Induced neural progenitor cells and iPS-neurons from major depressive disorder patients show altered bioenergetics and electrophysiological properties.


Journal

Molecular psychiatry
ISSN: 1476-5578
Titre abrégé: Mol Psychiatry
Pays: England
ID NLM: 9607835

Informations de publication

Date de publication:
22 Jun 2022
Historique:
received: 20 05 2021
accepted: 07 06 2022
revised: 30 05 2022
entrez: 22 6 2022
pubmed: 23 6 2022
medline: 23 6 2022
Statut: aheadofprint

Résumé

The molecular pathomechanisms of major depressive disorder (MDD) are still not completely understood. Here, we follow the hypothesis, that mitochondria dysfunction which is inevitably associated with bioenergetic disbalance is a risk factor that contributes to the susceptibility of an individual to develop MDD. Thus, we investigated molecular mechanisms related to mitochondrial function in induced neuronal progenitor cells (NPCs) which were reprogrammed from fibroblasts of eight MDD patients and eight non-depressed controls. We found significantly lower maximal respiration rates, altered cytosolic basal calcium levels, and smaller soma size in NPCs derived from MDD patients. These findings are partially consistent with our earlier observations in MDD patient-derived fibroblasts. Furthermore, we differentiated MDD and control NPCs into iPS-neurons and analyzed their passive biophysical and active electrophysiological properties to investigate whether neuronal function can be related to altered mitochondrial activity and bioenergetics. Interestingly, MDD patient-derived iPS-neurons showed significantly lower membrane capacitance, a less hyperpolarized membrane potential, increased Na

Identifiants

pubmed: 35732695
doi: 10.1038/s41380-022-01660-1
pii: 10.1038/s41380-022-01660-1
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Deutsche Forschungsgemeinschaft (German Research Foundation)
ID : 422182557
Organisme : Deutsche Forschungsgemeinschaft (German Research Foundation)
ID : GRK2174
Organisme : Deutsche Forschungsgemeinschaft (German Research Foundation)
ID : GRK2174
Organisme : Deutsche Forschungsgemeinschaft (German Research Foundation)
ID : GRK2174
Organisme : Deutsche Forschungsgemeinschaft (German Research Foundation)
ID : GRK2174
Organisme : Deutsche Forschungsgemeinschaft (German Research Foundation)
ID : GRK2174
Organisme : Deutsche Forschungsgemeinschaft (German Research Foundation)
ID : 422182557
Organisme : Bayerische Forschungsstiftung (Bavarian Research Foundation)
ID : ForIPS
Organisme : Bayerische Forschungsstiftung (Bavarian Research Foundation)
ID : ForInter
Organisme : Bayerische Forschungsstiftung (Bavarian Research Foundation)
ID : ForIPS
Organisme : Bayerische Forschungsstiftung (Bavarian Research Foundation)
ID : ForInter
Organisme : Bundesministerium für Bildung und Forschung (Federal Ministry of Education and Research)
ID : 01EE1401B
Organisme : Bundesministerium für Bildung und Forschung (Federal Ministry of Education and Research)
ID : 01EE1401B

Informations de copyright

© 2022. The Author(s).

