Plasma Neurofilament Light (NfL) in Patients Affected by Niemann-Pick Type C Disease (NPCD).

Niemann–Pick C biomarkers neurofilament light neurological disease

Journal

Journal of clinical medicine
ISSN: 2077-0383
Titre abrégé: J Clin Med
Pays: Switzerland
ID NLM: 101606588

Informations de publication

Date de publication:
19 Oct 2021
Historique:
received: 27 09 2021
revised: 15 10 2021
accepted: 15 10 2021
entrez: 23 10 2021
pubmed: 24 10 2021
medline: 24 10 2021
Statut: epublish

Résumé

(1) Background: Niemann-Pick type C disease (NPCD) is an autosomal recessive lysosomal storage disorder caused by mutations in the NPC1 or NPC2 genes. The clinical presentation is characterized by visceral and neurological involvement. Apart from a small group of patients presenting a severe perinatal form, all patients develop progressive and fatal neurological disease with an extremely variable age of onset. Different biomarkers have been identified; however, they poorly correlate with neurological disease. In this study we assessed the possible role of plasma NfL as a neurological disease-associated biomarker in NPCD. (2) Methods: Plasma NfL levels were measured in 75 healthy controls and 26 patients affected by NPCD (24 NPC1 and 2 NPC2; 39 samples). (3) Results: Plasma NfL levels in healthy controls correlated with age and were significantly lower in pediatric patients as compared to adult subjects (

Identifiants

pubmed: 34682919
pii: jcm10204796
doi: 10.3390/jcm10204796
pmc: PMC8537496
pii:
doi:

Types de publication

Journal Article

Langues

eng

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Auteurs

Andrea Dardis (A)

Regional Coordinator Centre for Rare Diseases, University Hospital of Udine, 33100 Udine, Italy.

Eleonora Pavan (E)

Regional Coordinator Centre for Rare Diseases, University Hospital of Udine, 33100 Udine, Italy.

Martina Fabris (M)

Institute of Clinical Pathology, Department of Laboratory Medicine, University Hospital of Udine, 33100 Udine, Italy.

Rosalia Maria Da Riol (RM)

Regional Coordinator Centre for Rare Diseases, University Hospital of Udine, 33100 Udine, Italy.

Annalisa Sechi (A)

Regional Coordinator Centre for Rare Diseases, University Hospital of Udine, 33100 Udine, Italy.

Agata Fiumara (A)

Regional Referral Center for Inherited Metabolic Disease, Department of Pediatrics, University of Catania, 95131 Catania, Italy.

Lucia Santoro (L)

Division of Pediatrics, Department of Clinical Sciences, Polytechnic University of Marche, Ospedali Riuniti, 60123 Ancona, Italy.

Maximiliano Ormazabal (M)

Regional Coordinator Centre for Rare Diseases, University Hospital of Udine, 33100 Udine, Italy.

Romina Milanic (R)

Institute of Clinical Pathology, Department of Laboratory Medicine, University Hospital of Udine, 33100 Udine, Italy.

Stefania Zampieri (S)

Regional Coordinator Centre for Rare Diseases, University Hospital of Udine, 33100 Udine, Italy.

Jessica Biasizzo (J)

Institute of Clinical Pathology, Department of Laboratory Medicine, University Hospital of Udine, 33100 Udine, Italy.

Maurizio Scarpa (M)

Regional Coordinator Centre for Rare Diseases, University Hospital of Udine, 33100 Udine, Italy.

Classifications MeSH