Oral health-related quality of life in children with osteogenesis imperfecta.
Community paediatric dentistry
Disturbances in dental development
Medically compromised/disability
Journal
European archives of paediatric dentistry : official journal of the European Academy of Paediatric Dentistry
ISSN: 1996-9805
Titre abrégé: Eur Arch Paediatr Dent
Pays: England
ID NLM: 101277157
Informations de publication
Date de publication:
Apr 2022
Apr 2022
Historique:
received:
14
05
2021
accepted:
27
08
2021
pubmed:
21
11
2021
medline:
13
4
2022
entrez:
20
11
2021
Statut:
ppublish
Résumé
Osteogenesis imperfecta (OI) results from mutations in the genes involved in the modification or biosynthesis of collagen. This study aimed to assess the oral health-related quality of life (OHRQoL) in children with OI. Participants were recruited from a highly specialised OI centre for children. The Child Oral-Health Impact Profile-Short Form (COHIP-SF) was used, adding demographic and qualitative questions. Children aged 8-16 years participated between January and October 2019. Statistical analysis was carried out. A higher COHIP-SF score indicates better OHRQoL (maximum score, 76). One hundred and six (106) children participated (44 female, mean age 11.93 years). COHIP-SF median score was 59. Children reporting mild OI (n = 55) had higher median scores (62) compared to severe OI (n = 7) with median scores of 55 (P = 0.087). When comparing mixed (< 12 years, n = 46) and permanent dentition (≥ 12, n = 60), no significant difference in OHRQoL was seen (P = 0.977). There was no significant difference between severities for each COHIP-SF domain. Limited data on the presence of dentinogenesis imperfecta did not impact overall score (P = 0.109), but was significant in the oral-health domain (P = 0.033). Common themes were the need for braces, discolouration, pain and function. This study confirmed that children with OI have dental concerns in areas including oral health, functional well-being and socio-emotional well-being. This was related to severity of OI.
Identifiants
pubmed: 34799841
doi: 10.1007/s40368-021-00664-9
pii: 10.1007/s40368-021-00664-9
pmc: PMC8994709
doi:
Types de publication
Journal Article
Langues
eng
Sous-ensembles de citation
IM
Pagination
261-270Informations de copyright
© 2021. Crown.
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