Modulating Mitochondrial DNA Heteroplasmy with Mitochondrially Targeted Endonucleases.

Gene therapy Genetic engineering Oxidative phosphorylation Restriction endonuclease Zinc finger nuclease mitoTALEN

Journal

Annals of biomedical engineering
ISSN: 1573-9686
Titre abrégé: Ann Biomed Eng
Pays: United States
ID NLM: 0361512

Informations de publication

Date de publication:
24 Aug 2022
Historique:
received: 05 05 2022
accepted: 09 08 2022
entrez: 24 8 2022
pubmed: 25 8 2022
medline: 25 8 2022
Statut: aheadofprint

Résumé

Mitochondria, mainly known as energy factories of eukaryotic cells, also exert several additional signaling and metabolic functions and are today recognized as major cellular biosynthetic and signaling hubs. Mitochondria possess their own genome (mitochondrial DNA-mtDNA), that encodes proteins essential for oxidative phosphorylation, and mutations in it are an important contributor to human disease. The mtDNA mutations often exist in heteroplasmic conditions, with both healthy and mutant versions of the mtDNA residing in patients' cells and the level of mutant mtDNA may vary between different tissues and organs and affect the clinical outcome of the disease. Thus, shifting the ratio between healthy and mutant mtDNA in patients' cells provides an intriguing therapeutic option for mtDNA diseases. In this review we describe current strategies for modulating mitochondrial heteroplasmy levels with engineered endonucleases including mitochondrially targeted TALENs and Zinc finger nucleases (ZFNs) and discuss their therapeutic potential. These gene therapy tools could in the future provide therapeutic help both for patients with mitochondrial disease as well as in preventing the transfer of pathogenic mtDNA mutations from a mother to her offspring.

Identifiants

pubmed: 36001180
doi: 10.1007/s10439-022-03051-7
pii: 10.1007/s10439-022-03051-7
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

© 2022. The Author(s).

