Incidence of Isolated Biliary Atresia during the COVID Lockdown in Europe: Results from a Collaborative Project by RARE-Liver.

COVID lockdown European reference network RARE-LIVER biliary atresia epidemiology stringency index

Journal

Journal of clinical medicine
ISSN: 2077-0383
Titre abrégé: J Clin Med
Pays: Switzerland
ID NLM: 101606588

Informations de publication

Date de publication:
18 Jan 2023
Historique:
received: 13 12 2022
revised: 09 01 2023
accepted: 10 01 2023
entrez: 11 2 2023
pubmed: 12 2 2023
medline: 12 2 2023
Statut: epublish

Résumé

Biliary atresia (BA) is a rare cholangiopathy where one of the proposed aetiological mechanisms is an infectious viral trigger. Coronavirus disease-19 (COVID) lockdown restrictions were implemented to reduce the transmission of infections. Strictness of lockdown varied across European countries. This study aimed to investigate if there was an association between strictness of lockdown and change in isolated BA (IBA) incidence in Europe. We approached European centres involved in the European Reference Network RARE-LIVER. We included IBA patients born between 2015 and June 2020. We calculated the number of IBA patients born per centre per month. The Stringency Index (SI) was used as lockdown strictness indicator. The association between percentage change of mean number of IBA patients born per month and the SI was assessed. We included 412 IBA patients from thirteen different centres. The median number of patients per month did not change: 6 (1-15) pre-lockdown and 7 (6-9) during lockdown ( In this European study, a stricter COVID-lockdown was seemingly accompanied by a simultaneous larger decrease in the number of IBA patients born per month in the lockdown. Results should be interpreted with caution due to the assumptions and limitations of the analysis.

Sections du résumé

BACKGROUND BACKGROUND
Biliary atresia (BA) is a rare cholangiopathy where one of the proposed aetiological mechanisms is an infectious viral trigger. Coronavirus disease-19 (COVID) lockdown restrictions were implemented to reduce the transmission of infections. Strictness of lockdown varied across European countries. This study aimed to investigate if there was an association between strictness of lockdown and change in isolated BA (IBA) incidence in Europe.
METHODS METHODS
We approached European centres involved in the European Reference Network RARE-LIVER. We included IBA patients born between 2015 and June 2020. We calculated the number of IBA patients born per centre per month. The Stringency Index (SI) was used as lockdown strictness indicator. The association between percentage change of mean number of IBA patients born per month and the SI was assessed.
RESULTS RESULTS
We included 412 IBA patients from thirteen different centres. The median number of patients per month did not change: 6 (1-15) pre-lockdown and 7 (6-9) during lockdown (
CONCLUSION CONCLUSIONS
In this European study, a stricter COVID-lockdown was seemingly accompanied by a simultaneous larger decrease in the number of IBA patients born per month in the lockdown. Results should be interpreted with caution due to the assumptions and limitations of the analysis.

Identifiants

pubmed: 36769422
pii: jcm12030775
doi: 10.3390/jcm12030775
pmc: PMC9918263
pii:
doi:

Types de publication

Journal Article

Langues

eng

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Auteurs

Mark Nomden (M)

Division of Paediatric Surgery, Department of Surgery, University of Groningen, University Medical Centre Groningen, 9713 GZ Groningen, The Netherlands.
European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.

Naved K Alizai (NK)

Department of Paediatric Surgery & Liver Unit, Leeds General Infirmary, Leeds LS1 3EX, UK.

Pietro Betalli (P)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Department of Paediatric Surgery, ASST Papa Giovanni XXIII, 24127 Bergamo, Italy.

Janneke L M Bruggink (JLM)

Division of Paediatric Surgery, Department of Surgery, University of Groningen, University Medical Centre Groningen, 9713 GZ Groningen, The Netherlands.
European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.

Mara Cananzi (M)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Pediatric Gastroenterology, Digestive Endoscopy, Hepatology and Care of the Child with Liver Transplantation, Department of Women's and Children's Health, University Hospital of Padova, 35128 Padova, Italy.

Vibeke Brix Christensen (VB)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Department of Pediatrics and Adolescent Medicine, Copenhagen University Hospital, Rigshospitalet, DK2100 Copenhagen, Denmark.

Lorenzo D'Antiga (L)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Department of Paediatric Hepatology, Gastroenterology and Transplantation ASST Papa Giovanni XXIII, 24127 Bergamo, Italy.

Mark Davenport (M)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Department of Paediatric Surgery, Kings College Hospital, London SE5 9RS, UK.

Björn Fischler (B)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Paediatric Digestive Diseases, Astrid Lindgren Children's Hospital, CLINTEC, Karolinska Institutet, Karolinska University Hospital, 171 64 Stockholm, Sweden.

Luise Hindemith (L)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Department of Paediatric Surgery, Hannover Medical School, 30625 Hannover, Germany.

Maria Hukkinen (M)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Paediatric Liver and Gut Research Group, Children's Hospital, Helsinki University Hospital, University of Helsinki, 00029 Helsinki, Finland.
Section of Paediatric Surgery, Children's Hospital, Helsinki University Hospital, University of Helsinki, 00029 Helsinki, Finland.

Lars S Johansen (LS)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Department of Pediatric Surgery, Copenhagen University Hospital, Rigshospitalet, DK2100 Copenhagen, Denmark.

Ruben H de Kleine (RH)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Division of Hepatico-Pancreatico-Biliary Surgery and Liver Transplantation, Department of Surgery, University of Groningen, University Medical Centre Groningen, 9713 GZ Groningen, The Netherlands.

Omid Madadi-Sanjani (O)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Department of Paediatric Surgery, Hannover Medical School, 30625 Hannover, Germany.

Evelyn G P Ong (EGP)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
The Liver Unit, Birmingham Children's Hospital, Birmingham B4 6NH, UK.

Mikko P Pakarinen (MP)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Paediatric Liver and Gut Research Group, Children's Hospital, Helsinki University Hospital, University of Helsinki, 00029 Helsinki, Finland.
Section of Paediatric Surgery, Children's Hospital, Helsinki University Hospital, University of Helsinki, 00029 Helsinki, Finland.

Claus Petersen (C)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Department of Paediatric Surgery, Hannover Medical School, 30625 Hannover, Germany.

Mathias Ruiz (M)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Department of Paediatric Gastroenterology, Hepatology and Nutrition, Reference Center for Rare Disease-Biliary Atresia and Genetic Cholestasis, Children's Hospital of Lyon, 69005 Lyon, France.

Matthias Schunn (M)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Department of Paediatric Surgery and Paediatric Urology, University Children's Hospital, 72076 Tübingen, Germany.

Ekkehard Sturm (E)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Paediatric Gastroenterology/Hepatology, University Hospital Tübingen, 72076 Tübingen, Germany.

Henkjan J Verkade (HJ)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Division of Paediatric Gastroenterology and Hepatology, Department of Paediatrics, Beatrix Children's Hospital, University of Groningen, University Medical Centre Groningen, 9713 GZ Groningen, The Netherlands.

Barbara E Wildhaber (BE)

European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.
Swiss Pediatric Liver Centre, Division of Pediatric Surgery, University Hospitals of Geneva, Department of Pediatrics, Gynecology, and Obstetrics, University of Geneva, 1205 Geneva, Switzerland.

Jan B F Hulscher (JBF)

Division of Paediatric Surgery, Department of Surgery, University of Groningen, University Medical Centre Groningen, 9713 GZ Groningen, The Netherlands.
European Reference Network for Hepatological Diseases (ERN RARE-LIVER), D-20246 Hamburg, Germany.

Classifications MeSH