Hemizygous loss of function mutations in

CLCN5 Dent disease chronic kidney disease nephrocalcinosis nephrolithiasis

Journal

Clinical kidney journal
ISSN: 2048-8505
Titre abrégé: Clin Kidney J
Pays: England
ID NLM: 101579321

Informations de publication

Date de publication:
Jan 2023
Historique:
received: 28 03 2022
entrez: 2 2 2023
pubmed: 3 2 2023
medline: 3 2 2023
Statut: epublish

Résumé

Dent disease type 1 is suspected in the presence of a complete phenotype of low molecular weight (LMW) proteinuria, hypercalciuria and at least one of the following: nephrocalcinosis, nephrolithiasis, haematuria, hypophosphatemia or chronic kidney disease (CKD). We present two brothers who presented with CKD alone. In the absence of typical clinical features, further assessment of LMW proteinuria and hypercalciuria was not undertaken. Whole-genome sequencing revealed hemizygous loss of function mutations in chloride voltage-gated channel 5 (

Identifiants

pubmed: 36726441
doi: 10.1093/ckj/sfac127
pii: sfac127
pmc: PMC9871842
doi:

Types de publication

Journal Article

Langues

eng

Pagination

192-194

Informations de copyright

© The Author(s) 2022. Published by Oxford University Press on behalf of the ERA.

Références

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Auteurs

Gary Leggatt (G)

University of Southampton, Southampton, UK.
Wessex Kidney Centre, Portsmouth, UK.

Christine Gast (C)

University of Southampton, Southampton, UK.
Wessex Kidney Centre, Portsmouth, UK.

Rodney D Gilbert (RD)

University of Southampton, Southampton, UK.
Southampton Children's Hospital, Southampton, UK.

Kristin Veighey (K)

University of Southampton, Southampton, UK.
Wessex Kidney Centre, Portsmouth, UK.
University Hospital Southampton NHS Foundation Trust, Southampton, UK.

Tahmina Rahman (T)

Wessex Kidney Centre, Portsmouth, UK.

Sarah Ennis (S)

University of Southampton, Southampton, UK.

Classifications MeSH