Metachronous Osteosarcoma, A Differential Diagnosis to be Considered in Children With Osteosarcoma: A Review of Literature and a Case From Our Center.


Journal

Journal of pediatric hematology/oncology
ISSN: 1536-3678
Titre abrégé: J Pediatr Hematol Oncol
Pays: United States
ID NLM: 9505928

Informations de publication

Date de publication:
01 04 2023
Historique:
received: 25 01 2022
accepted: 21 07 2022
pubmed: 18 10 2022
medline: 28 3 2023
entrez: 17 10 2022
Statut: ppublish

Résumé

Metachronous osteosarcomas (MOS) are currently defined as tumors that arise in a way and site unusual for typical metastasis. In this article, we reviewed the recent literature on the occurrence of metachronous osteosarcoma and presented a case from our center. Our patient, a 10-year-old girl, presented with metachronous osteoblastic osteosarcoma of the left distal femur ∼5 years after the successful treatment for osteosarcoma of the right distal femur. Even after several relapses, complete remission (CR) was achieved after the first osteosarcoma and after the metachronous osteosarcoma. The literature research revealed that metachronous osteosarcoma occurs in 3.4 to 5.4% of osteosarcoma patients. The time interval between the diagnosis of the initial osteosarcoma and the metachronous tumor ranged from 0.2 to 14.3 years (median 2.5 y). MOS appears to have differences in localization and metastatic spread, as well as a different survival pattern compared with primary osteosarcoma and osteosarcoma recurrence. Survival (median 4.3 y, range 0 to 24.6 y) appears to be associated with the time interval to diagnosis of MOS. In particular, early MOS (<24 mo after primary diagnosis) seem to have a poorer prognosis. Therefore, the occurrence of MOS at oncological unusual sites should be considered as a differential diagnosis in osteosarcoma survivors.

Identifiants

pubmed: 36251795
doi: 10.1097/MPH.0000000000002560
pii: 00043426-202304000-00001
pmc: PMC10030169
doi:

Types de publication

Review Case Reports Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

105-110

Informations de copyright

Copyright © 2022 The Author(s). Published by Wolters Kluwer Health, Inc.

Déclaration de conflit d'intérêts

The authors declare no conflict of interest.

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Auteurs

Jennifer Gotta (J)

Dr Senckenberg Institute of Pathology.

Konrad Bochennek (K)

Department for Children and Adolescents Medicine, University Hospital Frankfurt, Frankfurt am Main.

Thomas Klingebiel (T)

Department for Children and Adolescents Medicine, University Hospital Frankfurt, Frankfurt am Main.

Stefan Bielack (S)

Center for Pediatric, Adolescent and Women's Medicine, Olgahospital, Department of Pediatrics 5 (Oncology, Hematology, Immunology), Klinikum Stuttgart, Stuttgart, Germany.

Peter J Wild (PJ)

Dr Senckenberg Institute of Pathology.
Frankfurt Institute for Advanced Studies (FIAS).
Wildlab, University Hospital MVZ GmbH, Frankfurt am Main.

Melanie C Demes (MC)

Dr Senckenberg Institute of Pathology.
Wildlab, University Hospital MVZ GmbH, Frankfurt am Main.

Elise Gradhand (E)

Dr Senckenberg Institute of Pathology.

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