De Novo Inverted Duplication Deletion of 4p in a 14-Week-Old Male Fetus Aborted Due to Multiple Anomalies.

4p agenesis gastroschisis inv dup del lung hypoplasia

Journal

Journal of pediatric genetics
ISSN: 2146-4596
Titre abrégé: J Pediatr Genet
Pays: Germany
ID NLM: 101589859

Informations de publication

Date de publication:
Sep 2021
Historique:
received: 14 02 2020
accepted: 07 05 2020
entrez: 10 9 2021
pubmed: 11 9 2021
medline: 11 9 2021
Statut: ppublish

Résumé

Inverted duplications deletions are rare, complex, and nonrecurrent chromosomal rearrangements associated with a variable phenotype. In this case report, we described the phenotype and genotype of a 14-week-old male fetus, who was aborted after discovery of multiple anomalies (septal cystic hygroma, open abdominal wall, and a nonidentifiable lower limb). At autopsy, fluorescence in situ hybridization and array comparative genomic hybridization identified an inverted duplication with terminal deletion of 4p [46,XY,der(4)del(p16.3)dup(4)(p15.2p16.3)]. Only five genotypically similar cases have been reported, and we hope our case contribution will add meaningful to the body of knowledge.

Identifiants

pubmed: 34504730
doi: 10.1055/s-0040-1713156
pii: 2000022
pmc: PMC8416190
doi:

Types de publication

Case Reports

Langues

eng

Pagination

245-249

Informations de copyright

Thieme. All rights reserved.

Déclaration de conflit d'intérêts

Conflict of Interest None declared.

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Auteurs

Paolo Fontana (P)

Department of Medical Genetics, AORN San Pio, PO Gaetano Rummo, Benevento, Italy.

Laura Bernardini (L)

Division of Medical Genetics, IRCCS Casa Sollievo della Sofferenza Foundation, San Giovanni Rotondo, Foggia, Italy.

Cinzia Lombardi (C)

Department of Medical Genetics, AORN San Pio, PO Gaetano Rummo, Benevento, Italy.

Maria Grazia Giuffrida (MG)

Division of Medical Genetics, IRCCS Casa Sollievo della Sofferenza Foundation, San Giovanni Rotondo, Foggia, Italy.

Maria Ciavarella (M)

Department of Medical Genetics, AORN San Pio, PO Gaetano Rummo, Benevento, Italy.

Anna Capalbo (A)

Division of Medical Genetics, IRCCS Casa Sollievo della Sofferenza Foundation, San Giovanni Rotondo, Foggia, Italy.

Marianna Maioli (M)

Department of Medical Genetics, AORN San Pio, PO Gaetano Rummo, Benevento, Italy.

Francesca Scarano (F)

Department of Medical Genetics, AORN San Pio, PO Gaetano Rummo, Benevento, Italy.

Giuseppina Cantalupo (G)

Department of Medical Genetics, AORN San Pio, PO Gaetano Rummo, Benevento, Italy.

Mariateresa Falco (M)

Department of Medical Genetics, AORN San Pio, PO Gaetano Rummo, Benevento, Italy.

Gioacchino Scarano (G)

Department of Medical Genetics, AORN San Pio, PO Gaetano Rummo, Benevento, Italy.

Fortunato Lonardo (F)

Department of Medical Genetics, AORN San Pio, PO Gaetano Rummo, Benevento, Italy.

Classifications MeSH