Long-term follow-up of cladribine treatment in hairy cell leukemia: 30-year experience in a multicentric Italian study.


Journal

Blood cancer journal
ISSN: 2044-5385
Titre abrégé: Blood Cancer J
Pays: United States
ID NLM: 101568469

Informations de publication

Date de publication:
19 07 2022
Historique:
received: 02 03 2022
accepted: 28 06 2022
revised: 17 06 2022
entrez: 19 7 2022
pubmed: 20 7 2022
medline: 22 7 2022
Statut: epublish

Résumé

Hairy cell leukemia (HCL) is a rare lymphoproliferative disease with an excellent prognosis after treatment with cladribine (2CDA), although relapse may occur during follow-up. The aim of the study is to review the efficacy, safety, long-term remission rate, and overall survival (OS) in those patients who received 2CDA as first-line treatment. We retrospectively reviewed data of HCL patients treated with 2CDA between March 1991 and May 2019 at 18 Italian Hematological centers: 513 patients were evaluable for study purpose. The median age was 54 years (range 24-88) and ECOG was 0 in 84.9% of cases. A total of 330 (64.3%) patients received 2CDA intravenously and 183 (35.7%) subcutaneously. ORR was 91.8%: CR was obtained in 335 patients (65.3%), PR in 96 (18.7%), and hematological response in 40 (7.8%) patients; in 42 (8.2%) no response was observed. Hemoglobin value (p = 0.044), frequency of circulating hairy cells (p = 0.039), recovery of absolute neutrophil count (p = 0.006), and normalization of spleen (p ≤ 0.001) were associated with CR compared to PR in univariable analysis. At a median follow-up of 6.83 years (range 0.04-28.52), the median time to relapse was 12.2 years. A significant difference in duration of response was identified between patients that obtained a CR and PR (19.4 years versus 4.8 years, p < 0.0001). Non-hematological grade 3 or higher early toxicity was reported in 103 (20.1%) patients. Median OS was not reached: 95.3%, 92.4%, and 81.8% of patients were estimated to be alive at 5, 10, and 15 years, respectively. Forty-nine patients died (9.5%), following an infection in 14 cases (2.7%), natural causes in 14 (2.7%), cardiovascular events in 13 (2.5%), a second neoplasm in 6 (1.2%), and progression of HCL in 2 cases (0.4%). Following treatment of HCL with 2CDA, 80% of patients are estimated to be alive 15 years after diagnosis.

Identifiants

pubmed: 35853850
doi: 10.1038/s41408-022-00702-9
pii: 10.1038/s41408-022-00702-9
pmc: PMC9296486
doi:

Substances chimiques

Antineoplastic Agents 0
Cladribine 47M74X9YT5

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

109

Informations de copyright

© 2022. The Author(s).

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Auteurs

Livio Pagano (L)

Dipartimento di Diagnostica per Immagini, Radioterapia Oncologica ed Ematologia, Fondazione Policlinico Universitario A. Gemelli IRCCS, Roma, Italy.
Sezione di Ematologia, Dipartimento di Scienze Radiologiche ed Ematologiche, Università Cattolica del Sacro Cuore, Roma, Italy.

Marianna Criscuolo (M)

Dipartimento di Diagnostica per Immagini, Radioterapia Oncologica ed Ematologia, Fondazione Policlinico Universitario A. Gemelli IRCCS, Roma, Italy. marianna.criscuolo@policlinicogemelli.it.

Alessandro Broccoli (A)

IRCCS Azienda Ospedaliero-Universitaria di Bologna Istituto di Ematologia "Seràgnoli", Roma, Italy.
Dipartimento di Medicina Specialistica, Diagnostica e Sperimentale Università di Bologna, Bologna, Italy.

Alfonso Piciocchi (A)

GIMEMA Foundation, Franco Mandelli Onlus, Rome, Italy.

Marzia Varettoni (M)

Divisione di Ematologia, Fondazione IRCCS Policlinico San Matteo, Pavia, Italy.

Eugenio Galli (E)

Dipartimento di Diagnostica per Immagini, Radioterapia Oncologica ed Ematologia, Fondazione Policlinico Universitario A. Gemelli IRCCS, Roma, Italy.
Sezione di Ematologia, Dipartimento di Scienze Radiologiche ed Ematologiche, Università Cattolica del Sacro Cuore, Roma, Italy.

Antonella Anastasia (A)

Department of Hematology, ASST Spedali Civili, Brescia, Italy.