Références

Ashley, M. V., P. J. Laipis, and W. W. Hauswirth. Rapid segregation of heteroplasmic bovine mitochondria. Nucleic Acids Res. 17:7325, 1989.
pubmed: 2798094 pmcid: 334812 doi: 10.1093/nar/17.18.7325
Bacman, S. R., J. H. K. Kauppila, C. V. Pereira, N. Nissanka, M. Miranda, M. Pinto, S. L. Williams, N. G. Larsson, J. B. Stewart, and C. T. Moraes. MitoTALEN reduces mutant mtDNA load and restores tRNAAla levels in a mouse model of heteroplasmic mtDNA mutation. Nat. Med. 24(11):1696–1700, 2018.
pubmed: 30250143 pmcid: 6942693 doi: 10.1038/s41591-018-0166-8
Bacman, S. R., S. L. Williams, D. Duan, and C. T. Moraes. Manipulation of mtDNA heteroplasmy in all striated muscles of newborn mice by AAV9-mediated delivery of a mitochondria-targeted restriction endonuclease. Gene Ther. 19:1101–1106, 2012.
pubmed: 22130448 doi: 10.1038/gt.2011.196
Bacman, S. R., S. L. Williams, S. Garcia, and C. T. Moraes. Organ-specific shifts in mtDNA heteroplasmy following systemic delivery of a mitochondria-targeted restriction endonuclease. Gene Ther. 17:713–720, 2010.
pubmed: 20220783 pmcid: 3175591 doi: 10.1038/gt.2010.25
Bacman, S. R., S. L. Williams, M. Pinto, S. Peralta, and C. T. Moraes. Specific elimination of mutant mitochondrial genomes in patient-derived cells by mitoTALENs. Nat. Med. 19(9):1111–1113, 2013.
pubmed: 23913125 pmcid: 4153471 doi: 10.1038/nm.3261
Boch, J., H. Scholze, S. Schornack, A. Landgraf, S. Hahn, S. Kay, T. Lahaye, A. Nickstadt, and U. Bonas. Breaking the code of DNA binding specificity of TAL-type III effectors. Science. 326:1509–1512, 2009.
pubmed: 19933107 doi: 10.1126/science.1178811
B1H screens of C2H2-ZF domainsat. http://zf.princeton.edu/b1h/index.html
Cao, L., H. Shitara, T. Horii, Y. Nagao, H. Imai, K. Abe, T. Hara, J. I. Hayashi, and H. Yonekawa. The mitochondrial bottleneck occurs without reduction of mtDNA content in female mouse germ cells. Nat. Genet. 39:386–390, 2007.
pubmed: 17293866 doi: 10.1038/ng1970
Chan, D. C. Mitochondria: dynamic organelles in disease, aging, and development. Cell. 2006. https://doi.org/10.1016/j.cell.2006.06.010 .
doi: 10.1016/j.cell.2006.06.010 pubmed: 17174891
Chandel, N. S. Mitochondria as signaling organelles. BMC Biol. 12:1–7, 2014.
doi: 10.1186/1741-7007-12-1
Cree, L. M., D. C. Samuels, S. C. De Sousa Lopes, H. K. Rajasimha, P. Wonnapinij, J. R. Mann, H. H. M. Dahl, and P. F. Chinnery. A reduction of mitochondrial DNA molecules during embryogenesis explains the rapid segregation of genotypes. Nat. Genet. 40:249–254, 2008.
pubmed: 18223651 doi: 10.1038/ng.2007.63
Deng, D., C. Yan, X. Pan, M. Mahfouz, J. Wang, J. K. Zhu, Y. Shi, and N. Yan. Structural basis for sequence-specific recognition of DNA by TAL effectors. Science. 335:720–723, 2012.
pubmed: 22223738 pmcid: 3586824 doi: 10.1126/science.1215670
DiMauro, S., and G. Davidzon. Mitochondrial DNA and disease. Ann. Med. 2005. https://doi.org/10.1080/07853890510007368 .
doi: 10.1080/07853890510007368 pubmed: 16019721
DiMauro, S., and E. A. Schon. Mitochondrial respiratory-chain diseases. N. Engl. J. Med. 348:2656–2668, 2003.
pubmed: 12826641 doi: 10.1056/NEJMra022567
