NEURCLINPRACT2019049148
pmc: PMC8382380
doi:

Types de publication

Journal Article

Langues

eng

Pagination

249-255

Subventions

Organisme : NIDCD NIH HHS
ID : R01 DC014942
Pays : United States
Organisme : NIDCD NIH HHS
ID : R01 DC012519
Pays : United States
Organisme : NINDS NIH HHS
ID : R21 NS094684
Pays : United States
Organisme : NINDS NIH HHS
ID : R01 NS089757
Pays : United States
Organisme : NIDCD NIH HHS
ID : R01 DC010367
Pays : United States

Informations de copyright

© 2021 American Academy of Neurology.

Références

Brain Lang. 2010 Apr;113(1):13-20
pubmed: 20074786
J Stat Softw. 2010;33(1):1-22
pubmed: 20808728
Am J Speech Lang Pathol. 2018 Nov 21;27(4):1303-1318
pubmed: 30458509
Ann Neurol. 1987 Oct;22(4):533-4
pubmed: 3324947
J Am Geriatr Soc. 2005 Apr;53(4):695-9
pubmed: 15817019
Brain. 2012 May;135(Pt 5):1522-36
pubmed: 22382356
Mov Disord. 2017 Jun;32(6):853-864
pubmed: 28467028
Mov Disord Clin Pract. 2019 May 29;6(6):452-461
pubmed: 31392246
Brain. 2019 Aug 1;142(8):2466-2482
pubmed: 31199471
Neurology. 2013 Jul 23;81(4):337-45
pubmed: 23803320
J Am Soc Nephrol. 2008 May;19(5):841-3
pubmed: 18322159
Neurology. 2013 Jan 29;80(5):496-503
pubmed: 23359374
Cortex. 2017 May;90:138-148
pubmed: 27771043
Mov Disord. 2008 Nov 15;23(15):2129-70
pubmed: 19025984
Neurology. 2011 Mar 15;76(11):1006-14
pubmed: 21325651
Aphasiology. 2014 Aug;28(8-9):1004-1017
pubmed: 25309017
Brain. 2006 Jun;129(Pt 6):1385-98
pubmed: 16613895
J Commun Disord. 2014 Sep-Oct;51:43-50
pubmed: 25092638
JAMA Neurol. 2016 Jun 1;73(6):733-42
pubmed: 27111692
Neurocase. 2005 Aug;11(4):283-96
pubmed: 16093229
Brain. 2014 Oct;137(Pt 10):2783-95
pubmed: 25113789
Am J Alzheimers Dis Other Demen. 2009 Oct-Nov;24(5):408-16
pubmed: 19700669
Brain. 2018 Jan 1;141(1):302-317
pubmed: 29228180
Neurocase. 2018 Apr;24(2):111-120
pubmed: 29799310
Brain Lang. 2018 Sep;184:54-65
pubmed: 29980072
J Speech Hear Res. 1969 Jun;12(2):246-69
pubmed: 5808852
Psychiatry Clin Neurosci. 2002 Feb;56(1):111-5
pubmed: 11929580

Auteurs

Jennifer L Whitwell (JL)

Department of Radiology (JLW), Department of Health Sciences Research (PM), Division of Speech Pathology (JRD, HMC, RLU, EAS), and Division of Behavioral Neurology (HB, KAJ), Department of Neurology, and Department of Psychiatry and Psychology (MMM), Mayo Clinic, Rochester, MN.

Peter Martin (P)

Department of Radiology (JLW), Department of Health Sciences Research (PM), Division of Speech Pathology (JRD, HMC, RLU, EAS), and Division of Behavioral Neurology (HB, KAJ), Department of Neurology, and Department of Psychiatry and Psychology (MMM), Mayo Clinic, Rochester, MN.

Joseph R Duffy (JR)

Department of Radiology (JLW), Department of Health Sciences Research (PM), Division of Speech Pathology (JRD, HMC, RLU, EAS), and Division of Behavioral Neurology (HB, KAJ), Department of Neurology, and Department of Psychiatry and Psychology (MMM), Mayo Clinic, Rochester, MN.

Heather M Clark (HM)

Department of Radiology (JLW), Department of Health Sciences Research (PM), Division of Speech Pathology (JRD, HMC, RLU, EAS), and Division of Behavioral Neurology (HB, KAJ), Department of Neurology, and Department of Psychiatry and Psychology (MMM), Mayo Clinic, Rochester, MN.

Rene L Utianski (RL)

Department of Radiology (JLW), Department of Health Sciences Research (PM), Division of Speech Pathology (JRD, HMC, RLU, EAS), and Division of Behavioral Neurology (HB, KAJ), Department of Neurology, and Department of Psychiatry and Psychology (MMM), Mayo Clinic, Rochester, MN.

Hugo Botha (H)

Department of Radiology (JLW), Department of Health Sciences Research (PM), Division of Speech Pathology (JRD, HMC, RLU, EAS), and Division of Behavioral Neurology (HB, KAJ), Department of Neurology, and Department of Psychiatry and Psychology (MMM), Mayo Clinic, Rochester, MN.

Mary M Machulda (MM)

Department of Radiology (JLW), Department of Health Sciences Research (PM), Division of Speech Pathology (JRD, HMC, RLU, EAS), and Division of Behavioral Neurology (HB, KAJ), Department of Neurology, and Department of Psychiatry and Psychology (MMM), Mayo Clinic, Rochester, MN.

Edythe A Strand (EA)

Department of Radiology (JLW), Department of Health Sciences Research (PM), Division of Speech Pathology (JRD, HMC, RLU, EAS), and Division of Behavioral Neurology (HB, KAJ), Department of Neurology, and Department of Psychiatry and Psychology (MMM), Mayo Clinic, Rochester, MN.

Keith A Josephs (KA)

Department of Radiology (JLW), Department of Health Sciences Research (PM), Division of Speech Pathology (JRD, HMC, RLU, EAS), and Division of Behavioral Neurology (HB, KAJ), Department of Neurology, and Department of Psychiatry and Psychology (MMM), Mayo Clinic, Rochester, MN.

Classifications MeSH