Maria Cantonetti (M)

Dipartimento di Oncoematologia Policlinico Tor Vergata, Università Tor Vergata, Roma, Italy.

Livio Trentin (L)

Division of Haematology and Clinical Immunology, University of Padova, Padova, Italy.

Sofia Kovalchuk (S)

SOD C Ematologia, AOU Careggi, Firenze, Italy.

Lorella Orsucci (L)

S.C. Ematologia, A.O.U. Città della Salute e della Scienza di Torino, Torino, Italy.

Annamaria Frustaci (A)

Divisione di Ematologia, ASST Grande Ospedale Metropolitano Niguarda, Milano, Italy.

Angelica Spolzino (A)

Dipartimento di Medicina e Chirurgia, Università degli studi di Parma, Parma, Italy.
Oncoematologia, Istituto Oncologico Veneto IOV-IRCSS, Castelfranco Veneto, Italy.

Stefano Volpetti (S)

Clinica Ematologia, Azienda Sanitaria Universitaria Integrata, Udine, Italy.

Ombretta Annibali (O)

Hematology and Stem Cell Transplantation Unit, Campus Bio-Medico University, Roma, Italy.

Sergio Storti (S)

UOC Oncoematologia Fondazione di Ricerca e Cura Giovanni Paolo II, Campobasso - Università Cattolica del Sacro Cuore, Campobasso, Italy.

Caterina Stelitano (C)

Divisione di Ematologia, Azienda Ospedaliera "Bianchi Melacrino Morelli", Reggio Calabria, Italy.

Francesco Marchesi (F)

Haematology and Stem Cell Transplantation Unit, IRCCS Regina Elena National Cancer Institute, Roma, Italy.

Massimo Offidani (M)

Clinica di Ematologia, Azienda Ospedaliero-Universitaria Ospedali Riuniti di Ancona, Ancona, Italy.

Beatrice Casadei (B)

IRCCS Azienda Ospedaliero-Universitaria di Bologna Istituto di Ematologia "Seràgnoli", Roma, Italy.
Dipartimento di Medicina Specialistica, Diagnostica e Sperimentale Università di Bologna, Bologna, Italy.

Maria Elena Nizzoli (ME)

Divisione di Ematologia, Fondazione IRCCS Policlinico San Matteo, Pavia, Italy.

Maria Lucia De Luca (ML)

Divisione di Ematologia, Department of Translational and Precision Medicine, Sapienza University of Rome, Rome, Italy.

Luana Fianchi (L)

Dipartimento di Diagnostica per Immagini, Radioterapia Oncologica ed Ematologia, Fondazione Policlinico Universitario A. Gemelli IRCCS, Roma, Italy.

Marina Motta (M)

Department of Hematology, ASST Spedali Civili, Brescia, Italy.

Luca Guarnera (L)

Dipartimento di Oncoematologia Policlinico Tor Vergata, Università Tor Vergata, Roma, Italy.

Edoardo Simonetti (E)

Institute of Hematology and Center for Hemato-Oncology Research, Department of Medicine and Surgery, University and Hospital of Perugia, Perugia, Italy.

Andrea Visentin (A)

Division of Haematology and Clinical Immunology, University of Padova, Padova, Italy.

Francesco Vassallo (F)

S.C. Ematologia, A.O.U. Città della Salute e della Scienza di Torino, Torino, Italy.

Marina Deodato (M)

Divisione di Ematologia, ASST Grande Ospedale Metropolitano Niguarda, Milano, Italy.

Chiara Sarlo (C)

Hematology and Stem Cell Transplantation Unit, Campus Bio-Medico University, Roma, Italy.

Attilio Olivieri (A)

Clinica di Ematologia, Azienda Ospedaliero-Universitaria Ospedali Riuniti di Ancona, Ancona, Italy.

Brunangelo Falini (B)

Institute of Hematology and Center for Hemato-Oncology Research, Department of Medicine and Surgery, University and Hospital of Perugia, Perugia, Italy.

Alessandro Pulsoni (A)

Divisione di Ematologia, Department of Translational and Precision Medicine, Sapienza University of Rome, Rome, Italy.

Enrico Tiacci (E)

Institute of Hematology and Center for Hemato-Oncology Research, Department of Medicine and Surgery, University and Hospital of Perugia, Perugia, Italy.

Pier Luigi Zinzani (PL)

IRCCS Azienda Ospedaliero-Universitaria di Bologna Istituto di Ematologia "Seràgnoli", Roma, Italy.
Dipartimento di Medicina Specialistica, Diagnostica e Sperimentale Università di Bologna, Bologna, Italy.

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