Doyle, E. L., N. J. Booher, D. S. Standage, D. F. Voytas, V. P. Brendel, J. K. Vandyk, and A. J. Bogdanove. TAL Effector-Nucleotide Targeter (TALE-NT) 2.0: tools for TAL effector design and target prediction. Nucleic Acids Res. 40:W117–W122, 2012.
pubmed: 22693217 pmcid: 3394250 doi: 10.1093/nar/gks608
Druzhyna, N. M., G. L. Wilson, and S. P. LeDoux. Mitochondrial DNA repair in aging and disease. Mech. Ageing Dev. 129:383–390, 2008.
pubmed: 18417187 pmcid: 2666190 doi: 10.1016/j.mad.2008.03.002
Freyer, C., L. M. Cree, A. Mourier, J. B. Stewart, C. Koolmeister, D. Milenkovic, T. Wai, V. I. Floros, E. Hagström, E. E. Chatzidaki, R. J. Wiesner, D. C. Samuels, N. G. Larsson, and P. F. Chinnery. Variation in germ line mtDNA heteroplasmy is determined prenatally but modified during subsequent transmission. Nat. Genet. 44:1282, 2012.
pubmed: 23042113 pmcid: 3492742 doi: 10.1038/ng.2427
Gaj, T., C. A. Gersbach, and C. F. Barbas. ZFN, TALEN, and CRISPR/Cas-based methods for genome engineering. Trends Biotechnol. 31:397–405, 2013.
pubmed: 23664777 pmcid: 3694601 doi: 10.1016/j.tibtech.2013.04.004
Gammage, P. A., E. Gaude, L. Van Haute, P. Rebelo-Guiomar, C. B. Jackson, J. Rorbach, M. L. Pekalski, A. J. Robinson, M. Charpentier, J. P. Concordet, C. Frezza, and M. Minczuk. Near-complete elimination of mutant mtDNA by iterative or dynamic dose-controlled treatment with mtZFNs. Nucleic Acids Res. 44:7804–7816, 2016.
pubmed: 27466392 pmcid: 5027515 doi: 10.1093/nar/gkw676
Gammage, P. A., C. T. Moraes, and M. Minczuk. Mitochondrial genome engineering: the revolution may not be CRISPR-Ized. Trends Genet. 34:101, 2018.
pubmed: 29179920 pmcid: 5783712 doi: 10.1016/j.tig.2017.11.001
Gammage, P. A., J. Rorbach, A. I. Vincent, E. J. Rebar, and M. Minczuk. Mitochondrially targeted ZFNs for selective degradation of pathogenic mitochondrial genomes bearing large-scale deletions or point mutations. EMBO Mol. Med. 6:458, 2014.
pubmed: 24567072 pmcid: 3992073 doi: 10.1002/emmm.201303672
Gammage, P. A., C. Viscomi, M. L. Simard, A. S. H. Costa, E. Gaude, C. A. Powell, L. Van Haute, B. J. McCann, P. Rebelo-Guiomar, R. Cerutti, L. Zhang, E. J. Rebar, M. Zeviani, C. Frezza, J. B. Stewart, and M. Minczuk. Genome editing in mitochondria corrects a pathogenic mtDNA mutation in vivo. Nat. Med. 24:1691–1695, 2018.
pubmed: 30250142 pmcid: 6225988 doi: 10.1038/s41591-018-0165-9
Giles, R. E., H. Blanc, H. M. Cann, and D. C. Wallace. Maternal inheritance of human mitochondrial DNA. Proc. Natl. Acad. Sci. USA. 77:6715–6719, 1980.
pubmed: 6256757 pmcid: 350359 doi: 10.1073/pnas.77.11.6715
Gorman, G. S., P. F. Chinnery, S. DiMauro, M. Hirano, Y. Koga, R. McFarland, A. Suomalainen, D. R. Thorburn, M. Zeviani, and D. M. Turnbull. Mitochondrial diseases. Nat. Rev. Dis. Prim. 2(1):1–22, 2016.
Gray, M. W. Mitochondrial evolution. Cold Spring Harb. Perspect. Biol. 4:a011403, 2012.
pubmed: 22952398 pmcid: 3428767 doi: 10.1101/cshperspect.a011403
Guo, J., X. Chen, Z. Liu, H. Sun, Y. Zhou, Y. Dai, Y. Ma, L. He, X. Qian, J. Wang, J. Zhang, Y. Zhu, J. Zhang, B. Shen, and F. Zhou. DdCBE mediates efficient and inheritable modifications in mouse mitochondrial genome. Mol. Ther. - Nucleic Acids. 27:73–80, 2022.
pubmed: 34938607 doi: 10.1016/j.omtn.2021.11.016
Hamilton, G. The mitochondria mystery. Nature. 525:444–446, 2015.
