Validity and Prognostic Value of a Polygenic Risk Score for Parkinson's Disease.


Journal

Genes
ISSN: 2073-4425
Titre abrégé: Genes (Basel)
Pays: Switzerland
ID NLM: 101551097

Informations de publication

Date de publication:
23 11 2021
Historique:
received: 31 10 2021
accepted: 21 11 2021
entrez: 24 12 2021
pubmed: 25 12 2021
medline: 22 2 2022
Statut: epublish

Résumé

Idiopathic Parkinson's disease (PD) is a complex multifactorial disorder caused by the interplay of both genetic and non-genetic risk factors. Polygenic risk scores (PRSs) are one way to aggregate the effects of a large number of genetic variants upon the risk for a disease like PD in a single quantity. However, reassessment of the performance of a given PRS in independent data sets is a precondition for establishing the PRS as a valid tool to this end. We studied a previously proposed PRS for PD in a separate genetic data set, comprising 1914 PD cases and 4464 controls, and were able to replicate its ability to differentiate between cases and controls. We also assessed theoretically the prognostic value of the PD-PRS, i.e., its ability to predict the development of PD in later life for healthy individuals. As it turned out, the PD-PRS alone can be expected to perform poorly in this regard. Therefore, we conclude that the PD-PRS could serve as an important research tool, but that meaningful PRS-based prognosis of PD at an individual level is not feasible.

Identifiants

pubmed: 34946808
pii: genes12121859
doi: 10.3390/genes12121859
pmc: PMC8700849
pii:
doi:

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

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Auteurs

Sebastian Koch (S)

Institute of Medical Informatics and Statistics, Kiel University, University Medical Center Schleswig-Holstein, Campus Kiel, 24105 Kiel, Germany.

Björn-Hergen Laabs (BH)

Institute of Medical Biometry and Statistics, University of Luebeck, University Medical Center Schleswig-Holstein, Campus Luebeck, 23562 Luebeck, Germany.

Meike Kasten (M)

Department of Psychiatry, University of Luebeck, 23538 Luebeck, Germany.
Institute of Neurogenetics, University of Luebeck, University Medical Center Schleswig-Holstein, Campus Luebeck, 23538 Luebeck, Germany.

Eva-Juliane Vollstedt (EJ)

Institute of Neurogenetics, University of Luebeck, University Medical Center Schleswig-Holstein, Campus Luebeck, 23538 Luebeck, Germany.

Jos Becktepe (J)

Department of Neurology, Kiel University, 24105 Kiel, Germany.

Norbert Brüggemann (N)

Institute of Neurogenetics, University of Luebeck, University Medical Center Schleswig-Holstein, Campus Luebeck, 23538 Luebeck, Germany.
Department of Neurology, University of Luebeck, 23562 Luebeck, Germany.

Andre Franke (A)

Institute of Clinical Molecular Biology, Kiel University, 24105 Kiel, Germany.

Ulrike M Krämer (UM)

Department of Neurology, University of Luebeck, 23562 Luebeck, Germany.

Gregor Kuhlenbäumer (G)

Department of Neurology, Kiel University, 24105 Kiel, Germany.

Wolfgang Lieb (W)

Institute of Epidemiology and PopGen Biobank, Kiel University, University Medical Center Schleswig-Holstein, Campus Kiel, 24105 Kiel, Germany.

Brit Mollenhauer (B)

Department of Neurology, University Medical Center Goettingen, 37075 Goettingen, Germany.
Paracelsus-Elena-Klinik, 34128 Kassel, Germany.

Miriam Neis (M)

Department of Neurology, University of Luebeck, 23562 Luebeck, Germany.
Department of Midwifery Science, University of Luebeck, 23562 Luebeck, Germany.

Claudia Trenkwalder (C)

Paracelsus-Elena-Klinik, 34128 Kassel, Germany.
Department of Neurosurgery, University Medical Center Goettingen, 37075 Goettingen, Germany.

Eva Schäffer (E)

Department of Neurology, Kiel University, 24105 Kiel, Germany.

Tatiana Usnich (T)

Institute of Neurogenetics, University of Luebeck, University Medical Center Schleswig-Holstein, Campus Luebeck, 23538 Luebeck, Germany.

Michael Wittig (M)

Institute of Clinical Molecular Biology, Kiel University, 24105 Kiel, Germany.

Christine Klein (C)

Institute of Neurogenetics, University of Luebeck, University Medical Center Schleswig-Holstein, Campus Luebeck, 23538 Luebeck, Germany.

Inke R König (IR)

Institute of Medical Biometry and Statistics, University of Luebeck, University Medical Center Schleswig-Holstein, Campus Luebeck, 23562 Luebeck, Germany.

Katja Lohmann (K)

Institute of Neurogenetics, University of Luebeck, University Medical Center Schleswig-Holstein, Campus Luebeck, 23538 Luebeck, Germany.

Michael Krawczak (M)

Institute of Medical Informatics and Statistics, Kiel University, University Medical Center Schleswig-Holstein, Campus Kiel, 24105 Kiel, Germany.

Amke Caliebe (A)

Institute of Medical Informatics and Statistics, Kiel University, University Medical Center Schleswig-Holstein, Campus Kiel, 24105 Kiel, Germany.

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