Genome-wide association study in patients with posterior urethral valves.

BMP7 PCDH9 SALL1 genome wide association study lower urinary tract obstruction obstructive uropathy posterior urethral valves

Journal

Frontiers in pediatrics
ISSN: 2296-2360
Titre abrégé: Front Pediatr
Pays: Switzerland
ID NLM: 101615492

Informations de publication

Date de publication:
2022
Historique:
received: 07 07 2022
accepted: 19 08 2022
entrez: 14 10 2022
pubmed: 15 10 2022
medline: 15 10 2022
Statut: epublish

Résumé

Congenital lower urinary tract obstructions (LUTO) are most often caused by posterior urethral valves (PUV), a male limited anatomical obstruction of the urethra affecting 1 in 4,000 male live births. Little is known about the genetic background of PUV. Here, we report the largest genome-wide association study (GWAS) for PUV in 4 cohorts of patients and controls. The final meta-analysis included 756 patients and 4,823 ethnicity matched controls and comprised 5,754,208 variants that were genotyped or imputed and passed quality control in all 4 cohorts. No genome-wide significant locus was identified, but 33 variants showed suggestive significance (

Identifiants

pubmed: 36238604
doi: 10.3389/fped.2022.988374
pmc: PMC9552614
doi:

Types de publication

Journal Article

Langues

eng

Pagination

988374

Informations de copyright

Copyright © 2022 van der Zanden, Maj, Borisov, van Rooij, Quaedackers, Steffens, Schierbaum, Schneider, Waffenschmidt, Kiemeney, de Wall, Heilmann, Hofmann, Gehlen, Schumacher, Szczepanska, Taranta-Janusz, Kroll, Krzemien, Szmigielska, Schreuder, Weber, Zaniew, Roeleveld, Reutter, Feitz and Hilger.

Déclaration de conflit d'intérêts

Author SH was employed by Life&Brain GmbH. The remaining authors declare that the research was conducted in the absence of any commercial or financial relationships that could be construed as a potential conflict of interest.

Références

Am J Perinatol. 1994 Jan;11(1):37-9
pubmed: 8155208
Pediatr Nephrol. 2015 Mar;30(3):487-95
pubmed: 25270717
J Pediatr Urol. 2010 Dec;6(6):560-6
pubmed: 20149750
Nat Genet. 2011 Jan;43(1):48-50
pubmed: 21113153
PLoS One. 2016 Jul 15;11(7):e0158977
pubmed: 27420727
Genes (Basel). 2019 Dec 07;10(12):
pubmed: 31817908
Pediatr Nephrol. 2000 Jan;14(1):25-8
pubmed: 10654325
Nature. 2015 Oct 1;526(7571):68-74
pubmed: 26432245
Am J Med Genet A. 2016 Mar;170(3):622-33
pubmed: 26663319
Cell. 2020 Sep 3;182(5):1214-1231.e11
pubmed: 32888494
Nature. 2013 Mar 28;495(7442):467-73
pubmed: 23455423
Bioinformatics. 2010 Nov 15;26(22):2867-73
pubmed: 20926424
Gene Expr Patterns. 2009 Apr;9(4):224-30
pubmed: 19159697
Sci Rep. 2017 Feb 08;7:42170
pubmed: 28176844
Am J Hum Genet. 2019 May 2;104(5):994-1006
pubmed: 31051115
Nucleic Acids Res. 2019 Jan 8;47(D1):D711-D715
pubmed: 30357387
Am Heart J. 2002 Aug;144(2):212-8
pubmed: 12177636
PLoS Genet. 2009 Jun;5(6):e1000529
pubmed: 19543373
Birth Defects Res A Clin Mol Teratol. 2016 Aug;106(8):675-84
pubmed: 27150573
Birth Defects Res A Clin Mol Teratol. 2008 Apr;82(4):232-5
pubmed: 18240166
Genome Res. 2012 Sep;22(9):1790-7
pubmed: 22955989
Int J Epidemiol. 2017 Aug 1;46(4):1099-1100j
pubmed: 28082374
Genomics. 1998 Oct 1;53(1):81-9
pubmed: 9787079
J Pediatr Surg. 2019 Feb;54(2):318-321
pubmed: 30528204
Nat Commun. 2019 Apr 23;10(1):1891
pubmed: 31015401
J Pediatr. 1978 Aug;93(2):270-3
pubmed: 671168
Genes Dev. 1997 May 15;11(10):1207-25
pubmed: 9171367
Low Urin Tract Symptoms. 2019 Apr;11(2):O85-O88
pubmed: 29664229
Am J Med Genet A. 2012 Mar;158A(3):533-40
pubmed: 22308078
Matern Health Neonatol Perinatol. 2015 Nov 18;1:26
pubmed: 27057343
Am J Hum Genet. 2013 Oct 3;93(4):687-96
pubmed: 24094745

Auteurs

Loes F M van der Zanden (LFM)

Department for Health Evidence, Radboud Institute for Health Sciences, Radboud University Medical Center, Nijmegen, Netherlands.