Références

Klengel T, Binder EB. Gene-environment interactions in major depressive disorder. Can J Psychiatry. 2013;58:76–83.
pubmed: 23442893 doi: 10.1177/070674371305800203
Hasler G. Pathophysiology of depression: do we have any solid evidence of interest to clinicians? World Psychiatry. 2010;9:155–61.
pubmed: 20975857 pmcid: 2950973 doi: 10.1002/j.2051-5545.2010.tb00298.x
Manji H, Kato T, Di Prospero NA, Ness S, Beal MF, Krams M, et al. Impaired mitochondrial function in psychiatric disorders. Nat Rev Neurosci. 2012;13:293–307.
pubmed: 22510887 doi: 10.1038/nrn3229
Gardner A, Boles RG. Beyond the serotonin hypothesis: mitochondria, inflammation and neurodegeneration in major depression and affective spectrum disorders. Prog Neuropsychopharmacol Biol Psychiatry. 2011;35:730–43.
pubmed: 20691744 doi: 10.1016/j.pnpbp.2010.07.030
Klinedinst NJ, Regenold WT. A mitochondrial bioenergetic basis of depression. J Bioenerg Biomembr. 2015;47:155–71.
pubmed: 25262287 doi: 10.1007/s10863-014-9584-6
Kuffner K, Triebelhorn J, Meindl K, Benner C, Manook A, Sudria-Lopez D, et al. Major Depressive Disorder is Associated with Impaired Mitochondrial Function in Skin Fibroblasts. Cells. 2020;9:884.
pmcid: 7226727 doi: 10.3390/cells9040884
Karabatsiakis A, Bock C, Salinas-Manrique J, Kolassa S, Calzia E, Dietrich DE, et al. Mitochondrial respiration in peripheral blood mononuclear cells correlates with depressive subsymptoms and severity of major depression. Transl Psychiatry. 2014;4:e397.
pubmed: 26126180 pmcid: 4080325 doi: 10.1038/tp.2014.44
Hroudova J, Fisar Z, Kitzlerova E, Zverova M, Raboch J. Mitochondrial respiration in blood platelets of depressive patients. Mitochondrion. 2013;13:795–800.
pubmed: 23688905 doi: 10.1016/j.mito.2013.05.005
Gardner A, Johansson A, Wibom R, Nennesmo I, von Dobeln U, Hagenfeldt L, et al. Alterations of mitochondrial function and correlations with personality traits in selected major depressive disorder patients. J Affect Disord. 2003;76:55–68.
pubmed: 12943934 doi: 10.1016/S0165-0327(02)00067-8
Garbett KA, Vereczkei A, Kalman S, Wang L, Korade Z, Shelton RC, et al. Fibroblasts from patients with major depressive disorder show distinct transcriptional response to metabolic stressors. Transl Psychiatry. 2015;5:e523.
pubmed: 25756806 pmcid: 4354345 doi: 10.1038/tp.2015.14
Anglin RE, Garside SL, Tarnopolsky MA, Mazurek MF, Rosebush PI. The psychiatric manifestations of mitochondrial disorders: a case and review of the literature. J Clin Psychiatry. 2012;73:506–12.
pubmed: 22579150 doi: 10.4088/JCP.11r07237
Allen J, Romay-Tallon R, Brymer KJ, Caruncho HJ, Kalynchuk LE. Mitochondria and Mood: Mitochondrial Dysfunction as a Key Player in the Manifestation of Depression. Front Neurosci. 2018;12:386.
pubmed: 29928190 pmcid: 5997778 doi: 10.3389/fnins.2018.00386
Picard M, McEwen BS. Mitochondria impact brain function and cognition. Proc Natl Acad Sci USA. 2014;111:7–8.
pubmed: 24367081 doi: 10.1073/pnas.1321881111
Verhoeven JE, Revesz D, Wolkowitz OM, Penninx BW. Cellular aging in depression: Permanent imprint or reversible process?: An overview of the current evidence, mechanistic pathways, and targets for interventions. Bioessays. 2014;36:968–78.
pubmed: 25143317 doi: 10.1002/bies.201400068
Sjovall F, Ehinger JK, Marelsson SE, Morota S, Frostner EA, Uchino H, et al. Mitochondrial respiration in human viable platelets-methodology and influence of gender, age and storage. Mitochondrion. 2013;13:7–14.
pubmed: 23164798 doi: 10.1016/j.mito.2012.11.001
Vadodaria KC, Ji Y, Skime M, Paquola AC, Nelson T, Hall-Flavin D, et al. Altered serotonergic circuitry in SSRI-resistant major depressive disorder patient-derived neurons. Mol Psychiatry. 2019;24:808–18.
pubmed: 30903001 pmcid: 7409972 doi: 10.1038/s41380-019-0377-5
Soliman MA, Aboharb F, Zeltner N, Studer L. Pluripotent stem cells in neuropsychiatric disorders. Mol Psychiatry. 2017;22:1241–9.
pubmed: 28322279 pmcid: 5582162 doi: 10.1038/mp.2017.40
Vadodaria KC, Mertens J, Paquola A, Bardy C, Li X, Jappelli R, et al. Generation of functional human serotonergic neurons from fibroblasts. Mol Psychiatry. 2016;21:49–61.
pubmed: 26503761 doi: 10.1038/mp.2015.161
Lu J, Zhong X, Liu H, Hao L, Huang CT, Sherafat MA, et al. Generation of serotonin neurons from human pluripotent stem cells. Nat Biotechnol. 2016;34:89–94.
pubmed: 26655496 doi: 10.1038/nbt.3435
Takahashi K, Tanabe K, Ohnuki M, Narita M, Ichisaka T, Tomoda K, et al. Induction of pluripotent stem cells from adult human fibroblasts by defined factors. Cell. 2007;131:861–72.
