Coexistence of TEMPI syndrome and leukocytoclastic vasculitis successfully treated with autologous stem cell transplantation.

MGUS angiogenesis erythrocytosis inflammation multiple myeloma

Journal

EJHaem
ISSN: 2688-6146
Titre abrégé: EJHaem
Pays: United States
ID NLM: 101761942

Informations de publication

Date de publication:
Nov 2022
Historique:
received: 26 07 2022
accepted: 18 08 2022
entrez: 5 12 2022
pubmed: 6 12 2022
medline: 6 12 2022
Statut: epublish

Résumé

The TEMPI syndrome is a very rare paraneoplastic syndrome associated with plasma cell dyscrasia and monoclonal gammopathy. First described in 2011, the pathophysiology of TEMPI syndrome is still unknown. Essential for diagnosis is to recognize the five clinical findings: telangiectasias, erythrocytosis and elevated serum erythropoietin, monoclonal gammopathy, perinephric fluid collection, and intrapulmonary shunting. Here we report a case of a woman with the coexistence of TEMPI and leukocytoclastic vasculitis, shedding light on a possible common inflammatory pathway involved in the pathogenesis of the syndrome.

Identifiants

pubmed: 36467823
doi: 10.1002/jha2.561
pii: JHA2561
pmc: PMC9713062
doi:

Types de publication

Case Reports

Langues

eng

Pagination

1385-1387

Informations de copyright

© 2022 The Authors. eJHaem published by British Society for Haematology and John Wiley & Sons Ltd.

Déclaration de conflit d'intérêts

The authors declare they have no conflicts of interest.The authors received no specific funding for this work.

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Auteurs

Davide Nappi (D)

Hematology and Bone Marrow Transplantation Bolzano Hospital Bolzano Italy.

Martina Tauber (M)

Department of Pathology Bolzano Hospital Bolzano Italy.

David Sykes (D)

Massachusetts General Hospital Center for Regenerative Medicine Boston Massachusetts USA.

Classifications MeSH