Early-onset and severe pulmonary arterial hypertension due to a novel compound heterozygous association of rare

blood cells genetics hypoxia inducible factor pulmonary circulation

Journal

Pulmonary circulation
ISSN: 2045-8932
Titre abrégé: Pulm Circ
Pays: United States
ID NLM: 101557243

Informations de publication

Date de publication:
Apr 2022
Historique:
received: 03 11 2021
revised: 03 01 2022
accepted: 25 01 2022
entrez: 23 6 2022
pubmed: 24 6 2022
medline: 24 6 2022
Statut: epublish

Résumé

Very rare cases of pulmonary arterial hypertension (PAH) have been linked to homozygous or compound heterozygous von Hippel-Lindau (

Identifiants

pubmed: 35734542
doi: 10.1002/pul2.12052
pii: PUL212052
pmc: PMC9190294
doi:

Types de publication

Case Reports

Langues

eng

Pagination

e12052

Informations de copyright

© 2022 The Authors. Pulmonary Circulation published by John Wiley & Sons Ltd on behalf of Pulmonary Vascular Research Institute.

Déclaration de conflit d'intérêts

Outside the submitted work, Antoine Bondue received consultancy fees from Amicus, Baeyer, Boehringer Ingelheim, Sanofi, Pfizer, and Alnylam; speaker fees from Pfizer, Sanofi, and Alnylam and reports travel grants from Abbott, Pfizer, and Takeda. Jean‐Luc Vachiery received consultant fees from Actelion, Bayer, Bial Portela, PhaseBio, Respira Therapeutics, United Therapeutics, and SoniVie and reports speaker fees and travel grants from Actelion, Acceleron, Bayer, Merck, Novartis, United Therapeutics. Laura Chomette reports travel grants from Sanofi and Pfizer. Remaining authors declare that there are no conflicts of interest.

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Auteurs

Laura Chomette (L)

Department of Cardiology, CUB Hôpital Erasme Université Libre de Bruxelles (ULB) Brussels Belgium.
Institut de Recherche Interdisciplinaire en Biologie Humaine et Moléculaire (IRIBHM) Université Libre de Bruxelles (ULB) Brussels Belgium.

Isabelle Migeotte (I)

Institut de Recherche Interdisciplinaire en Biologie Humaine et Moléculaire (IRIBHM) Université Libre de Bruxelles (ULB) Brussels Belgium.
Department of Human Genetics, CUB Hôpital Erasme Université Libre de Bruxelles (ULB) Brussels Belgium.

Céline Dewachter (C)

Department of Cardiology, CUB Hôpital Erasme Université Libre de Bruxelles (ULB) Brussels Belgium.

Jean-Luc Vachiery (JL)

Department of Cardiology, CUB Hôpital Erasme Université Libre de Bruxelles (ULB) Brussels Belgium.

Guillaume Smits (G)

Department of Human Genetics, CUB Hôpital Erasme Université Libre de Bruxelles (ULB) Brussels Belgium.

Antoine Bondue (A)

Department of Cardiology, CUB Hôpital Erasme Université Libre de Bruxelles (ULB) Brussels Belgium.
Institut de Recherche Interdisciplinaire en Biologie Humaine et Moléculaire (IRIBHM) Université Libre de Bruxelles (ULB) Brussels Belgium.

Classifications MeSH