Nuclear RNA binding regulates TDP-43 nuclear localization and passive nuclear export.

CP: Molecular biology RNA TDP-43 amyotrophic lateral sclerosis frontotemporal dementia neurodegeneration nuclear transport splicing transcription

Journal

Cell reports
ISSN: 2211-1247
Titre abrégé: Cell Rep
Pays: United States
ID NLM: 101573691

Informations de publication

Date de publication:
19 07 2022
Historique:
received: 27 09 2021
revised: 26 03 2022
accepted: 27 06 2022
entrez: 20 7 2022
pubmed: 21 7 2022
medline: 23 7 2022
Statut: ppublish

Résumé

Nuclear clearance of the RNA-binding protein TDP-43 is a hallmark of neurodegeneration and an important therapeutic target. Our current understanding of TDP-43 nucleocytoplasmic transport does not fully explain its predominantly nuclear localization or mislocalization in disease. Here, we show that TDP-43 exits nuclei by passive diffusion, independent of facilitated mRNA export. RNA polymerase II blockade and RNase treatment induce TDP-43 nuclear efflux, suggesting that nuclear RNAs sequester TDP-43 in nuclei and limit its availability for passive export. Induction of TDP-43 nuclear efflux by short, GU-rich oligomers (presumably by outcompeting TDP-43 binding to endogenous nuclear RNAs), and nuclear retention conferred by splicing inhibition, demonstrate that nuclear TDP-43 localization depends on binding to GU-rich nuclear RNAs. Indeed, RNA-binding domain mutations markedly reduce TDP-43 nuclear localization and abolish transcription blockade-induced nuclear efflux. Thus, the nuclear abundance of GU-RNAs, dictated by the balance of transcription, pre-mRNA processing, and RNA export, regulates TDP-43 nuclear localization.

Identifiants

pubmed: 35858577
pii: S2211-1247(22)00908-1
doi: 10.1016/j.celrep.2022.111106
pmc: PMC9345261
mid: NIHMS1825578
pii:
doi:

Substances chimiques

DNA-Binding Proteins 0
RNA, Nuclear 0

Types de publication

Journal Article Research Support, Non-U.S. Gov't Research Support, N.I.H., Intramural Research Support, N.I.H., Extramural Research Support, U.S. Gov't, Non-P.H.S.

Langues

eng

Sous-ensembles de citation

IM

Pagination

111106

Subventions

Organisme : NINDS NIH HHS
ID : R03 NS127011
Pays : United States
Organisme : Intramural NIH HHS
ID : ZIA HD008954
Pays : United States
Organisme : NINDS NIH HHS
ID : K08 NS104273
Pays : United States
Organisme : NINDS NIH HHS
ID : R01 NS123538
Pays : United States
Organisme : NIGMS NIH HHS
ID : T32 GM007445
Pays : United States

Informations de copyright

Copyright © 2022 The Author(s). Published by Elsevier Inc. All rights reserved.

Déclaration de conflit d'intérêts

Declaration of interests The authors declare no competing interests.

