Mutated axon guidance gene PLXNB2 sustains growth and invasiveness of stem cells isolated from cancers of unknown primary.


Journal

EMBO molecular medicine
ISSN: 1757-4684
Titre abrégé: EMBO Mol Med
Pays: England
ID NLM: 101487380

Informations de publication

Date de publication:
08 03 2023
Historique:
revised: 28 12 2022
received: 31 03 2022
accepted: 11 01 2023
pubmed: 2 2 2023
medline: 11 3 2023
entrez: 1 2 2023
Statut: ppublish

Résumé

The genetic changes sustaining the development of cancers of unknown primary (CUP) remain elusive. The whole-exome genomic profiling of 14 rigorously selected CUP samples did not reveal specific recurring mutation in known driver genes. However, by comparing the mutational landscape of CUPs with that of most other human tumor types, it emerged a consistent enrichment of changes in genes belonging to the axon guidance KEGG pathway. In particular, G842C mutation of PlexinB2 (PlxnB2) was predicted to be activating. Indeed, knocking down the mutated, but not the wild-type, PlxnB2 in CUP stem cells resulted in the impairment of self-renewal and proliferation in culture, as well as tumorigenic capacity in mice. Conversely, the genetic transfer of G842C-PlxnB2 was sufficient to promote CUP stem cell proliferation and tumorigenesis in mice. Notably, G842C-PlxnB2 expression in CUP cells was associated with basal EGFR phosphorylation, and EGFR blockade impaired the viability of CUP cells reliant on the mutated receptor. Moreover, the mutated PlxnB2 elicited CUP cell invasiveness, blocked by EGFR inhibitor treatment. In sum, we found that a novel activating mutation of the axon guidance gene PLXNB2 sustains proliferative autonomy and confers invasive properties to stem cells isolated from cancers of unknown primary, in EGFR-dependent manner.

Identifiants

pubmed: 36722641
doi: 10.15252/emmm.202216104
pmc: PMC9994481
doi:

Substances chimiques

ErbB Receptors EC 2.7.10.1
PLXNB2 protein, human 0
Plxnb2 protein, mouse 0
Nerve Tissue Proteins 0

Banques de données

GEO
['GSE167473']

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

e16104

Informations de copyright

© 2023 The Authors. Published under the terms of the CC BY 4.0 license.

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Auteurs

Serena Brundu (S)

Candiolo Cancer Institute, FPO-IRCCS, Turin, Italy.

Virginia Napolitano (V)

Department of Life Sciences and Public Health, Università Cattolica del Sacro Cuore, Rome, Italy.

Giulia Franzolin (G)

Candiolo Cancer Institute, FPO-IRCCS, Turin, Italy.

Ettore Lo Cascio (E)

Department of Biotechnological Sciences and Intensive Care, Università Cattolica del Sacro Cuore, Rome, Italy.

Roberta Mastrantonio (R)

Department of Life Sciences and Public Health, Università Cattolica del Sacro Cuore, Rome, Italy.

Gabriele Sardo (G)

Candiolo Cancer Institute, FPO-IRCCS, Turin, Italy.

Eliano Cascardi (E)

Candiolo Cancer Institute, FPO-IRCCS, Turin, Italy.
Department of Medical Sciences, University of Turin, Turin, Italy.

Federica Verginelli (F)

Candiolo Cancer Institute, FPO-IRCCS, Turin, Italy.

Sergio Sarnataro (S)

Telethon Institute of Genetic and Medicine, Pozzuoli, Italy.

Gennaro Gambardella (G)

Telethon Institute of Genetic and Medicine, Pozzuoli, Italy.
Department of Electrical Engineering and Information Technology, University of Naples Federico II, Naples, Italy.

Alberto Pisacane (A)

Candiolo Cancer Institute, FPO-IRCCS, Turin, Italy.

Alessandro Arcovito (A)

Department of Biotechnological Sciences and Intensive Care, Università Cattolica del Sacro Cuore, Rome, Italy.
Fondazione Policlinico Gemelli (FPG) - IRCCS, Rome, Italy.

Carla Boccaccio (C)

Candiolo Cancer Institute, FPO-IRCCS, Turin, Italy.
Department of Oncology, University of Turin, Turin, Italy.

Paolo M Comoglio (PM)

IFOM, FIRC Institute of Molecular Oncology, Milan, Italy.

Enrico Giraudo (E)

Candiolo Cancer Institute, FPO-IRCCS, Turin, Italy.
Department of Science and Drug Technology, University of Turin, Turin, Italy.

Luca Tamagnone (L)

Department of Life Sciences and Public Health, Università Cattolica del Sacro Cuore, Rome, Italy.
Fondazione Policlinico Gemelli (FPG) - IRCCS, Rome, Italy.

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Classifications MeSH