Role of ductular reaction and ductular-canalicular junctions in identifying severe primary biliary cholangitis.

AE2, anion exchanger 2 ALP, alkaline phosphatase ALPt0, ALP at diagnosis ALPt12, ALP at 12 months after UDCA therapy ALT, alanine aminotransferase ALTt0, ALT at diagnosis AMA, antimitochondrial antibody ANA, antinuclear antibody AST, aspartate aminotransferase ASTt0, AST at diagnosis BAC, bile acid control BIL, bilirubin BILt0, BIL at diagnosis CA, cholangitis activity CK19, cytokeratin 19 CK7, cytokeratin 7 Cholangiopathy Cholestasis DCJ, ductular–canalicular junction DCJ/d, DCJ per ductule DCJ/pt, DCJ per portal tract DR, ductular reaction EpCAM, epithelial cell adhesion molecule GGT, gamma-glutamyl transferase HA, hepatitis activity HSC, hepatic stellate cell Histology IH, intermediate hepatocyte Liver biopsy MF, myofibroblast Muc-1, mucin 1 PBC, primary biliary cholangitis PCNA, proliferating cell nuclear antigen RT-qPCR, real-time quantitative PCR Regeneration SCTR, secretin receptor SQ, semiquantitative UDCA, ursodeoxycholic acid ULN, upper limit of normal URS, UDCA response score Ursodeoxycholic acid WT, wild type αSMA, α-smooth muscle actin

Journal

JHEP reports : innovation in hepatology
ISSN: 2589-5559
Titre abrégé: JHEP Rep
Pays: Netherlands
ID NLM: 101761237

Informations de publication

Date de publication:
Nov 2022
Historique:
received: 17 02 2022
revised: 21 07 2022
accepted: 03 08 2022
entrez: 21 10 2022
pubmed: 22 10 2022
medline: 22 10 2022
Statut: epublish

Résumé

Primary biliary cholangitis (PBC) is a chronic cholangiopathy characterised by immuno-mediated injury of interlobular bile ducts leading to intrahepatic cholestasis and progressive liver fibrosis. PBC histology is characterised by portal inflammation, progressive fibrosis, ductopenia, and the appearance of the so-called ductular reaction. The aim of the present study was to investigate the pathogenetic relevance of ductular reaction in PBC. Liver biopsies were collected from naïve people with PBC (N = 87). Clinical-serological parameters were obtained at diagnosis and after 1 year of ursodeoxycholic acid (UDCA) treatment. Histological staging was performed on all slides according to multiple scoring systems and criteria for PBC. Liver samples were obtained from Ductular reaction in people with PBC correlated with the disease stage and liver fibrosis, but not with disease activity; an extensive ductular reaction correlated with serum alkaline phosphatase levels at diagnosis, response to UDCA, and individuals' estimated survival, independently from other histological parameters, including disease stage. In people with PBC, reactive ductules were associated with the establishment of junctions with bile canaliculi and with fibrogenetic cell activation. Consistently, in a mouse model of intrahepatic cholestasis, UDCA treatment was effective in reducing ductular reaction and fibrosis and increasing ductular-canalicular junctions. Extensive ductular reaction outlines a severe histologic phenotype in PBC and is associated with an inadequate therapy response and a worse estimated prognosis. In people affected by primary biliary cholangitis (PBC), the histological appearance of extensive ductular reaction identifies individuals at risk of progressive fibrosis. Ductular reaction at diagnosis correlates with the lack of response to first-line therapy with ursodeoxycholic acid and serves to restore ductular-canalicular junctions in people with PBC. Assessing ductular reaction extension at diagnosis may add valuable information for clinicians.

