A Rare Case of Fraser Syndrome with Partial Vaginal Agenesis and Its Successful Reconstructive Cosmetic Management: A Case Report.

Cryptophthalmos Fraser syndrome Lotus flap Vaginal agenesis

Journal

Journal of obstetrics and gynaecology of India
ISSN: 0971-9202
Titre abrégé: J Obstet Gynaecol India
Pays: India
ID NLM: 0374763

Informations de publication

Date de publication:
Aug 2022
Historique:
received: 13 07 2020
accepted: 01 02 2021
entrez: 4 8 2022
pubmed: 5 8 2022
medline: 5 8 2022
Statut: ppublish

Résumé

Fraser syndrome is a rare disorder with autosomal recessive inheritance having a wide spectrum of phenotypic appearances. A fourteen-year-old female presented to us with a chief complaint of acute retention of urine without any cyclical abdominal pain with syndromic appearance. She had partial vaginal agenesis which was treated by successful reconstructive surgery by lotus petal flap technique followed by recanalisation. Objective of this report is to highlight the rare disease of Fraser syndrome along with successful rare surgical management.

Identifiants

pubmed: 35923511
doi: 10.1007/s13224-021-01462-5
pii: 1462
pmc: PMC9339435
doi:

Types de publication

Case Reports

Langues

eng

Pagination

349-352

Informations de copyright

© Federation of Obstetric & Gynecological Societies of India 2022.

Références

Fetal Pediatr Pathol. 2008;27(2):99-104
pubmed: 18568997
Oman J Ophthalmol. 2011 May;4(2):87-9
pubmed: 21897626
J Obstet Gynaecol India. 2014 Dec;64(Suppl 1):95-9
pubmed: 25404827
Eur J Obstet Gynecol Reprod Biol. 2017 Oct;217:167-172
pubmed: 28915489

Auteurs

Sambedana Panigrahi (S)

Department of O and G, SCB MCH, Cuttack, Odisha India.

Kirtirekha Mohapatra (K)

Department of O and G, SCB MCH, Cuttack, Odisha India.

Madhusmita Pradhan (M)

Department of O and G, SCB MCH, Cuttack, Odisha India.

Shubhankar Mishra (S)

Department of Neurology, SCB MCH, Cuttack, Odisha India.

Sampriti Samal (S)

Department of Plastic Surgery, SCB MCH, Cuttack, Odisha India.

Classifications MeSH