pubmed: 26399812 doi: 10.1038/525444a
Hashimoto, M., S. R. Bacman, S. Peralta, M. J. Falk, A. Chomyn, D. C. Chan, S. L. Williams, and C. T. Moraes. MitoTALEN: a general approach to reduce mutant mtDNA loads and restore oxidative phosphorylation function in mitochondrial diseases. Mol. Ther. 23:1592–1599, 2015.
pubmed: 26159306 pmcid: 4817924 doi: 10.1038/mt.2015.126
Herrmann, J. M., and W. Neupert. Protein transport into mitochondria. Curr. Opin. Microbiol. 3:210–214, 2000.
pubmed: 10744987 doi: 10.1016/S1369-5274(00)00077-1
Holt, I. J., A. E. Harding, and J. A. Morgan-Hughes. Deletions of muscle mitochondrial DNA in patients with mitochondrial myopathies. Nature. 331(6158):717–719, 1988.
pubmed: 2830540 doi: 10.1038/331717a0
Hoy, M. A. Molecular systematics and the evolution of arthropods. Insect Mol. Genet. 2013. https://doi.org/10.1016/B978-0-12-415874-0.00012-3 .
doi: 10.1016/B978-0-12-415874-0.00012-3
Jackson, C. B., D. M. Turnbull, M. Minczuk, and P. A. Gammage. Therapeutic manipulation of mtDNA Heteroplasmy: A Shifting Perspective. Trends Mol. Med. 26:698–709, 2020.
pubmed: 32589937 doi: 10.1016/j.molmed.2020.02.006
Katajisto, P., J. Döhla, C. L. Chaffer, N. Pentinmikko, N. Marjanovic, S. Iqbal, R. Zoncu, W. Chen, R. A. Weinberg, and D. M. Sabatini. Asymmetric apportioning of aged mitochondria between daughter cells is required for stemness. Science. 348:340–343, 2015.
pubmed: 25837514 pmcid: 4405120 doi: 10.1126/science.1260384
Kim, C. A., and J. M. Berg. A 2.2 Å resolution crystal structure of a designed zinc finger protein bound to DNA. Nat. Struct. Biol. 3(11):940–945, 1996.
pubmed: 8901872 doi: 10.1038/nsb1196-940
Lagouge, M., and N. G. Larsson. The role of mitochondrial DNA mutations and free radicals in disease and ageing. J. Intern. Med. 273:529–543, 2013.
pubmed: 23432181 pmcid: 3675642 doi: 10.1111/joim.12055
Lee, H., S. Lee, G. Baek, A. Kim, B. C. Kang, H. Seo, and J. S. Kim. Mitochondrial DNA editing in mice with DddA-TALE fusion deaminases. Nat. Commun. 12(1):1–6, 2021.
doi: 10.1038/s41467-020-20314-w
Lightowlers, R. N., P. F. Chinnery, D. M. Turnbull, N. Howell, and D. M. Turnbuu. Mammalian mitochondrial genetics: heredity, heteroplasmy and disease. Trends Genet. 13:450–455, 1997.
pubmed: 9385842 doi: 10.1016/S0168-9525(97)01266-3
Liu, X., C. N. Kim, J. Yang, R. Jemmerson, and X. Wang. Induction of apoptotic program in cell-free extracts: requirement for dATP and cytochrome c. Cell. 86:147–157, 1996.
pubmed: 8689682 doi: 10.1016/S0092-8674(00)80085-9
Mani, M., K. Kandavelou, F. J. Dy, S. Durai, and S. Chandrasegaran. Design, engineering, and characterization of zinc finger nucleases. Biochem. Biophys. Res. Commun. 335:447–457, 2005.
pubmed: 16084494 doi: 10.1016/j.bbrc.2005.07.089
McCully, J. D., D. B. Cowan, S. M. Emani, and P. J. del Nido. Mitochondrial transplantation: from animal models to clinical use in humans. Mitochondrion. 2017. https://doi.org/10.1016/j.mito.2017.03.004 .
doi: 10.1016/j.mito.2017.03.004 pubmed: 28342934
Minczuk, M., M. A. Papworth, P. Kolasinska, M. P. Murphy, and A. Klug. Sequence-specific modification of mitochondrial DNA using a chimeric zinc finger methylase. Proc. Natl. Acad. Sci. USA. 103:19689, 2006.
pubmed: 17170133 pmcid: 1750892 doi: 10.1073/pnas.0609502103