Carlo Maj (C)

Institute for Genomic Statistics and Bioinformatics, Medical Faculty, University of Bonn, Bonn, Germany.

Oleg Borisov (O)

Institute for Genomic Statistics and Bioinformatics, Medical Faculty, University of Bonn, Bonn, Germany.

Iris A L M van Rooij (IALM)

Department for Health Evidence, Radboud Institute for Health Sciences, Radboud University Medical Center, Nijmegen, Netherlands.

Josine S L T Quaedackers (JSLT)

Department of Urology, University Medical Center Groningen, Groningen, Netherlands.

Martijn Steffens (M)

Department of Urology, Isala, Zwolle, Netherlands.

Luca Schierbaum (L)

Institute of Human Genetics, School of Medicine and University Hospital Bonn, University of Bonn, Bonn, Germany.

Sophia Schneider (S)

Institute of Human Genetics, School of Medicine and University Hospital Bonn, University of Bonn, Bonn, Germany.

Lea Waffenschmidt (L)

Institute of Human Genetics, School of Medicine and University Hospital Bonn, University of Bonn, Bonn, Germany.

Lambertus A L M Kiemeney (LALM)

Department for Health Evidence, Radboud Institute for Health Sciences, Radboud University Medical Center, Nijmegen, Netherlands.

Liesbeth L L de Wall (LLL)

Division of Pediatric Urology, Department of Urology, Radboud Institute for Molecular Life Sciences, Radboudumc Amalia Children's Hospital, Nijmegen, Netherlands.

Stefanie Heilmann (S)

Institute of Human Genetics, School of Medicine and University Hospital Bonn, University of Bonn, Bonn, Germany.

Aybike Hofmann (A)

Department of Pediatric Urology, Clinic St. Hedwig, University Medical Center Regensburg, Regensburg, Germany.

Jan Gehlen (J)

Center for Human Genetics, University Hospital of Marburg, Marburg, Germany.

Johannes Schumacher (J)

Center for Human Genetics, University Hospital of Marburg, Marburg, Germany.

Maria Szczepanska (M)

Department of Pediatrics, Faculty of Medical Sciences in Zabrze, Medical University of Silesia in Katowice, Zabrze, Poland.

Katarzyna Taranta-Janusz (K)

Department of Pediatrics and Nephrology, Medical University of Białystok, Białystok, Poland.

Pawel Kroll (P)

Neurourology Unit, Pediatric Surgery and Urology Clinic, Poznań, Poland.

Grazyna Krzemien (G)

Department of Pediatrics and Nephrology, Medical University of Warsaw, Warsaw, Poland.

Agnieszka Szmigielska (A)

Department of Pediatrics and Nephrology, Medical University of Warsaw, Warsaw, Poland.

Michiel F Schreuder (MF)

Department of Pediatric Nephrology, Radboud Institute for Molecular Life Sciences, Radboudumc Amalia Children's Hospital, Nijmegen, Netherlands.

Stefanie Weber (S)

University Children Hospital Marburg, Philipps University Marburg, Marburg, Germany.

Marcin Zaniew (M)

Department of Pediatrics, University of Zielona Góra, Zielona Góra, Poland.

Nel Roeleveld (N)

Department for Health Evidence, Radboud Institute for Health Sciences, Radboud University Medical Center, Nijmegen, Netherlands.

Heiko Reutter (H)

Division of Neonatology and Pediatric Intensive Care, Department of Pediatrics and Adolescent Medicine, Friedrich-Alexander University of Erlangen-Nürnberg, Erlangen, Germany.

Wout F J Feitz (WFJ)

Division of Pediatric Urology, Department of Urology, Radboud Institute for Molecular Life Sciences, Radboudumc Amalia Children's Hospital, Nijmegen, Netherlands.

Alina C Hilger (AC)

Institute of Human Genetics, School of Medicine and University Hospital Bonn, University of Bonn, Bonn, Germany.
Department of Pediatrics and Adolescent Medicine, Friedrich-Alexander University of Erlangen-Nürnberg, Erlangen, Germany.
Research Center on Rare Kidney Diseases, University Hospital Erlangen, Erlangen, Germany.

Classifications MeSH