Sections du résumé

Background & Aims UNASSIGNED
Primary biliary cholangitis (PBC) is a chronic cholangiopathy characterised by immuno-mediated injury of interlobular bile ducts leading to intrahepatic cholestasis and progressive liver fibrosis. PBC histology is characterised by portal inflammation, progressive fibrosis, ductopenia, and the appearance of the so-called ductular reaction. The aim of the present study was to investigate the pathogenetic relevance of ductular reaction in PBC.
Methods UNASSIGNED
Liver biopsies were collected from naïve people with PBC (N = 87). Clinical-serological parameters were obtained at diagnosis and after 1 year of ursodeoxycholic acid (UDCA) treatment. Histological staging was performed on all slides according to multiple scoring systems and criteria for PBC. Liver samples were obtained from
Results UNASSIGNED
Ductular reaction in people with PBC correlated with the disease stage and liver fibrosis, but not with disease activity; an extensive ductular reaction correlated with serum alkaline phosphatase levels at diagnosis, response to UDCA, and individuals' estimated survival, independently from other histological parameters, including disease stage. In people with PBC, reactive ductules were associated with the establishment of junctions with bile canaliculi and with fibrogenetic cell activation. Consistently, in a mouse model of intrahepatic cholestasis, UDCA treatment was effective in reducing ductular reaction and fibrosis and increasing ductular-canalicular junctions.
Conclusions UNASSIGNED
Extensive ductular reaction outlines a severe histologic phenotype in PBC and is associated with an inadequate therapy response and a worse estimated prognosis.
Lay summary UNASSIGNED
In people affected by primary biliary cholangitis (PBC), the histological appearance of extensive ductular reaction identifies individuals at risk of progressive fibrosis. Ductular reaction at diagnosis correlates with the lack of response to first-line therapy with ursodeoxycholic acid and serves to restore ductular-canalicular junctions in people with PBC. Assessing ductular reaction extension at diagnosis may add valuable information for clinicians.

Identifiants

pubmed: 36267871
doi: 10.1016/j.jhepr.2022.100556
pii: S2589-5559(22)00128-8
pmc: PMC9576897
doi:

Types de publication

Journal Article

Langues

eng

Pagination

100556

Subventions

Organisme : BLRD VA
ID : I01 BX000574
Pays : United States
Organisme : BLRD VA
ID : IK6 BX004601
Pays : United States

Informations de copyright

© 2022 The Author(s).

Déclaration de conflit d'intérêts

The authors declare that there is no conflict of interest. Please refer to the accompanying ICMJE disclosure forms for further details.

Références

Hepatology. 2004 Jun;39(6):1739-45
pubmed: 15185318
Hepatology. 2019 Jan;69(1):394-419
pubmed: 30070375
Gut. 2018 Sep;67(9):1568-1594
pubmed: 29593060
Biochim Biophys Acta Mol Basis Dis. 2018 Apr;1864(4 Pt B):1308-1318
pubmed: 28965883
Am J Gastroenterol. 2003 May;98(5):1155-8
pubmed: 12809842
Am J Pathol. 2018 Mar;188(3):627-639
pubmed: 29248458
Hepatology. 2017 Mar;65(3):907-919
pubmed: 27880989
Hepatology. 2019 Jan;69(1):420-430
pubmed: 30070383
JHEP Rep. 2021 Jan 27;3(2):100248
pubmed: 33681748
Gut. 2010 Feb;59(2):247-57
pubmed: 19880964
Liver Int. 2020 Nov;40(11):2590-2601
pubmed: 32757367
Gastroenterology. 2014 Feb;146(2):349-56
pubmed: 24315991
Lancet Gastroenterol Hepatol. 2018 Sep;3(9):626-634
pubmed: 30017646
J Hepatol. 2009 Aug;51(2):237-67
pubmed: 19501929
J Hepatol. 2017 Jul;67(1):145-172
pubmed: 28427765
Lancet Gastroenterol Hepatol. 2019 Jun;4(6):445-453
pubmed: 30922873
Cell. 1993 Nov 5;75(3):451-62
pubmed: 8106172
Cell Stem Cell. 2020 Oct 1;27(4):557-573
pubmed: 32971004
J Hepatol. 2020 Aug;73(2):423-440
pubmed: 32330604
Pathol Int. 2010 Mar;60(3):167-74
pubmed: 20403042
Am J Gastroenterol. 1999 Nov;94(11):3310-3
pubmed: 10566735
Hepatology. 2021 Sep;74(3):1496-1508
pubmed: 33724515
Lancet. 2020 Dec 12;396(10266):1915-1926
pubmed: 33308474
Hepatology. 2016 Mar;63(3):930-50
pubmed: 26223498
Virchows Arch A Pathol Anat Histol. 1978 Aug 22;379(2):103-12
pubmed: 150690
J Pathol. 2019 May;248(1):66-76
pubmed: 30584802
J Clin Pathol. 2019 Oct;72(10):669-676
pubmed: 31371396
Int J Mol Sci. 2018 Sep 25;19(10):
pubmed: 30257529
Aliment Pharmacol Ther. 2019 Nov;50(10):1127-1136
pubmed: 31621931

Auteurs

Diletta Overi (D)

Department of Anatomical, Histological, Forensic Medicine and Orthopedic Sciences, Sapienza University of Rome, Rome, Italy.