Minczuk, M., M. A. Papworth, J. C. Miller, M. P. Murphy, and A. Klug. Development of a single-chain, quasi-dimeric zinc-finger nuclease for the selective degradation of mutated human mitochondrial DNA. Nucleic Acids Res. 36:3926–3938, 2008.
pubmed: 18511461 pmcid: 2475635 doi: 10.1093/nar/gkn313
Mingozzi, F., and K. A. High. Overcoming the Host Immune Response to Adeno-Associated Virus Gene Delivery Vectors: The Race Between Clearance, Tolerance, Neutralization, and Escape. Annu. Rev. Virol. 4:511–534, 2017.
pubmed: 28961410 doi: 10.1146/annurev-virology-101416-041936
Mok, B. Y., M. H. de Moraes, J. Zeng, D. E. Bosch, A. V. Kotrys, A. Raguram, F. S. Hsu, M. C. Radey, S. B. Peterson, V. K. Mootha, J. D. Mougous, and D. R. Liu. A bacterial cytidine deaminase toxin enables CRISPR-free mitochondrial base editing. Nature. 583(7817):631–637, 2020.
pubmed: 32641830 pmcid: 7381381 doi: 10.1038/s41586-020-2477-4
Moretton, A., F. Morel, B. Macao, P. Lachaume, L. Ishak, M. Lefebvre, I. Garreau-Balandier, P. Vernet, M. Falkenberg, and G. Farge. Selective mitochondrial DNA degradation following double-strand breaks. PLoS ONE. 12:e0176795, 2017.
pubmed: 28453550 pmcid: 5409072 doi: 10.1371/journal.pone.0176795
Moscou, M. J., and A. J. Bogdanove. A simple cipher governs DNA recognition by TAL effectors. Science. 326:1501, 2009.
pubmed: 19933106 doi: 10.1126/science.1178817
Nissanka, N., and C. T. Moraes. Mitochondrial DNA heteroplasmy in disease and targeted nuclease-based therapeutic approaches. EMBO Rep. 21:e49612, 2020.
pubmed: 32073748 pmcid: 7054667 doi: 10.15252/embr.201949612
Park, C. B., and N. G. Larsson. Mitochondrial DNA mutations in disease and aging. J. Cell Biol. 193:809–818, 2011.
pubmed: 21606204 pmcid: 3105550 doi: 10.1083/jcb.201010024
Peeva, V., D. Blei, G. Trombly, S. Corsi, M. J. Szukszto, P. Rebelo-Guiomar, P. A. Gammage, A. P. Kudin, C. Becker, J. Altmüller, M. Minczuk, G. Zsurka, and W. S. Kunz. Linear mitochondrial DNA is rapidly degraded by components of the replication machinery. Nat. Commun. 9(1):1–11, 2018.
doi: 10.1038/s41467-018-04131-w
Pereira, C. V., S. R. Bacman, T. Arguello, U. Zekonyte, S. L. Williams, D. R. Edgell, and C. T. Moraes. mitoTev-TALE: a monomeric DNA editing enzyme to reduce mutant mitochondrial DNA levels. EMBO Mol. Med. 10:e8084, 2018.
pubmed: 30012581 pmcid: 6127889 doi: 10.15252/emmm.201708084
Persikov, A. V., J. L. Wetzel, E. F. Rowland, B. L. Oakes, D. J. Xu, M. Singh, and M. B. Noyes. A systematic survey of the Cys2His2 zinc finger DNA-binding landscape. Nucleic Acids Res. 43:1965–1984, 2015.
pubmed: 25593323 pmcid: 4330361 doi: 10.1093/nar/gku1395
Pingoud, A., G. G. Wilson, and W. Wende. Type II restriction endonucleases—a historical perspective and more. Nucleic Acids Res. 42:7489–7527, 2014.
pubmed: 24878924 pmcid: 4081073 doi: 10.1093/nar/gku447
Poulton, J., M. R. Chiaratti, F. V. Meirelles, S. Kennedy, D. Wells, and I. J. Holt. Transmission of mitochondrial DNA diseases and ways to prevent them. PLoS Genet. 6:e1001066, 2010.
pubmed: 20711358 pmcid: 2920841 doi: 10.1371/journal.pgen.1001066
Rahman, S., J. Poulton, D. Marchington, and A. Suomalainen. Decrease of 3243 A–>G mtDNA mutation from blood in MELAS syndrome: a longitudinal study. Am. J. Hum. Genet. 68:238–240, 2001.
