Endomyocardial fibrosis of the right ventricle in a patient with schistosomiasis: a case report.

Cardiomyopathy Case report Endomyocardial fibrosis Heart failure Hepatopathy Schistosomiasis

Journal

European heart journal. Case reports
ISSN: 2514-2119
Titre abrégé: Eur Heart J Case Rep
Pays: England
ID NLM: 101730741

Informations de publication

Date de publication:
Aug 2022
Historique:
received: 08 02 2022
revised: 11 03 2022
accepted: 22 07 2022
entrez: 11 8 2022
pubmed: 12 8 2022
medline: 12 8 2022
Statut: epublish

Résumé

Endomyocardial fibrosis (EMF) is a rare and underdiagnosed cause of restrictive cardiomyopathy. Its aetiology is not yet defined and could be caused by the influence of different clinical factors that seem to combine with genetic aspects of individuals susceptible to an inflammatory process that leads to formation of fibrosis. We describe a case of a 50-year-old man from the northeastern region of Brazil, where there is high prevalence of schistosomiasis. He presented to our centre with symptoms of right heart failure. The echocardiogram showed normal left ventricular ejection fraction. Right ventricular had normal systolic function but in the apical region was filled with a homogeneous and hypoechoic image causing obliteration and restriction of the apex. The late gadolinium enhancement with cardiac magnetic resonance showed diffuse and heterogeneous subendocardial fibrosis in the right ventricle apex consistent with EMF, but declined endocardiectomy. This report presents an interesting case of EMF and schistosomiasis simultaneously. The hypothesis of parasitosis as a probable cause of EMF was raised by helminth-induced hypereosinophilia. Complementary imaging tests such as magnetic resonance imaging and echocardiography, in addition to clinical and epidemiological suspicion, are essential for its diagnosis. Early surgical resolution becomes crucial for long-term survival.

Sections du résumé

Background UNASSIGNED
Endomyocardial fibrosis (EMF) is a rare and underdiagnosed cause of restrictive cardiomyopathy. Its aetiology is not yet defined and could be caused by the influence of different clinical factors that seem to combine with genetic aspects of individuals susceptible to an inflammatory process that leads to formation of fibrosis.
Case summary UNASSIGNED
We describe a case of a 50-year-old man from the northeastern region of Brazil, where there is high prevalence of schistosomiasis. He presented to our centre with symptoms of right heart failure. The echocardiogram showed normal left ventricular ejection fraction. Right ventricular had normal systolic function but in the apical region was filled with a homogeneous and hypoechoic image causing obliteration and restriction of the apex. The late gadolinium enhancement with cardiac magnetic resonance showed diffuse and heterogeneous subendocardial fibrosis in the right ventricle apex consistent with EMF, but declined endocardiectomy.
Discussion UNASSIGNED
This report presents an interesting case of EMF and schistosomiasis simultaneously. The hypothesis of parasitosis as a probable cause of EMF was raised by helminth-induced hypereosinophilia. Complementary imaging tests such as magnetic resonance imaging and echocardiography, in addition to clinical and epidemiological suspicion, are essential for its diagnosis. Early surgical resolution becomes crucial for long-term survival.

Identifiants

pubmed: 35949701
doi: 10.1093/ehjcr/ytac312
pii: ytac312
pmc: PMC9356724
doi:

Types de publication

Case Reports

Langues

eng

Pagination

ytac312

Informations de copyright

© The Author(s) 2022. Published by Oxford University Press on behalf of the European Society of Cardiology.

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Auteurs

Cristhian Espinoza Romero (C)

Heart failure deparment.Heart Institute (InCor). Hospital das Clinicas da Universidade de São Paulo, São Paulo, Brazil.

Ivna Cunha Vieira Lima (ICV)

Heart failure deparment.Heart Institute (InCor). Hospital das Clinicas da Universidade de São Paulo, São Paulo, Brazil.

Viviane Tiemi Hotta (VT)

Heart failure deparment.Heart Institute (InCor). Hospital das Clinicas da Universidade de São Paulo, São Paulo, Brazil.

Edimar Alcides Bocchi (EA)

Heart failure deparment.Heart Institute (InCor). Hospital das Clinicas da Universidade de São Paulo, São Paulo, Brazil.

Vera Maria Cury Salemi (VMC)

Heart failure deparment.Heart Institute (InCor). Hospital das Clinicas da Universidade de São Paulo, São Paulo, Brazil.

Classifications MeSH