Références

Methods Mol Biol. 2009;464:181-205
pubmed: 18951186
Nat Commun. 2017 Jun 29;8(1):45
pubmed: 28663553
PLoS One. 2011;6(8):e23882
pubmed: 21858232
Front Cell Neurosci. 2021 Jul 19;15:708181
pubmed: 34349625
Structure. 2016 Sep 6;24(9):1537-49
pubmed: 27545621
Proc Natl Acad Sci U S A. 2008 Oct 14;105(41):15779-84
pubmed: 18840688
Nature. 2020 Jul;583(7818):711-719
pubmed: 32728246
Mol Cell. 2011 Aug 5;43(3):340-52
pubmed: 21723171
Trends Cell Biol. 2006 Mar;16(3):125-34
pubmed: 16478663
Wiley Interdiscip Rev RNA. 2018 Jan;9(1):
pubmed: 28853213
Nucleic Acids Res. 2018 Dec 14;46(22):11939-11951
pubmed: 30398641
Proc Natl Acad Sci U S A. 2017 Feb 28;114(9):2206-2211
pubmed: 28193894
Elife. 2020 Jul 21;9:
pubmed: 32692309
Gene. 2004 Dec 8;343(1):1-9
pubmed: 15563827
Proc Natl Acad Sci U S A. 2009 Mar 3;106(9):3089-94
pubmed: 19208808
J Cell Biol. 2017 Nov 6;216(11):3609-3624
pubmed: 28864541
Front Mol Neurosci. 2018 Oct 09;11:372
pubmed: 30356856
Front Mol Neurosci. 2019 Dec 17;12:301
pubmed: 31920533
Nature. 2011 Jul 20;475(7356):333-41
pubmed: 21776079
Cell. 2013 Aug 29;154(5):996-1009
pubmed: 23993093
Elife. 2018 Oct 03;7:
pubmed: 30281021
Nat Chem Biol. 2017 May;13(5):501-507
pubmed: 28263964
J Cell Sci. 2017 May 1;130(9):1519-1531
pubmed: 28302904
J Cell Sci. 2005 Nov 15;118(Pt 22):5243-55
pubmed: 16249233
Sci Rep. 2018 May 4;8(1):7084
pubmed: 29728564
Nat Neurosci. 2019 Oct;22(10):1709-1717
pubmed: 31451803
J Comput Chem. 2021 Sep 5;42(23):1670-1680
pubmed: 34109652
Neuron. 2019 Apr 17;102(2):321-338.e8
pubmed: 30826182
EMBO J. 2020 Jan 2;39(1):e101689
pubmed: 31617608
Nature. 1992 Feb 20;355(6362):730-2
pubmed: 1371331
Genome Res. 2020 Jan;30(1):1-11
pubmed: 31852722
Mol Cell. 2020 Apr 2;78(1):9-29
pubmed: 32243832
Genes Dev. 1998 Jan 1;12(1):55-66
pubmed: 9420331
Science. 2018 May 25;360(6391):918-921
pubmed: 29650702
Biochem Biophys Res Commun. 2006 Dec 22;351(3):602-11
pubmed: 17084815
Proc Natl Acad Sci U S A. 2020 Mar 17;117(11):5883-5894
pubmed: 32132204
J Biol Chem. 2019 Apr 26;294(17):6696-6709
pubmed: 30824544
Nat Commun. 2018 Jul 20;9(1):2845
pubmed: 30030424
Sci Rep. 2018 Jun 8;8(1):8755
pubmed: 29884807
Sci Rep. 2018 Mar 6;8(1):4049
pubmed: 29511296
Cell. 1999 Dec 23;99(7):677-90
pubmed: 10619422
Biochim Biophys Acta. 1971 Dec 3;249(2):462-92
pubmed: 5134192
Trends Mol Med. 2014 Feb;20(2):66-71
pubmed: 24355761
Nat Commun. 2015 Jan 05;6:5845
pubmed: 25556531
Wiley Interdiscip Rev RNA. 2013 Mar-Apr;4(2):167-79
pubmed: 23424172
Biochem Biophys Res Commun. 2009 Mar 13;380(3):431-6
pubmed: 19284986
Genes Cells. 2017 Sep;22(9):785-798
pubmed: 28695676
Proc Natl Acad Sci U S A. 2004 Mar 2;101(9):2987-92
pubmed: 14981256
Protein Sci. 2020 Jun;29(6):1459-1472
pubmed: 32096308
Nat Genet. 2008 May;40(5):572-4
pubmed: 18372902
Nat Commun. 2021 Oct 29;12(1):6241
pubmed: 34716321
J Biol Chem. 2001 Sep 28;276(39):36337-43
pubmed: 11470789
Ann Neurol. 2008 Apr;63(4):535-8
pubmed: 18288693
Mol Cell. 2020 Aug 6;79(3):443-458.e7
pubmed: 32649883
Sci Rep. 2018 Mar 15;8(1):4606
pubmed: 29545601
J Biol Chem. 2008 Nov 28;283(48):33147-54
pubmed: 18826947
J Vis Exp. 2021 Jul 9;(173):
pubmed: 34309603
J Cell Biol. 2016 Oct 10;215(1):57-76
pubmed: 27697925
Genes Dev. 2012 Aug 1;26(15):1679-84
pubmed: 22855830
Science. 2012 Mar 30;335(6076):1643-6
pubmed: 22461616
Nature. 1999 Dec 16;402(6763):835-8
pubmed: 10617207
Elife. 2015 Jan 02;4:
pubmed: 25555158
J Clin Invest. 2020 Mar 2;130(3):1139-1155
pubmed: 31714900
J Cell Biol. 1996 Sep;134(6):1365-73
pubmed: 8830767
Proc Natl Acad Sci U S A. 2002 May 28;99(11):7496-501
pubmed: 12032311
Nat Rev Mol Cell Biol. 2016 Apr;17(4):227-39
pubmed: 26726035
Chem Soc Rev. 2009 Oct;38(10):2887-921
