Case report: Congenital extrahepatic portocaval shunt presenting as pulmonary arterial hypertension in a pregnant patient.

Abernethy syndrome portopulmonary hypertension pregnancy

Journal

Pulmonary circulation
ISSN: 2045-8932
Titre abrégé: Pulm Circ
Pays: United States
ID NLM: 101557243

Informations de publication

Date de publication:
Jan 2022
Historique:
received: 01 10 2021
revised: 20 11 2021
accepted: 22 11 2021
entrez: 4 5 2022
pubmed: 5 5 2022
medline: 5 5 2022
Statut: epublish

Résumé

Congenital extrahepatic portocaval shunt (CEPS) is a rare condition in which a rare congenital vascular anomaly of the portal system is present. CEPS may manifest as pulmonary arterial hypertension (PAH). When diagnosed and treated early, PAH can be reversible. We report a case of a previously asymptomatic woman, who manifested with severe pulmonary hypertension during pregnancy and was consequently diagnosed with CEPS. After unsuccessful medical treatment, urgent lung transplantation was done.

Identifiants

pubmed: 35506097
doi: 10.1002/pul2.12008
pii: PUL212008
pmc: PMC9052963
doi:

Types de publication

Case Reports

Langues

eng

Pagination

e12008

Informations de copyright

© 2021 The Authors. Pulmonary Circulation published by John Wiley & Sons Ltd on behalf of Pulmonary Vascular Research Institute.

Déclaration de conflit d'intérêts

The authors declare that there are no conflict of interests.

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Auteurs

Matevž Harlander (M)

Department of Pulmonary Diseases and Allergy University Medical Centre Ljubljana Ljubljana Slovenia.
Faculty of Medicine Ljubljana University of Ljubljana Ljubljana Slovenia.

Maja Badovinac (M)

Department of Pulmonary Diseases and Allergy University Medical Centre Ljubljana Ljubljana Slovenia.

Frosina Markoska (F)

Department of Pulmonary Diseases and Allergy University Medical Centre Ljubljana Ljubljana Slovenia.

Barbara Salobir (B)

Department of Pulmonary Diseases and Allergy University Medical Centre Ljubljana Ljubljana Slovenia.
Faculty of Medicine Ljubljana University of Ljubljana Ljubljana Slovenia.

Tomaž Štupnik (T)

Faculty of Medicine Ljubljana University of Ljubljana Ljubljana Slovenia.
Department of Thoracic Surgery University Medical Centre Ljubljana Ljubljana Slovenia.

Marija Iča Dolenšek (MI)

Institute of Radiology University Medical Centre Ljubljana Ljubljana Slovenia.

Izidor Kern (I)

Cytology and Pathology Laboratory University Clinic of Respiratory and Allergic Diseases Golnik Golnik Slovenia.

Vojka Gorjup (V)

Department of Intensive Internal Medicine University Medical Centre Ljubljana Ljubljana Slovenia.

Nazzareno Galiè (N)

DIMES S. Orsola University Hospital University of Bologna and IRCCS Bologna Italy.

Classifications MeSH