Genome screening, reporting, and genetic counseling for healthy populations.


Journal

Human genetics
ISSN: 1432-1203
Titre abrégé: Hum Genet
Pays: Germany
ID NLM: 7613873

Informations de publication

Date de publication:
Feb 2023
Historique:
received: 05 05 2022
accepted: 16 08 2022
pubmed: 5 11 2022
medline: 15 2 2023
entrez: 4 11 2022
Statut: ppublish

Résumé

Rapid advancements of genome sequencing (GS) technologies have enhanced our understanding of the relationship between genes and human disease. To incorporate genomic information into the practice of medicine, new processes for the analysis, reporting, and communication of GS data are needed. Blood samples were collected from adults with a PCR-confirmed SARS-CoV-2 (COVID-19) diagnosis (target N = 1500). GS was performed. Data were filtered and analyzed using custom pipelines and gene panels. We developed unique patient-facing materials, including an online intake survey, group counseling presentation, and consultation letters in addition to a comprehensive GS report. The final report includes results generated from GS data: (1) monogenic disease risks; (2) carrier status; (3) pharmacogenomic variants; (4) polygenic risk scores for common conditions; (5) HLA genotype; (6) genetic ancestry; (7) blood group; and, (8) COVID-19 viral lineage. Participants complete pre-test genetic counseling and confirm preferences for secondary findings before receiving results. Counseling and referrals are initiated for clinically significant findings. We developed a genetic counseling, reporting, and return of results framework that integrates GS information across multiple areas of human health, presenting possibilities for the clinical application of comprehensive GS data in healthy individuals.

Identifiants

pubmed: 36331656
doi: 10.1007/s00439-022-02480-7
pii: 10.1007/s00439-022-02480-7
pmc: PMC9638226
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

181-192

Subventions

Organisme : CIHR
ID : VR4-172753
Pays : Canada
Organisme : Canadian Institutes of Health Research
ID : VR4-172753
Pays : Canada

Informations de copyright

© 2022. The Author(s), under exclusive licence to Springer-Verlag GmbH Germany, part of Springer Nature.

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Auteurs

Selina Casalino (S)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.

Erika Frangione (E)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.

Monica Chung (M)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.

Georgia MacDonald (G)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.

Sunakshi Chowdhary (S)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.

Chloe Mighton (C)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.
University of Toronto, Toronto, Canada.
Unity Health Toronto, Toronto, Canada.

Hanna Faghfoury (H)

University Health Network, Toronto, Canada.

Yvonne Bombard (Y)

University of Toronto, Toronto, Canada.
Unity Health Toronto, Toronto, Canada.

Lisa Strug (L)

The Hospital for Sick Children, Toronto, Canada.

Trevor J Pugh (TJ)

University Health Network, Toronto, Canada.
Ontario Institute for Cancer Research, Toronto, Canada.

Jared Simpson (J)

Ontario Institute for Cancer Research, Toronto, Canada.

Saranya Arnoldo (S)

University of Toronto, Toronto, Canada.
William Osler Health System, Brampton, Canada.

Navneet Aujla (N)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.

Erin Bearss (E)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.

Alexandra Binnie (A)

William Osler Health System, Brampton, Canada.

Bjug Borgundvaag (B)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
University of Toronto, Toronto, Canada.

Howard Chertkow (H)

Baycrest Health Sciences, Toronto, Canada.

Marc Clausen (M)

Unity Health Toronto, Toronto, Canada.

Marc Dagher (M)

University of Toronto, Toronto, Canada.
Women's College Hospital, Toronto, Canada.

Luke Devine (L)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
University of Toronto, Toronto, Canada.

David Di Iorio (D)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.

Steven Marc Friedman (SM)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
University Health Network, Toronto, Canada.

Chun Yiu Jordan Fung (CYJ)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.

Anne-Claude Gingras (AC)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.
University of Toronto, Toronto, Canada.

Lee W Goneau (LW)

Dynacare Medical Laboratories, Brampton, Canada.

Deepanjali Kaushik (D)

William Osler Health System, Brampton, Canada.

Zeeshan Khan (Z)

Mackenzie Health, Richmond Hill, Canada.

Elisa Lapadula (E)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.

Tiffany Lu (T)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.

Tony Mazzulli (T)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
University of Toronto, Toronto, Canada.

Allison McGeer (A)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.
University of Toronto, Toronto, Canada.

Shelley L McLeod (SL)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
University of Toronto, Toronto, Canada.

Gregory Morgan (G)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada.
University of Toronto, Toronto, Canada.

David Richardson (D)

William Osler Health System, Brampton, Canada.

Harpreet Singh (H)

University of Toronto, Toronto, Canada.

Seth Stern (S)

Mackenzie Health, Richmond Hill, Canada.

Ahmed Taher (A)

University of Toronto, Toronto, Canada.
University Health Network, Toronto, Canada.
Mackenzie Health, Richmond Hill, Canada.

Iris Wong (I)

Mackenzie Health, Richmond Hill, Canada.

Natasha Zarei (N)

Mackenzie Health, Richmond Hill, Canada.

Elena Greenfeld (E)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
University of Toronto, Toronto, Canada.

Limin Hao (L)

Laboratory for Molecular Medicine, Partners Personalized Medicine, Boston, USA.

Matthew Lebo (M)

Laboratory for Molecular Medicine, Partners Personalized Medicine, Boston, USA.
Harvard Medical School & Brigham and Women's Hospital, Boston, USA.

William Lane (W)

Harvard Medical School & Brigham and Women's Hospital, Boston, USA.

Abdul Noor (A)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
University of Toronto, Toronto, Canada.

Jennifer Taher (J)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada.
University of Toronto, Toronto, Canada.

Jordan Lerner-Ellis (J)

Pathology & Laboratory Medicine, Mount Sinai Hospital, Sinai Health, Toronto, ON, Canada. jordan.lerner-ellis@sinaihealth.ca.
Lunenfeld-Tanenbaum Research Institute, Sinai Health, Toronto, Canada. jordan.lerner-ellis@sinaihealth.ca.
University of Toronto, Toronto, Canada. jordan.lerner-ellis@sinaihealth.ca.

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