pubmed: 19771335
J Mol Biol. 2021 May 14;433(10):166948
pubmed: 33744316
Science. 2008 Mar 21;319(5870):1668-72
pubmed: 18309045
EMBO J. 1997 Jun 16;16(12):3587-98
pubmed: 9218800
Mov Disord. 2009 Sep 15;24(12):1843-7
pubmed: 19609911
Neuron. 2019 Apr 17;102(2):339-357.e7
pubmed: 30853299
J Proteome Res. 2010 Feb 5;9(2):1104-20
pubmed: 20020773
FEBS Lett. 2017 Jun;591(11):1489-1507
pubmed: 28380257
Nat Neurosci. 2011 Apr;14(4):452-8
pubmed: 21358640
Angew Chem Int Ed Engl. 2010 Jun 7;49(25):4170-98
pubmed: 20518023
Proc Natl Acad Sci U S A. 2019 Feb 19;116(8):2935-2944
pubmed: 30718402
Front Mol Neurosci. 2019 Feb 14;12:25
pubmed: 30837838
Neuron. 2016 Dec 21;92(6):1266-1278
pubmed: 28009274
Nat Neurosci. 2011 Apr;14(4):459-68
pubmed: 21358643
Nature. 2006 Mar 30;440(7084):697-701
pubmed: 16572176
Mol Cell. 2014 Sep 4;55(5):745-57
pubmed: 25192364
Science. 2021 Feb 5;371(6529):
pubmed: 33335017
J Cell Sci. 2008 Nov 15;121(Pt 22):3778-85
pubmed: 18957508
Nat Protoc. 2020 Aug;15(8):2568-2588
pubmed: 32651564
Cell. 2015 Sep 24;163(1):123-33
pubmed: 26406374
Life Sci Alliance. 2019 Sep 16;2(5):
pubmed: 31527135
Annu Rev Biochem. 2018 Jun 20;87:51-73
pubmed: 29589958
Nucleic Acids Res. 2021 Dec 16;49(22):13092-13107
pubmed: 34871434
Cell Rep. 2019 Apr 23;27(4):1133-1150.e8
pubmed: 31018129
Elife. 2020 Mar 02;9:
pubmed: 32119645
Sci Rep. 2018 May 4;8(1):7083
pubmed: 29728608
Front Genet. 2019 Jan 22;9:712
pubmed: 30723494
Cell. 1995 Nov 3;83(3):415-22
pubmed: 8521471
Annu Rev Biochem. 2015;84:291-323
pubmed: 25784052
Nat Commun. 2018 Jan 29;9(1):420
pubmed: 29379020
Science. 2015 Aug 7;349(6248):650-5
pubmed: 26250685
Nat Chem Biol. 2007 Sep;3(9):570-5
pubmed: 17643112
Nat Chem Biol. 2018 Feb;14(2):163-170
pubmed: 29251720
BMC Biol. 2016 Jul 05;14:54
pubmed: 27380775
Nat Commun. 2020 Sep 11;11(1):4577
pubmed: 32917881
J Biol Chem. 2017 Jul 14;292(28):11992-12006
pubmed: 28566288
Nat Rev Neurosci. 2018 Dec;19(12):715-728
pubmed: 30410025
Nature. 2010 Aug 26;466(7310):1069-75
pubmed: 20740007
Proc Natl Acad Sci U S A. 2017 Mar 21;114(12):E2466-E2475
pubmed: 28265061
Genes (Basel). 2015 Mar 20;6(1):124-49
pubmed: 25802992
J Cell Biol. 2003 Oct 27;163(2):257-69
pubmed: 14581454
Curr Opin Neurobiol. 2019 Dec;59:87-94
pubmed: 31163285
Brain. 2010 Jun;133(Pt 6):1763-71
pubmed: 20472655
Elife. 2019 Nov 07;8:
pubmed: 31697236
EMBO J. 2009 Sep 2;28(17):2541-53
pubmed: 19680228
Neuron. 2019 Apr 17;102(2):294-320
pubmed: 30998900
Nature. 1999 Dec 16;402(6763):832-5
pubmed: 10617206
Nucleic Acids Res. 2013 May;41(9):5062-74
pubmed: 23519609
Proc Natl Acad Sci U S A. 2018 Aug 21;115(34):E7970-E7977
pubmed: 30082412
Int J Biochem Cell Biol. 2017 Oct;91(Pt B):184-193
pubmed: 28591617
J Cell Biol. 1990 Sep;111(3):807-16
pubmed: 2391365
Nat Struct Mol Biol. 2013 Dec;20(12):1443-9
pubmed: 24240615
Nature. 1999 Dec 16;402(6763):838-41
pubmed: 10617208
Genes Dev. 2011 May 15;25(10):1052-64
pubmed: 21576265
Nat Commun. 2018 Jun 13;9(1):2319
pubmed: 29899397
Cell. 2018 Jun 28;174(1):202-217.e9
pubmed: 29958108
Nat Commun. 2020 Jan 9;11(1):137
pubmed: 31919425
Nucleic Acids Res. 2020 Mar 18;48(5):2621-2642
pubmed: 31863590
Front Mol Biosci. 2021 Apr 12;8:659610
pubmed: 33912591
Open Biol. 2018 Mar;8(3):
pubmed: 29563193
Lancet Neurol. 2008 May;7(5):409-16
pubmed: 18396105
Hum Mutat. 2009 Nov;30(11):E974-83
pubmed: 19655382
J Biol Chem. 2008 May 9;283(19):13302-9
pubmed: 18305110
Cancer Sci. 2014 Jan;105(1):110-6
pubmed: 24635824
Proc Natl Acad Sci U S A. 1998 Dec 22;95(26):15293-8
pubmed: 9860962
EMBO J. 2002 Jun 3;21(11):2664-71
pubmed: 12032079
Science. 2006 Oct 6;314(5796):130-3
pubmed: 17023659
Adv Genet. 2015;91:1-53
pubmed: 26410029