pubmed: 18035408 doi: 10.1016/j.cell.2007.11.019
Okita K, Matsumura Y, Sato Y, Okada A, Morizane A, Okamoto S, et al. A more efficient method to generate integration-free human iPS cells. Nat Methods. 2011;8:409–12.
pubmed: 21460823 doi: 10.1038/nmeth.1591
Inoue H, Nagata N, Kurokawa H, Yamanaka S. iPS cells: a game changer for future medicine. EMBO J. 2014;33:409–17.
pubmed: 24500035 pmcid: 3989624 doi: 10.1002/embj.201387098
Takahashi K, Yamanaka S. Induced pluripotent stem cells in medicine and biology. Development. 2013;140:2457–61.
pubmed: 23715538 doi: 10.1242/dev.092551
Heard KJ, Shokhirev MN, Becronis C, Fredlender C, Zahid N, Le AT, et al. Chronic cortisol differentially impacts stem cell-derived astrocytes from major depressive disorder patients. Transl Psychiatry. 2021;11:608.
pubmed: 34848679 pmcid: 8632962 doi: 10.1038/s41398-021-01733-9
Consortium HDi. Bioenergetic deficits in Huntington’s disease iPSC-derived neural cells and rescue with glycolytic metabolites. Hum Mol Genet. 2020;29:1757–71.
doi: 10.1093/hmg/ddy430
Lorenz C, Lesimple P, Bukowiecki R, Zink A, Inak G, Mlody B, et al. Human iPSC-Derived Neural Progenitors Are an Effective Drug Discovery Model for Neurological mtDNA Disorders. Cell Stem Cell. 2017;20:659–74 e659.
pubmed: 28132834 doi: 10.1016/j.stem.2016.12.013
Mertens J, Wang QW, Kim Y, Yu DX, Pham S, Yang B, et al. Differential responses to lithium in hyperexcitable neurons from patients with bipolar disorder. Nature. 2015;527:95–99.
pubmed: 26524527 pmcid: 4742055 doi: 10.1038/nature15526
McNeill RV, Ziegler GC, Radtke F, Nieberler M, Lesch KP, Kittel-Schneider S. Mental health dished up-the use of iPSC models in neuropsychiatric research. J Neural Transm (Vienna). 2020;127:1547–68.
doi: 10.1007/s00702-020-02197-9
Srivastava R, Faust T, Ramos A, Ishizuka K, Sawa A. Dynamic Changes of the Mitochondria in Psychiatric Illnesses: New Mechanistic Insights From Human Neuronal Models. Biol Psychiatry. 2018;83:751–60.
pubmed: 29486891 pmcid: 6469392 doi: 10.1016/j.biopsych.2018.01.007
Gimenez-Palomo A, Dodd S, Anmella G, Carvalho AF, Scaini G, Quevedo J, et al. The Role of Mitochondria in Mood Disorders: From Physiology to Pathophysiology and to Treatment. Front Psychiatry. 2021;12:546801.
pubmed: 34295268 pmcid: 8291901 doi: 10.3389/fpsyt.2021.546801
Osete JR, Akkouh IA, de Assis DR, Szabo A, Frei E, Hughes T, et al. Lithium increases mitochondrial respiration in iPSC-derived neural precursor cells from lithium responders. Mol Psychiatry. 2021;26:6789–805.
pubmed: 34075196 pmcid: 8760072 doi: 10.1038/s41380-021-01164-4
Schulze M, Hoja S, Winner B, Winkler J, Edenhofer F, Riemenschneider MJ. Model Testing of PluriTest with Next-Generation Sequencing Data. Stem Cells Dev. 2016;25:569–71.
pubmed: 26978076 doi: 10.1089/scd.2015.0266
Yan Y, Shin S, Jha BS, Liu Q, Sheng J, Li F, et al. Efficient and rapid derivation of primitive neural stem cells and generation of brain subtype neurons from human pluripotent stem cells. Stem Cells Transl Med. 2013;2:862–70.
pubmed: 24113065 pmcid: 3808201 doi: 10.5966/sctm.2013-0080
Milenkovic VM, Slim D, Bader S, Koch V, Heinl ES, Alvarez-Carbonell D, et al. CRISPR-Cas9 Mediated TSPO Gene Knockout alters Respiration and Cellular Metabolism in Human Primary Microglia Cells. Int J Mol Sci. 2019;20:3359.
pmcid: 6651328 doi: 10.3390/ijms20133359
Schindelin J, Arganda-Carreras I, Frise E, Kaynig V, Longair M, Pietzsch T, et al. Fiji: an open-source platform for biological-image analysis. Nat Methods. 2012;9:676–82.
pubmed: 22743772 doi: 10.1038/nmeth.2019
Bader S, Wolf L, Milenkovic VM, Gruber M, Nothdurfter C, Rupprecht R, et al. Differential effects of TSPO ligands on mitochondrial function in mouse microglia cells. Psychoneuroendocrinology. 2019;106:65–76.
pubmed: 30954920 doi: 10.1016/j.psyneuen.2019.03.029
Bates D, Machler M, Bolker BM, Walker SC. Fitting Linear Mixed-Effects Models Using lme4. J Stat Softw. 2015;67:1–48.
doi: 10.18637/jss.v067.i01
Kuznetsova A, Brockhoff PB, Christensen RHB. lmerTest Package: Tests in Linear Mixed Effects Models. J Stat Softw. 2017;82:1–26.
doi: 10.18637/jss.v082.i13
Hilbert S, Stadler M, Lindl A, Naumann F, Bühner M. Analyzing longitudinal intervention studies with linear mixed models. Test Psychometrics Methodol Appl Psychol. 2019;26:101–19.
Zhang X, Huang CT, Chen J, Pankratz MT, Xi J, Li J, et al. Pax6 is a human neuroectoderm cell fate determinant. Cell Stem Cell. 2010;7:90–100.
