Characterization of Cognitive, Language and Adaptive Profiles of Children and Adolescents with Malan Syndrome.

Malan Syndrome NFIX variants adaptive behavior cognition intellectual disability sensory processing

Journal

Journal of clinical medicine
ISSN: 2077-0383
Titre abrégé: J Clin Med
Pays: Switzerland
ID NLM: 101606588

Informations de publication

Date de publication:
14 Jul 2022
Historique:
received: 04 05 2022
revised: 16 06 2022
accepted: 16 06 2022
entrez: 27 7 2022
pubmed: 28 7 2022
medline: 28 7 2022
Statut: epublish

Résumé

Malan Syndrome (MS) is an ultra-rare overgrowth genetic syndrome due to heterozygous variants or deletions in the Nuclear Factor I X

Identifiants

pubmed: 35887841
pii: jcm11144078
doi: 10.3390/jcm11144078
pmc: PMC9316998
pii:
doi:

Types de publication

Journal Article

Langues

eng

Références

Am J Hum Genet. 2010 Aug 13;87(2):189-98
pubmed: 20673863
Am J Med Genet A. 2013 May;161A(5):1105-9
pubmed: 23495138
Hum Mutat. 2014 Sep;35(9):1092-100
pubmed: 24924640
Annu Rev Genomics Hum Genet. 2011;12:25-51
pubmed: 21801020
Orphanet J Rare Dis. 2022 Jun 18;17(1):235
pubmed: 35717370
Am J Med Genet A. 2010 Nov;152A(11):2714-26
pubmed: 20949508
J Intellect Disabil Res. 2011 Oct;55(10):973-87
pubmed: 21790824
J Intellect Disabil Res. 2020 Dec;64(12):956-969
pubmed: 33034087
Am J Med Genet A. 2019 Oct;179(10):2119-2123
pubmed: 31369202
Hum Mutat. 2018 Sep;39(9):1226-1237
pubmed: 29897170
Development. 2018 Feb 7;145(3):
pubmed: 29437824
J Pediatr Genet. 2015 Sep;4(3):136-43
pubmed: 27617124
Eur J Hum Genet. 2015 May;23(5):610-5
pubmed: 25118028
Am J Med Genet A. 2020 Nov;182(11):2731-2736
pubmed: 32945093
Pediatr Res. 2015 Nov;78(5):533-9
pubmed: 26200704
Cell Rep. 2016 Mar 8;14(9):2238-2249
pubmed: 26923583
Hum Genome Var. 2017 Jun 01;4:17022
pubmed: 28584646
Eur J Med Genet. 2015 Sep;58(9):488-91
pubmed: 26193383

Auteurs

Paolo Alfieri (P)

Child and Adolescent Neuropsychiatry Unit, Department of Neuroscience, Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.

Marina Macchiaiolo (M)

Rare Diseases and Medical Genetics Unit, University-Hospital Pediatric Department (DPUO), Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.

Martina Collotta (M)

Child and Adolescent Neuropsychiatry Unit, Department of Neuroscience, Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.

Federica Alice Maria Montanaro (FAM)

Child and Adolescent Neuropsychiatry Unit, Department of Neuroscience, Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.

Cristina Caciolo (C)

Child and Adolescent Neuropsychiatry Unit, Department of Neuroscience, Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.

Francesca Cumbo (F)

Child and Adolescent Neuropsychiatry Unit, Department of Neuroscience, Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.

Paolo Galassi (P)

Child and Adolescent Neuropsychiatry Unit, Department of Neuroscience, Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.

Filippo Maria Panfili (FM)

Academic Department of Pediatrics, Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.

Fabiana Cortellessa (F)

Rare Diseases and Medical Genetics Unit, University-Hospital Pediatric Department (DPUO), Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.

Marcella Zollino (M)

Genetica Medica, Fondazione Policlinico Universitario A. Gemelli, IRCCS, 00168 Rome, Italy.
Dipartimento Universitario Scienze della Vita e Sanità Pubblica, Sezione di Medicina Genomica, Università Cattolica del Sacro Cuore Facoltà di Medicina e Chirurgia, 00168 Roma, Italy.

Maria Accadia (M)

Medical Genetics Service, Hospital "Cardinale G. Panico", 73039 Tricase, Italy.

Marco Seri (M)

Unit of Medical Genetics, Azienda Ospedaliero Universitaria di Bologna, IRCCS, 40126 Bologna, Italy.

Marco Tartaglia (M)

Genetics and Rare Diseases Research Division, Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.

Andrea Bartuli (A)

Rare Diseases and Medical Genetics Unit, University-Hospital Pediatric Department (DPUO), Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.

Corrado Mammì (C)

Operative Unit of Medical Genetics Bianchi-Melacrino-Morelli Great Metropolitan Hospital, 89133 Reggio Calabria, Italy.

Stefano Vicari (S)

Child and Adolescent Neuropsychiatry Unit, Department of Neuroscience, Bambino Gesù Children's Hospital, IRCCS, 00165 Rome, Italy.
Department of Life Sciences and Public Health, Università Cattolica del Sacro Cuore, 00168 Rome, Italy.

Manuela Priolo (M)

Operative Unit of Medical Genetics Bianchi-Melacrino-Morelli Great Metropolitan Hospital, 89133 Reggio Calabria, Italy.

Classifications MeSH