Auteurs

Lauren Duan (L)

Brain Science Institute, Johns Hopkins University School of Medicine, Baltimore, MD 21205, USA.

Benjamin L Zaepfel (BL)

Biochemistry, Cellular and Molecular Biology Program, Johns Hopkins University School of Medicine, Baltimore, MD 21205, USA.

Vasilisa Aksenova (V)

Division of Molecular and Cellular Biology, National Institute of Child Health and Human Development, National Institutes of Health, Bethesda, MD 20892, USA.

Mary Dasso (M)

Division of Molecular and Cellular Biology, National Institute of Child Health and Human Development, National Institutes of Health, Bethesda, MD 20892, USA.

Jeffrey D Rothstein (JD)

Brain Science Institute, Johns Hopkins University School of Medicine, Baltimore, MD 21205, USA; Department of Neurology, Johns Hopkins University School of Medicine, Baltimore, MD 21205, USA.

Petr Kalab (P)

Department of Chemical and Biomolecular Engineering, Whiting School of Engineering, Johns Hopkins University, Baltimore, MD 21218, USA. Electronic address: petr@jhu.edu.

Lindsey R Hayes (LR)

Brain Science Institute, Johns Hopkins University School of Medicine, Baltimore, MD 21205, USA; Department of Neurology, Johns Hopkins University School of Medicine, Baltimore, MD 21205, USA. Electronic address: lhayes@jhmi.edu.

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