An Atypical Case of Head Tremor and Extensive White Matter in an Adult Female Caused by 3-Hydroxy-3-methylglutaryl-CoA Lyase Deficiency.

HMG-CoA lyase deficiency HMGCL HMGLD NGS inherited metabolic diseases

Journal

Diagnostics (Basel, Switzerland)
ISSN: 2075-4418
Titre abrégé: Diagnostics (Basel)
Pays: Switzerland
ID NLM: 101658402

Informations de publication

Date de publication:
28 Aug 2021
Historique:
received: 25 05 2021
revised: 31 07 2021
accepted: 24 08 2021
entrez: 28 9 2021
pubmed: 29 9 2021
medline: 29 9 2021
Statut: epublish

Résumé

3-Hydroxy-3-methylglutaryl-CoA (HMG-CoA) Lyase deficiency (HMGLD) (OMIM 246450) is an autosomal recessive genetic disorder caused by homozygous or compound heterozygous variants in the

Identifiants

pubmed: 34573903
pii: diagnostics11091561
doi: 10.3390/diagnostics11091561
pmc: PMC8469356
pii:
doi:

Types de publication

Case Reports

Langues

eng

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Auteurs

Nassim Boutouchent (N)

Normandie University, UNIROUEN, INSERM U1245, CHU Rouen, Department of Metabolic Biochemistry, 76000 Rouen, France.

Julie Bourilhon (J)

Rouen University Hospital, CHU de Rouen, Department of Neurology, 76000 Rouen, France.
Department of Neurophysiology, Rouen University Hospital, 76000 Rouen, France.

Bénédicte Sudrié-Arnaud (B)

Normandie University, UNIROUEN, INSERM U1245, CHU Rouen, Department of Metabolic Biochemistry, 76000 Rouen, France.

Antoine Bonnevalle (A)

Rouen University Hospital, CHU de Rouen, Department of Neurology, 76000 Rouen, France.

Lucie Guyant-Maréchal (L)

Department of Neurophysiology, Rouen University Hospital, 76000 Rouen, France.

Cécile Acquaviva (C)

Department of Biochemistry and Molecular Biology, Inborn Errors of Metabolism, Center of Biology and Pathology Est, CHU Lyon, 69310 Bron, France.

Loréna Dujardin-Ippolito (L)

Normandie University, UNIROUEN, INSERM U1245, CHU Rouen, Department of Metabolic Biochemistry, 76000 Rouen, France.

Soumeya Bekri (S)

Normandie University, UNIROUEN, INSERM U1245, CHU Rouen, Department of Metabolic Biochemistry, 76000 Rouen, France.

Ivana Dabaj (I)

Normandie University, UNIROUEN, INSERM U1245, CHU Rouen, Department of Neonatal Pediatrics, Intensive Care and Neuropediatrics, 76000 Rouen, France.

Abdellah Tebani (A)

Normandie University, UNIROUEN, INSERM U1245, CHU Rouen, Department of Metabolic Biochemistry, 76000 Rouen, France.

Classifications MeSH