Ganglioneuroblastoma Presenting as Obstructive Sleep Apnea in a 5-Year-Old Boy.
Journal
The Journal of craniofacial surgery
ISSN: 1536-3732
Titre abrégé: J Craniofac Surg
Pays: United States
ID NLM: 9010410
Informations de publication
Date de publication:
01 May 2023
01 May 2023
Historique:
received:
06
08
2022
accepted:
24
09
2022
medline:
5
5
2023
pubmed:
10
1
2023
entrez:
9
1
2023
Statut:
ppublish
Résumé
The authors present an interesting case of ganglioneuroblastoma, a tumor of the sympathetic chain, presenting as severe obstructive sleep apnea in a healthy 5-year-old boy. The patient's initial polysomnogram demonstrated an apnea-hypopnea index (AHI) of 86 events/hour. He underwent an adenotonsillectomy at an outside hospital and his repeat AHI was still 62. The patient was nonobese and nonsyndromic appearing, which made his incredibly high AHI perplexing. He underwent sleep endoscopy and direct laryngoscopy for further evaluation, which demonstrated a large mass in the left posterior pharynx. He then underwent surgical excision with a resolution of his obstructive sleep apnea.
Identifiants
pubmed: 36617675
doi: 10.1097/SCS.0000000000009155
pii: 00001665-990000000-00513
doi:
Types de publication
Case Reports
Journal Article
Langues
eng
Pagination
e252-e254Informations de copyright
Copyright © 2023 by Mutaz B. Habal, MD.
Déclaration de conflit d'intérêts
The authors report no conflicts of interest.
Références
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Urata S, Yoshida M, Ebihara Y, et al. Surgical management of a giant cervical ganglioneuroma. Auris Nasus Larynx 2013;40:577–580
Okamatsu C, London WB, Naranjo A, et al. Clinicopathological characteristics of ganglioneuroma and ganglioneuroblastoma: a report from the CCG and COG. Pediatr Blood Cancer 2009;53:563–569
McGann EK, Goldberg AM, Lelegren MJ, et al. Primary cervical ganglioneuroblastoma, nodular subtype. Auris Nasus Larynx 2022;49:889–892