pubmed: 20621053 pmcid: 2904346 doi: 10.1016/j.stem.2010.04.017
Zheng X, Boyer L, Jin M, Mertens J, Kim Y, Ma L, et al. Metabolic reprogramming during neuronal differentiation from aerobic glycolysis to neuronal oxidative phosphorylation. Elife 2016;5:e13374.
Shadrina M, Bondarenko EA, Slominsky PA. Genetics Factors in Major Depression Disease. Front Psychiatry. 2018;9:334.
pubmed: 30083112 pmcid: 6065213 doi: 10.3389/fpsyt.2018.00334
Wray NR, Ripke S, Mattheisen M, Trzaskowski M, Byrne EM, Abdellaoui A, et al. Genome-wide association analyses identify 44 risk variants and refine the genetic architecture of major depression. Nat Genet. 2018;50:668–81.
pubmed: 29700475 pmcid: 5934326 doi: 10.1038/s41588-018-0090-3
Gratten J, Wray NR, Keller MC, Visscher PM. Large-scale genomics unveils the genetic architecture of psychiatric disorders. Nat Neurosci. 2014;17:782–90.
pubmed: 24866044 pmcid: 4112149 doi: 10.1038/nn.3708
Sun H, Kennedy PJ, Nestler EJ. Epigenetics of the depressed brain: role of histone acetylation and methylation. Neuropsychopharmacology. 2013;38:124–37.
pubmed: 22692567 doi: 10.1038/npp.2012.73
Nestler EJ. Epigenetic mechanisms of depression. JAMA Psychiatry. 2014;71:454–6.
pubmed: 24499927 pmcid: 4057796 doi: 10.1001/jamapsychiatry.2013.4291
Uchida S, Yamagata H, Seki T, Watanabe Y. Epigenetic mechanisms of major depression: targeting neuronal plasticity. Psychiatry Clin Neurosci. 2018;72:212–27.
pubmed: 29154458 doi: 10.1111/pcn.12621
Barbu MC, Shen X, Walker RM, Howard DM, Evans KL, Whalley HC, et al. Epigenetic prediction of major depressive disorder. Mol Psychiatry. 2021;26:5112–23.
pubmed: 32523041 doi: 10.1038/s41380-020-0808-3
Lin E, Tsai SJ. Epigenetics and Depression: An Update. Psychiatry Investig. 2019;16:654–61.
pubmed: 31455063 pmcid: 6761788 doi: 10.30773/pi.2019.07.17.2
Doi A, Park IH, Wen B, Murakami P, Aryee MJ, Irizarry R, et al. Differential methylation of tissue- and cancer-specific CpG island shores distinguishes human induced pluripotent stem cells, embryonic stem cells and fibroblasts. Nat Genet. 2009;41:1350–3.
pubmed: 19881528 pmcid: 2958040 doi: 10.1038/ng.471
Lister R, Pelizzola M, Kida YS, Hawkins RD, Nery JR, Hon G, et al. Hotspots of aberrant epigenomic reprogramming in human induced pluripotent stem cells. Nature. 2011;471:68–73.
pubmed: 21289626 pmcid: 3100360 doi: 10.1038/nature09798
Ohi Y, Qin H, Hong C, Blouin L, Polo JM, Guo T, et al. Incomplete DNA methylation underlies a transcriptional memory of somatic cells in human iPS cells. Nat Cell Biol. 2011;13:541–9.
pubmed: 21499256 pmcid: 3987913 doi: 10.1038/ncb2239
Lindau M, Neher E. Patch-clamp techniques for time-resolved capacitance measurements in single cells. Pflug Arch. 1988;411:137–46.
doi: 10.1007/BF00582306
Hernández-Balaguera E, Vara H, Polo JL. Identification of Capacitance Distribution in Neuronal Membranes from a Fractional-Order Electrical Circuit and Whole-Cell Patch-Clamped Cells. J Electrochem Soc. 2018;165:G3104–G3111.
doi: 10.1149/2.0161812jes
Kim MH, von Gersdorff H. Extending the realm of membrane capacitance measurements to nerve terminals with complex morphologies. J Physiol. 2010;588:2011–2.
pubmed: 20551018 pmcid: 2911205 doi: 10.1113/jphysiol.2010.191270
Vaarmann A, Mandel M, Zeb A, Wareski P, Liiv J, Kuum M, et al. Mitochondrial biogenesis is required for axonal growth. Development. 2016;143:1981–92.
pubmed: 27122166
Pre D, Nestor MW, Sproul AA, Jacob S, Koppensteiner P, Chinchalongporn V, et al. A time course analysis of the electrophysiological properties of neurons differentiated from human induced pluripotent stem cells (iPSCs). PLoS ONE. 2014;9:e103418.
pubmed: 25072157 pmcid: 4114788 doi: 10.1371/journal.pone.0103418
Fang D, Qing Y, Yan S, Chen D, Yan SS. Development and Dynamic Regulation of Mitochondrial Network in Human Midbrain Dopaminergic Neurons Differentiated from iPSCs. Stem Cell Rep. 2016;7:678–92.
doi: 10.1016/j.stemcr.2016.08.014
Helm K, Viol K, Weiger TM, Tass PA, Grefkes C, Del Monte D, et al. Neuronal connectivity in major depressive disorder: a systematic review. Neuropsychiatr Dis Treat. 2018;14:2715–37.
pubmed: 30425491 pmcid: 6200438 doi: 10.2147/NDT.S170989
Drysdale AT, Grosenick L, Downar J, Dunlop K, Mansouri F, Meng Y, et al. Resting-state connectivity biomarkers define neurophysiological subtypes of depression. Nat Med. 2017;23:28–38.
pubmed: 27918562 doi: 10.1038/nm.4246

