Mutational and splicing landscape in a cohort of 43,000 patients tested for hereditary cancer.


Journal

NPJ genomic medicine
ISSN: 2056-7944
Titre abrégé: NPJ Genom Med
Pays: England
ID NLM: 101685193

Informations de publication

Date de publication:
25 Aug 2022
Historique:
received: 06 01 2022
accepted: 10 08 2022
entrez: 25 8 2022
pubmed: 26 8 2022
medline: 26 8 2022
Statut: epublish

Résumé

DNA germline genetic testing can identify individuals with cancer susceptibility. However, DNA sequencing alone is limited in its detection and classification of mRNA splicing variants, particularly those located far from coding sequences. Here we address the limitations of splicing variant identification and interpretation by pairing DNA and RNA sequencing and describe the mutational and splicing landscape in a clinical cohort of 43,524 individuals undergoing genetic testing for hereditary cancer predisposition.

Identifiants

pubmed: 36008414
doi: 10.1038/s41525-022-00323-y
pii: 10.1038/s41525-022-00323-y
pmc: PMC9411123
doi:

Types de publication

Journal Article

Langues

eng

Pagination

49

Informations de copyright

© 2022. The Author(s).

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Auteurs

Carolyn Horton (C)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Ashley Cass (A)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Blair R Conner (BR)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Lily Hoang (L)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Heather Zimmermann (H)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Nelly Abualkheir (N)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

David Burks (D)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Dajun Qian (D)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Bhuvan Molparia (B)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Huy Vuong (H)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Holly LaDuca (H)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Jessica Grzybowski (J)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Kate Durda (K)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Robert Pilarski (R)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Jessica Profato (J)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.

Katherine Clayback (K)

Roswell Park Comprehensive Cancer Center, 665 Elm St, Buffalo, NY, 14203, USA.

Martin Mahoney (M)

Roswell Park Comprehensive Cancer Center, 665 Elm St, Buffalo, NY, 14203, USA.

Courtney Schroeder (C)

Indiana University School of Medicine, 975 W. Walnut Street, IB 130, Indianapolis, IN, 46202, USA.

Wilfredo Torres-Martinez (W)

Indiana University School of Medicine, 975 W. Walnut Street, IB 130, Indianapolis, IN, 46202, USA.

Aaron Elliott (A)

Realm IDx. One Enterprise, Aliso Viejo, CA, 92656, USA.

Elizabeth C Chao (EC)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA.
University of California, Irvine, School of Medicine, 1001 Health Sciences Rd, Irvine, CA, 92617, USA.

Rachid Karam (R)

Ambry Genetics. One Enterprise, Aliso Viejo, CA, 92656, USA. rkaram@ambrygen.com.

Classifications MeSH