Mitochondrial dysfunction in chromaffin cells from the R6/1 mouse model of Huntington's disease: Impact on exocytosis and calcium current regulation.


Journal

Neurobiology of disease
ISSN: 1095-953X
Titre abrégé: Neurobiol Dis
Pays: United States
ID NLM: 9500169

Informations de publication

Date de publication:
04 2023
Historique:
received: 25 10 2022
revised: 08 02 2023
accepted: 15 02 2023
pubmed: 23 2 2023
medline: 23 3 2023
entrez: 22 2 2023
Statut: ppublish

Résumé

From a pathogenic perspective, Huntington's disease (HD) is being considered as a synaptopathy. As such, alterations in brain neurotransmitter release occur. As the activity of the sympathoadrenal axis is centrally controlled, deficits in the exocytotic release of catecholamine release may also occur. In fact, in chromaffin cells (CCs) of the adrenal medulla of the R6/1 model of HD, decrease of secretion and altered kinetics of the exocytotic fusion pore have been reported. Those alterations could be linked to mitochondrial deficits occurring in peripheral CCs, similar to those described in brain mitochondria. Here we have inquired about alterations in mitochondrial structure and function and their impact on exocytosis and calcium channel currents (I

Identifiants

pubmed: 36806818
pii: S0969-9961(23)00060-8
doi: 10.1016/j.nbd.2023.106046
pii:
doi:

Substances chimiques

Calcium SY7Q814VUP
Carbonyl Cyanide p-Trifluoromethoxyphenylhydrazone 370-86-5
Catecholamines 0

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

106046

Informations de copyright

Copyright © 2023 The Authors. Published by Elsevier Inc. All rights reserved.

Auteurs

Ana Fernández (A)

Instituto Teófilo Hernando, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Departamento de Farmacología, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Instituto de Investigación Sanitaria del Hospital Universitario de La Princesa, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Fundación Teófilo Hernando, Parque científico de Madrid, Cantoblanco, Madrid, Spain.

Carmen Martínez-Ramírez (C)

Instituto Teófilo Hernando, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Departamento de Farmacología, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Instituto de Investigación Sanitaria del Hospital Universitario de La Princesa, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Fundación Teófilo Hernando, Parque científico de Madrid, Cantoblanco, Madrid, Spain.

Ana Gómez (A)

Servicio de Neurobiología, IRYCIS, Hospital Universitario Ramón y Cajal, Madrid, Spain.

Antonio M G de Diego (AMG)

Instituto Teófilo Hernando, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Departamento de Farmacología, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain.

Luis Gandía (L)

Instituto Teófilo Hernando, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Departamento de Farmacología, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Fundación Teófilo Hernando, Parque científico de Madrid, Cantoblanco, Madrid, Spain.

María José Casarejos (MJ)

Servicio de Neurobiología, IRYCIS, Hospital Universitario Ramón y Cajal, Madrid, Spain.

Antonio G García (AG)

Instituto Teófilo Hernando, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Departamento de Farmacología, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Instituto de Investigación Sanitaria del Hospital Universitario de La Princesa, Facultad de Medicina, Universidad Autónoma de Madrid, Madrid, Spain; Fundación Teófilo Hernando, Parque científico de Madrid, Cantoblanco, Madrid, Spain. Electronic address: agg@uam.es.

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Classifications MeSH