Different Mechanisms Cause Hypomethylation of Both

11p15.5 imprinted genes cluster DNA methylation defects Silver–Russell syndrome differentially methylated regions imprinting disorders microduplication

Journal

Genes
ISSN: 2073-4425
Titre abrégé: Genes (Basel)
Pays: Switzerland
ID NLM: 101551097

Informations de publication

Date de publication:
16 10 2022
Historique:
received: 10 08 2022
revised: 27 09 2022
accepted: 13 10 2022
entrez: 27 10 2022
pubmed: 28 10 2022
medline: 29 10 2022
Statut: epublish

Résumé

Silver-Russell syndrome is an imprinting disorder characterised by pre- and post-natal growth retardation and several heterogeneous molecular defects affecting different human genomic loci. In the majority of cases, the molecular defect is the loss of methylation (LOM) of the

Identifiants

pubmed: 36292759
pii: genes13101875
doi: 10.3390/genes13101875
pmc: PMC9602374
pii:
doi:

Types de publication

Case Reports Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Références

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Auteurs

Francesco Passaretti (F)

Department of Molecular Medicine and Medical Biotechnology, Università degli Studi di Napoli Federico II, 80131 Naples, Italy.
U.O.C. Medical Genetics, Department of Translational Medical Sciences, A.O.U. Federico II, 80131 Naples, Italy.

Laura Pignata (L)

Department of Environmental Biological and Pharmaceutical Sciences and Technologies (DiSTABiF), Università degli Studi della Campania "Luigi Vanvitelli", 81100 Caserta, Italy.

Giuseppina Vitiello (G)

U.O.C. Medical Genetics, Department of Translational Medical Sciences, A.O.U. Federico II, 80131 Naples, Italy.

Viola Alesi (V)

Laboratory of Medical Genetics, Translational Cytogenomics Research Unit, Bambino Gesù Children Hospital, IRCCS, 00165 Rome, Italy.

Gemma D'Elia (G)

Laboratory of Medical Genetics, Translational Cytogenomics Research Unit, Bambino Gesù Children Hospital, IRCCS, 00165 Rome, Italy.

Francesco Cecere (F)

Department of Environmental Biological and Pharmaceutical Sciences and Technologies (DiSTABiF), Università degli Studi della Campania "Luigi Vanvitelli", 81100 Caserta, Italy.
Institute of Genetics and Biophysics (IGB) "Adriano Buzzati-Traverso", Consiglio Nazionale delle Ricerche (CNR), 80131 Naples, Italy.

Fabio Acquaviva (F)

U.O.S. Medical Genetics, Pediatrics of Chronic and Multifactorial Diseases, A.O.R.N. Santobono-Pausilipon, 80129 Naples, Italy.

Daniele De Brasi (D)

U.O.S. Medical Genetics, Pediatrics of Chronic and Multifactorial Diseases, A.O.R.N. Santobono-Pausilipon, 80129 Naples, Italy.

Antonio Novelli (A)

Laboratory of Medical Genetics, Translational Cytogenomics Research Unit, Bambino Gesù Children Hospital, IRCCS, 00165 Rome, Italy.

Andrea Riccio (A)

Department of Environmental Biological and Pharmaceutical Sciences and Technologies (DiSTABiF), Università degli Studi della Campania "Luigi Vanvitelli", 81100 Caserta, Italy.
Institute of Genetics and Biophysics (IGB) "Adriano Buzzati-Traverso", Consiglio Nazionale delle Ricerche (CNR), 80131 Naples, Italy.

Achille Iolascon (A)

Department of Molecular Medicine and Medical Biotechnology, Università degli Studi di Napoli Federico II, 80131 Naples, Italy.
U.O.C. Medical Genetics, Department of Translational Medical Sciences, A.O.U. Federico II, 80131 Naples, Italy.
CEINGE Advanced Biotechnology, 80131 Naples, Italy.

Flavia Cerrato (F)

Department of Environmental Biological and Pharmaceutical Sciences and Technologies (DiSTABiF), Università degli Studi della Campania "Luigi Vanvitelli", 81100 Caserta, Italy.

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Classifications MeSH