Auteurs

Julian Triebelhorn (J)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany.

Iseline Cardon (I)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany.

Kerstin Kuffner (K)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany.

Stefanie Bader (S)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany.

Tatjana Jahner (T)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany.

Katrin Meindl (K)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany.

Tanja Rothhammer-Hampl (T)

Department of Neuropathology, Regensburg University Hospital, 93053, Regensburg, Germany.

Markus J Riemenschneider (MJ)

Department of Neuropathology, Regensburg University Hospital, 93053, Regensburg, Germany.

Konstantin Drexler (K)

Department of Dermatology, Regensburg University Hospital, 93053, Regensburg, Germany.

Mark Berneburg (M)

Department of Dermatology, Regensburg University Hospital, 93053, Regensburg, Germany.

Caroline Nothdurfter (C)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany.

André Manook (A)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany.

Christoph Brochhausen (C)

Institute of Pathology, University of Regensburg, 93053, Regensburg, Germany.
Central Biobank of the University of Regensburg and the Regensburg University Hospital, 93053, Regensburg, Germany.

Thomas C Baghai (TC)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany.

Sven Hilbert (S)

Institute of Educational Research, Faculty of Human Sciences, University of Regensburg, 93053, Regensburg, Germany.

Rainer Rupprecht (R)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany.

Vladimir M Milenkovic (VM)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany.

Christian H Wetzel (CH)

Department of Psychiatry and Psychotherapy, University of Regensburg, 93053, Regensburg, Germany. christian.wetzel@klinik.uni-regensburg.de.

Classifications MeSH