Klippel Trenaunay syndrome in a 3-year-old: A case report.

Case report Klippel Trenaunay syndrome Port-wine stain Sclerotherapy Varicose veins Vascular malformations

Journal

International journal of surgery case reports
ISSN: 2210-2612
Titre abrégé: Int J Surg Case Rep
Pays: Netherlands
ID NLM: 101529872

Informations de publication

Date de publication:
Oct 2022
Historique:
received: 13 08 2022
revised: 13 09 2022
accepted: 14 09 2022
pubmed: 29 9 2022
medline: 29 9 2022
entrez: 28 9 2022
Statut: ppublish

Résumé

Klippel-Trenaunay syndrome (KTS) is characterized by a triad of port-wine stain, varicose veins and soft tissue or bony hypertrophy of lower limb. Varicose veins in Klippel Trenaunay syndrome are mostly distributed in the lateral aspect of the lower limb. The exact etiology of KTS is not known, and the treatment usually starts with conservative management- limb elevation, compression stockings and physiotherapy. However, some cases are severe enough to warrant surgical management. Here we present a case of a 3-year-old male child with clinical features suggestive of Klippel Trenaunay Syndrome managed successfully with sclerotherapy of persistent lateral marginal vein of servelle. At one month follow-up the vein was sclerosed and there was a significant reduction in varicosities of leg. Starting treatment of varicose veins in Klippel Trenaunay Syndrome in children is effective in preventing long-term complications in adults. Thus, treating venous malformation with sclerotherapy is warranted in early childhood to prevent venous hypertension and chronic venous insufficiency. Varicose veins in KT syndrome can be managed successfully by sclerotherapy of lateral marginal vein of servelle resulting in significant reduction in varicosities of leg.

Identifiants

pubmed: 36170793
pii: S2210-2612(22)00919-1
doi: 10.1016/j.ijscr.2022.107673
pmc: PMC9568750
pii:
doi:

Types de publication

Case Reports

Langues

eng

Pagination

107673

Informations de copyright

Copyright © 2022 The Authors. Published by Elsevier Ltd.. All rights reserved.

Déclaration de conflit d'intérêts

Declaration of competing interest None.

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Auteurs

Robin Man Karmacharya (RM)

Cardiothoracic and Vascular Surgery Unit, Department of Surgery, Kathmandu University School of Medical Sciences, Dhulikhel, Kavre, Nepal.

Satish Vaidya (S)

Cardiothoracic and Vascular Surgery Unit, Department of Surgery, Kathmandu University School of Medical Sciences, Dhulikhel, Kavre, Nepal.

Binay Yadav (B)

Cardiothoracic and Vascular Surgery Unit, Department of Surgery, Kathmandu University School of Medical Sciences, Dhulikhel, Kavre, Nepal. Electronic address: binayyadav98@gmail.com.

Sahasra Joshi (S)

Kathmandu University School of Medical Sciences, Dhulikhel, Kavre, Nepal.

Diwas Karkee (D)

Kathmandu University School of Medical Sciences, Dhulikhel, Kavre, Nepal.

Sujita Marasini (S)

Kathmandu University School of Medical Sciences, Dhulikhel, Kavre, Nepal.

Sadiksha Khadka (S)

Kathmandu University School of Medical Sciences, Dhulikhel, Kavre, Nepal.

Swechha Bhatt (S)

Kathmandu University School of Medical Sciences, Dhulikhel, Kavre, Nepal.

Classifications MeSH