Clinical Quiz-A Rare Case of Anal Canal Duplication in the Context of Currarino Syndrome.

anal canal anorectal malformation congenital abnormalities currarino syndrome sacral defect

Journal

European journal of pediatric surgery reports
ISSN: 2194-7619
Titre abrégé: European J Pediatr Surg Rep
Pays: Germany
ID NLM: 101620104

Informations de publication

Date de publication:
Jan 2021
Historique:
received: 19 04 2021
accepted: 05 07 2021
entrez: 15 11 2021
pubmed: 16 11 2021
medline: 16 11 2021
Statut: epublish

Résumé

Currarino syndrome (CS) is a rare condition that presents with any combination of a sacral defect, a presacral mass, and an anorectal malformation. This collection, referred to as Currarino's triad, may not necessarily present as all three abnormalities in the diagnosis of the syndrome. Anal canal duplication (ACD) is an even rarer occurrence. We present a case that lies on the CS spectrum with an associated ACD and discuss a complex surgical challenge that necessitated a customized management plan, devised through a multidisciplinary approach.

Identifiants

pubmed: 34777941
doi: 10.1055/s-0041-1735595
pii: 210591
pmc: PMC8580735
doi:

Types de publication

Case Reports

Langues

eng

Pagination

e68-e71

Informations de copyright

The Author(s). This is an open access article published by Thieme under the terms of the Creative Commons Attribution License, permitting unrestricted use, distribution, and reproduction so long as the original work is properly cited. ( https://creativecommons.org/licenses/by/4.0/ ).

Déclaration de conflit d'intérêts

Conflict of Interest None declared.

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Auteurs

Sean Jared Connor (SJ)

Department of Paediatric Surgery, Chris Hani Baragwanath Hospital, Johannesburg, Gauteng, South Africa.
University of the Witwatersrand School of Clinical Medicine, Johannesburg, Gauteng, South Africa.

Giulia Brisighelli (G)

Department of Paediatric Surgery, Chris Hani Baragwanath Hospital, Johannesburg, Gauteng, South Africa.

Nirav Patel (N)

Department of Paediatric Surgery, University of the Witwatersrand, Johannesburg, Gauteng, South Africa.

Marc A Levitt (MA)

Department of Surgery, Colorectal and Pelvic Reconstructive Surgery, Children's National Hospital, Washington, District of Columbia, United States.

Classifications MeSH