Guido Carpino (G)

Department of Movement, Human and Health Sciences, Division of Health Sciences, University of Rome 'Foro Italico', Rome, Italy.

Laura Cristoferi (L)

Division of Gastroenterology, Center for Autoimmune Liver Diseases, Department of Medicine and Surgery, University of Milano-Bicocca, Monza, Italy.
European Reference Network on Hepatological Diseases (ERN RARE-LIVER), San Gerardo Hospital, Monza, Italy.

Paolo Onori (P)

Department of Anatomical, Histological, Forensic Medicine and Orthopedic Sciences, Sapienza University of Rome, Rome, Italy.

Lindsey Kennedy (L)

Hepatology and Gastroenterology, Medicine, Indiana University School of Medicine, Indianapolis, IN, USA.
Richard L. Roudebush VA Medical Center, Indianapolis, IN, USA.

Heather Francis (H)

Hepatology and Gastroenterology, Medicine, Indiana University School of Medicine, Indianapolis, IN, USA.
Richard L. Roudebush VA Medical Center, Indianapolis, IN, USA.

Nicola Zucchini (N)

Division of Gastroenterology, Center for Autoimmune Liver Diseases, Department of Medicine and Surgery, University of Milano-Bicocca, Monza, Italy.
European Reference Network on Hepatological Diseases (ERN RARE-LIVER), San Gerardo Hospital, Monza, Italy.

Cristina Rigamonti (C)

Department of Translational Medicine, Università degli Studi del Piemonte Orientale 'A. Avogadro', Novara, Italy.

Mauro Viganò (M)

Division of Hepatology, Ospedale San Giuseppe, University of Milan, Milan, Italy.

Annarosa Floreani (A)

Studiosa Senior, University of Padua, Padua, Italy.
Scientific Consultant, IRCCS Negrar, Verona, Italy.

Daphne D'Amato (D)

Division of Gastroenterology, Center for Autoimmune Liver Diseases, Department of Medicine and Surgery, University of Milano-Bicocca, Monza, Italy.

Alessio Gerussi (A)

Division of Gastroenterology, Center for Autoimmune Liver Diseases, Department of Medicine and Surgery, University of Milano-Bicocca, Monza, Italy.
European Reference Network on Hepatological Diseases (ERN RARE-LIVER), San Gerardo Hospital, Monza, Italy.

Rosanna Venere (R)

Department of Translational and Precision Medicine, Sapienza University of Rome, Rome, Italy.

Gianfranco Alpini (G)

Hepatology and Gastroenterology, Medicine, Indiana University School of Medicine, Indianapolis, IN, USA.
Richard L. Roudebush VA Medical Center, Indianapolis, IN, USA.

Shannon Glaser (S)

Department of Medical Physiology, Texas A&M University College of Medicine, Bryan, TX, USA.

Domenico Alvaro (D)

Department of Translational and Precision Medicine, Sapienza University of Rome, Rome, Italy.

Pietro Invernizzi (P)

Division of Gastroenterology, Center for Autoimmune Liver Diseases, Department of Medicine and Surgery, University of Milano-Bicocca, Monza, Italy.
European Reference Network on Hepatological Diseases (ERN RARE-LIVER), San Gerardo Hospital, Monza, Italy.

Eugenio Gaudio (E)

Department of Anatomical, Histological, Forensic Medicine and Orthopedic Sciences, Sapienza University of Rome, Rome, Italy.

Vincenzo Cardinale (V)

Department of Medico-Surgical Sciences and Biotechnologies, Sapienza University of Rome, Latina, Italy.

Marco Carbone (M)

Division of Gastroenterology, Center for Autoimmune Liver Diseases, Department of Medicine and Surgery, University of Milano-Bicocca, Monza, Italy.
European Reference Network on Hepatological Diseases (ERN RARE-LIVER), San Gerardo Hospital, Monza, Italy.

Classifications MeSH