pubmed: 11085913 doi: 10.1086/316930
Reddy, P., A. Ocampo, K. Suzuki, J. Luo, S. R. Bacman, S. L. Williams, A. Sugawara, D. Okamura, Y. Tsunekawa, J. Wu, D. Lam, X. Xiong, N. Montserrat, C. R. Esteban, G. H. Liu, I. Sancho-Martinez, D. Manau, S. Civico, F. Cardellach, M. Del Mar O’Callaghan, J. Campistol, H. Zhao, J. M. Campistol, C. T. Moraes, and J. C. Izpisua Belmonte. Selective elimination of mitochondrial mutations in the germline by genome editing. Cell. 161:459–469, 2015.
pubmed: 25910206 pmcid: 4505837 doi: 10.1016/j.cell.2015.03.051
Rossignol, R., B. Faustin, C. Rocher, M. Malgat, J. P. Mazat, and T. Letellier. Mitochondrial threshold effects. Biochem. J. 370:751–762, 2003.
pubmed: 12467494 pmcid: 1223225 doi: 10.1042/bj20021594
Sallevelt, S. C. E. H., J. C. F. M. Dreesen, M. Drüsedau, S. Spierts, E. Coonen, F. H. J. van Tienen, R. J. T. van Golde, I. F. M. de Coo, J. P. M. Geraedts, C. E. M. de Die-Smulders, and H. J. M. Smeets. Preimplantation genetic diagnosis in mitochondrial DNA disorders: challenge and success. J. Med. Genet. 50:125–132, 2013.
pubmed: 23339111 doi: 10.1136/jmedgenet-2012-101172
Santorelli, F. M., K. Tanji, S. Shanske, and S. DiMauro. Heterogeneous clinical presentation of the mtDNA NARP/T8993G mutation. Neurology. 49:270–273, 1997.
pubmed: 9222207 doi: 10.1212/WNL.49.1.270
Shokolenko, I. N., and M. F. Alexeyev. Mitochondrial DNA: a disposable genome? Biochim. Biophys. Acta. 1852:1805, 2015.
pubmed: 26071375 pmcid: 4523420 doi: 10.1016/j.bbadis.2015.05.016
Shoubridge, E. A., and T. Wai. Mitochondrial DNA and the mammalian oocyte. Curr. Top. Dev. Biol. 77:87–111, 2007.
pubmed: 17222701 doi: 10.1016/S0070-2153(06)77004-1
Skladal, D., J. Halliday, and D. R. Thorburn. Minimum birth prevalence of mitochondrial respiratory chain disorders in children. Brain. 126:1905–1912, 2003.
pubmed: 12805096 doi: 10.1093/brain/awg170
Smith, J., M. Bibikova, F. G. Whitby, A. R. Reddy, S. Chandrasegaran, and D. Carroll. Requirements for double-strand cleavage by chimeric restriction enzymes with zinc finger DNA-recognition domains. Nucleic Acids Res. 28:3361, 2000.
pubmed: 10954606 pmcid: 110700 doi: 10.1093/nar/28.17.3361
Spinelli, J. B., and M. C. Haigis. The multifaceted contributions of mitochondria to cellular metabolism. Nat. Cell Biol. 20(7):745–754, 2018.
pubmed: 29950572 pmcid: 6541229 doi: 10.1038/s41556-018-0124-1
Suomalainen, A., and B. J. Battersby. Mitochondrial diseases: the contribution of organelle stress responses to pathology. Nat. Rev. Mol. Cell Biol. 19(2):77–92, 2017.
pubmed: 28792006 doi: 10.1038/nrm.2017.66
Szczesny, R. J., M. S. Hejnowicz, K. Steczkiewicz, A. Muszewska, L. S. Borowski, K. Ginalski, and A. Dziembowski. Identification of a novel human mitochondrial endo-/exonuclease Ddk1/c20orf72 necessary for maintenance of proper 7S DNA levels. Nucleic Acids Res. 41:3144, 2013.
pubmed: 23358826 pmcid: 3597694 doi: 10.1093/nar/gkt029
Taylor, R. W., and D. M. Turnbull. Mitochondrial DNA mutations in human disease. Nat. Rev. Genet. 6:389–402, 2005.
pubmed: 15861210 pmcid: 1762815 doi: 10.1038/nrg1606
Tools | TAL Effector Nucleotide Targeter 2.0at. https://tale-nt.cac.cornell.edu/
