Case Report: Inactivating PTH/PTHrP Signaling Disorder Type 1 Presenting With PTH Resistance.

Albright hereditary osteodystrophy GNAS PTH1R alfacalcidol epilepsy iPPSD1 parathyroid hormone pseudohypoparathyreoidism

Journal

Frontiers in endocrinology
ISSN: 1664-2392
Titre abrégé: Front Endocrinol (Lausanne)
Pays: Switzerland
ID NLM: 101555782

Informations de publication

Date de publication:
2022
Historique:
received: 25 04 2022
accepted: 31 05 2022
entrez: 18 7 2022
pubmed: 19 7 2022
medline: 20 7 2022
Statut: epublish

Résumé

PTH resistance is characterized by elevated parathyroid hormone (PTH) levels, hypocalcemia, hyperphosphatemia and it is classically associated with

Identifiants

pubmed: 35846276
doi: 10.3389/fendo.2022.928284
pmc: PMC9280615
doi:

Substances chimiques

Parathyroid Hormone 0
Parathyroid Hormone-Related Protein 0

Types de publication

Case Reports Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

928284

Informations de copyright

Copyright © 2022 Demaret, Wintjens, Sana, Docquir, Bertin, Ide, Monestier, Karadurmus, Benoit and Maystadt.

Déclaration de conflit d'intérêts

The authors declare that the research was conducted in the absence of any commercial or financial relationships that could be construed as a potential conflict of interest.

Références

Am J Hum Genet. 2008 Dec;83(6):781-6
pubmed: 19061984
Science. 2019 Apr 12;364(6436):148-153
pubmed: 30975883
Childs Nerv Syst. 2011 Dec;27(12):2035-9
pubmed: 21994050
Case Rep Med. 2016;2016:7645938
pubmed: 27703483
Am J Med Genet. 1997 Aug 22;71(3):283-8
pubmed: 9268097
Pediatr Radiol. 1985;15(2):141-3
pubmed: 3975110
Genet Med. 2015 May;17(5):405-24
pubmed: 25741868
Genes Brain Behav. 2016 Sep;15(7):669-77
pubmed: 27415614
Dev Cell. 2002 Aug;3(2):183-94
pubmed: 12194850
Hum Mol Genet. 2005 Jan 1;14(1):1-5
pubmed: 15525660
Arch Oral Biol. 2016 Jul;67:28-33
pubmed: 27019138
Case Rep Endocrinol. 2020 Nov 10;2020:8840082
pubmed: 33224538
J Clin Endocrinol Metab. 2007 Mar;92(3):1088-95
pubmed: 17164305
J Clin Invest. 1998 Jul 1;102(1):34-40
pubmed: 9649554
Clin Case Rep. 2018 Aug 16;6(10):1933-1940
pubmed: 30349702
Nat Struct Mol Biol. 2018 Dec;25(12):1086-1092
pubmed: 30455434
Childs Nerv Syst. 2007 Nov;23(11):1239-50
pubmed: 17639419
Eur J Pediatr. 1984 Feb;141(4):231-5
pubmed: 6734674
Ann Hum Biol. 2017 Mar;44(2):99-107
pubmed: 27892699
Eur J Endocrinol. 2016 Dec;175(6):P1-P17
pubmed: 27401862
Acta Pharmacol Sin. 2012 Mar;33(3):300-11
pubmed: 22266723
J Clin Endocrinol Metab. 2011 Oct;96(10):3020-30
pubmed: 21816789
Clin Genet. 2018 Nov;94(5):457-460
pubmed: 29987841
J Clin Endocrinol Metab. 2001 Apr;86(4):1788-94
pubmed: 11297619
Clin Genet. 2019 Oct;96(4):378-379
pubmed: 31297790
Neurol India. 2011 Jul-Aug;59(4):586-9
pubmed: 21891938

Auteurs

Tanguy Demaret (T)

Centre de Génétique Humaine, Institut de Pathologie et Génétique (IPG), Gosselies, Belgium.

René Wintjens (R)

Unité Microbiologie, Chimie Bioorganique et Macromoléculaire (CP206/04), Institut de Pharmacie, Université Libre de Bruxelles (ULB), Brussels, Belgium.

Gwenaelle Sana (G)

Service de Pédiatrie, Grand Hôpital de Charleroi (GHdC), Charleroi, Belgium.

Joachim Docquir (J)

Service de Pédiatrie, Grand Hôpital de Charleroi (GHdC), Charleroi, Belgium.

Frederic Bertin (F)

Service de Radiologie, Grand Hôpital de Charleroi (GHdC), Charleroi, Belgium.

Christophe Ide (C)

Service de Radiologie, Grand Hôpital de Charleroi (GHdC), Charleroi, Belgium.

Olivier Monestier (O)

Centre de Génétique Humaine, Institut de Pathologie et Génétique (IPG), Gosselies, Belgium.

Deniz Karadurmus (D)

Centre de Génétique Humaine, Institut de Pathologie et Génétique (IPG), Gosselies, Belgium.

Valerie Benoit (V)

Centre de Génétique Humaine, Institut de Pathologie et Génétique (IPG), Gosselies, Belgium.

Isabelle Maystadt (I)

Centre de Génétique Humaine, Institut de Pathologie et Génétique (IPG), Gosselies, Belgium.
Département de Médecine, Unité de Recherche en Physiologie Moléculaire (URPhyM), Université de Namur (UNamur), Namur, Belgium.

Articles similaires

[Redispensing of expensive oral anticancer medicines: a practical application].

Lisanne N van Merendonk, Kübra Akgöl, Bastiaan Nuijen
1.00
Humans Antineoplastic Agents Administration, Oral Drug Costs Counterfeit Drugs

Smoking Cessation and Incident Cardiovascular Disease.

Jun Hwan Cho, Seung Yong Shin, Hoseob Kim et al.
1.00
Humans Male Smoking Cessation Cardiovascular Diseases Female
Humans United States Aged Cross-Sectional Studies Medicare Part C
1.00
Humans Yoga Low Back Pain Female Male

Classifications MeSH