Tuppen, H. A. L., E. L. Blakely, D. M. Turnbull, and R. W. Taylor. Mitochondrial DNA mutations and human disease. Biochim. Biophys. Acta – Bioenerg. 1797:113–128, 2010.
doi: 10.1016/j.bbabio.2009.09.005
Wallace, D. C. A mitochondrial paradigm of metabolic and degenerative diseases, aging, and cancer: a dawn for evolutionary medicine. Annu. Rev. Genet. 39:359, 2005.
pubmed: 16285865 pmcid: 2821041 doi: 10.1146/annurev.genet.39.110304.095751
Wallace, D. C., G. Singh, M. T. Lott, J. A. Hodge, T. G. Schurr, A. M. S. Lezza, L. J. Elsas, and E. K. Nikoskelainen. Mitochondrial DNA mutation associated with Leber’s hereditary optic neuropathy. Science. 242:1427–1430, 1988.
pubmed: 3201231 doi: 10.1126/science.3201231
Wang, D., P. W. L. Tai, and G. Gao. Adeno-associated virus vector as a platform for gene therapy delivery. Nat. Rev. Drug Discov. 18:358–378, 2019.
pubmed: 30710128 pmcid: 6927556 doi: 10.1038/s41573-019-0012-9
Wanrooij, S., and M. Falkenberg. The human mitochondrial replication fork in health and disease. Biochim. Biophys. Acta. 1797:1378–1388, 2010.
pubmed: 20417176 doi: 10.1016/j.bbabio.2010.04.015
Wei, Y., Z. Li, K. Xu, H. Feng, L. Xie, D. Li, Z. Zuo, M. Zhang, C. Xu, H. Yang, and E. Zuo. Mitochondrial base editor DdCBE causes substantial DNA off-target editing in nuclear genome of embryos. Cell Discov. 8(1):1–4, 2022.
Yakes, F. M., and B. Van Houten. Mitochondrial DNA damage is more extensive and persists longer than nuclear DNA damage in human cells following oxidative stress. Proc. Natl. Acad. Sci. USA. 94:514–519, 1997.
pubmed: 9012815 pmcid: 19544 doi: 10.1073/pnas.94.2.514
Yamada, Y., M. Ito, M. Arai, M. Hibino, T. Tsujioka, and H. Harashima. Challenges in promoting mitochondrial transplantation therapy. Int. J. Mol. Sci. 2020. https://doi.org/10.3390/ijms21176365 .
doi: 10.3390/ijms21176365 pubmed: 33327477 pmcid: 7764951
Yang, X., J. Jiang, Z. Li, J. Liang, and Y. Xiang. Strategies for mitochondrial gene editing. Comput. Struct. Biotechnol. J. 2021. https://doi.org/10.1016/j.csbj.2021.06.003 .
doi: 10.1016/j.csbj.2021.06.003 pubmed: 35035786 pmcid: 8733169
Yang, Y., H. Wu, X. Kang, Y. Liang, T. Lan, T. Li, T. Tan, J. Peng, Q. Zhang, G. An, Y. Liu, Q. Yu, Z. Ma, Y. Lian, B. S. Soh, Q. Chen, P. Liu, Y. Chen, X. Sun, R. Li, X. Zhen, P. Liu, Y. Yu, X. Li, and Y. Fan. Targeted elimination of mutant mitochondrial DNA in MELAS-iPSCs by mitoTALENs. Protein Cell. 9:283–297, 2018.
pubmed: 29318513 pmcid: 5829275 doi: 10.1007/s13238-017-0499-y
Zekonyte, U., S. R. Bacman, J. Smith, W. Shoop, C. V. Pereira, G. Tomberlin, J. Stewart, D. Jantz, and C. T. Moraes. Mitochondrial targeted meganuclease as a platform to eliminate mutant mtDNA in vivo. Nat. Commun. 12:1–11, 2021.
doi: 10.1038/s41467-021-23561-7
Zhang, H., S. P. Burr, and P. F. Chinnery. The mitochondrial DNA genetic bottleneck: inheritance and beyond. Essays Biochem. 62:225–234, 2018.
pubmed: 29880721 doi: 10.1042/EBC20170096

Auteurs

Nikita Mikhailov (N)

A.I.Virtanen Institute for Molecular Sciences, University of Eastern Finland, 70211, Kuopio, Finland.

Riikka H Hämäläinen (RH)

A.I.Virtanen Institute for Molecular Sciences, University of Eastern Finland, 70211, Kuopio, Finland. riikka.martikainen@uef.fi.

Classifications MeSH