Nutritional Status and Circulating Levels of Fat-Soluble Vitamins in Cystic Fibrosis Patients: A Cohort Study and Evaluation of the Effect of CFTR Modulators.

CFTR modulators cystic fibrosis malnutrition

Journal

Children (Basel, Switzerland)
ISSN: 2227-9067
Titre abrégé: Children (Basel)
Pays: Switzerland
ID NLM: 101648936

Informations de publication

Date de publication:
30 Jan 2023
Historique:
received: 28 09 2022
revised: 15 01 2023
accepted: 27 01 2023
entrez: 25 2 2023
pubmed: 26 2 2023
medline: 26 2 2023
Statut: epublish

Résumé

Improved therapy in CF has led to an overall improvement in nutritional status. The objectives of our study are: to cross-sectionally assess nutritional status and serum levels of fat-soluble vitamins; to retrospectively evaluate the efficacy of modulators on nutritional status and fat-soluble vitamin levels. In patients younger than 2 years of age, we evaluated growth, in patients aged 2-18 years, we assessed BMI z-scores, and in adults, we assessed absolute BMI values. Levels of 25(OH)D, vitamins A, and E were measured. A cross-sectional analysis was conducted on 318 patients, 109 (34.3%) with pancreatic sufficiency. Only three patients were under 2 years old. In 135 patients aged 2-18 years, the median BMI z-score was 0.11, and 5 (3.7%) patients had malnutrition (z-score ≤ 2SD). In 180 adults, the median BMI was 21.8 kg/m Malnutrition is present in a limited number of subjects. The prevalence of subjects with suboptimal 25(OH)D levels is high. ETI showed a beneficial effect on nutritional status and circulating levels of fat-soluble vitamins.

Sections du résumé

BACKGROUND BACKGROUND
Improved therapy in CF has led to an overall improvement in nutritional status. The objectives of our study are: to cross-sectionally assess nutritional status and serum levels of fat-soluble vitamins; to retrospectively evaluate the efficacy of modulators on nutritional status and fat-soluble vitamin levels.
METHODS METHODS
In patients younger than 2 years of age, we evaluated growth, in patients aged 2-18 years, we assessed BMI z-scores, and in adults, we assessed absolute BMI values. Levels of 25(OH)D, vitamins A, and E were measured.
RESULTS RESULTS
A cross-sectional analysis was conducted on 318 patients, 109 (34.3%) with pancreatic sufficiency. Only three patients were under 2 years old. In 135 patients aged 2-18 years, the median BMI z-score was 0.11, and 5 (3.7%) patients had malnutrition (z-score ≤ 2SD). In 180 adults, the median BMI was 21.8 kg/m
CONCLUSIONS CONCLUSIONS
Malnutrition is present in a limited number of subjects. The prevalence of subjects with suboptimal 25(OH)D levels is high. ETI showed a beneficial effect on nutritional status and circulating levels of fat-soluble vitamins.

Identifiants

pubmed: 36832382
pii: children10020252
doi: 10.3390/children10020252
pmc: PMC9955178
pii:
doi:

Types de publication

Journal Article

Langues

eng

Références

N Engl J Med. 2015 Jul 16;373(3):220-31
pubmed: 25981758
Pediatr Pulmonol. 2002 Aug;34(2):91-100
pubmed: 12112774
Lancet Respir Med. 2014 Nov;2(11):902-910
pubmed: 25311995
Nutrients. 2021 Aug 24;13(9):
pubmed: 34578785
Pediatrics. 2001 Jan;107(1):1-13
pubmed: 11134427
J Cyst Fibros. 2019 Jan;18(1):94-101
pubmed: 30146268
Front Pharmacol. 2020 Feb 21;10:1662
pubmed: 32153386
J Cyst Fibros. 2022 Sep;21(5):777-783
pubmed: 35396178
N Engl J Med. 2018 Oct 25;379(17):1671-1672
pubmed: 30334694
J Pediatr Pharmacol Ther. 2020;25(3):192-197
pubmed: 32265602
Lung. 2019 Jun;197(3):371-376
pubmed: 30887107
Am J Respir Crit Care Med. 2013 Jun 1;187(11):1219-25
pubmed: 23590265
Chest. 2018 Aug;154(2):383-393
pubmed: 29750923
Thorax. 2002 Jul;57(7):596-601
pubmed: 12096202
J Cyst Fibros. 2018 Jan;17(1):89-95
pubmed: 28711222
J Cyst Fibros. 2021 May;20(3):381-387
pubmed: 33531206
Cells. 2022 May 28;11(11):
pubmed: 35681464
Clin Chem. 2004 Aug;50(8):1415-7
pubmed: 15277348
Lancet Respir Med. 2017 Jul;5(7):557-567
pubmed: 28606620
Semin Respir Crit Care Med. 2019 Dec;40(6):775-791
pubmed: 31659726
J Pharm Biomed Anal. 2006 Sep 18;42(2):232-6
pubmed: 16765550
Lancet Respir Med. 2017 Feb;5(2):107-118
pubmed: 28011037
J Cyst Fibros. 2022 Mar;21(2):265-271
pubmed: 34862121
Nutrition. 2021 May;85:111124
pubmed: 33571868
N Engl J Med. 2017 Nov 23;377(21):2013-2023
pubmed: 29099344
Ital J Pediatr. 2021 Jan 6;47(1):2
pubmed: 33407736
Lancet. 2019 Nov 23;394(10212):1940-1948
pubmed: 31679946
Lancet Respir Med. 2020 Jan;8(1):65-124
pubmed: 31570318
World Rev Nutr Diet. 2022;124:374-381
pubmed: 35240644
J Cyst Fibros. 2017 Nov;16 Suppl 2:S70-S78
pubmed: 28986019
J Acad Nutr Diet. 2021 Jul;121(7):1364-1378.e2
pubmed: 32532673
Nutrients. 2022 Mar 13;14(6):
pubmed: 35334873
Lancet. 2021 Jun 5;397(10290):2195-2211
pubmed: 34090606
Curr Opin Pulm Med. 2019 Nov;25(6):674-679
pubmed: 31567328
Am J Respir Crit Care Med. 2020 Jan 15;201(2):188-197
pubmed: 31601120
Antioxidants (Basel). 2021 Mar 19;10(3):
pubmed: 33808590
J Cyst Fibros. 2018 Mar;17(2):153-178
pubmed: 29506920
Nutrients. 2021 Dec 09;13(12):
pubmed: 34959965
Nutrients. 2021 Dec 10;13(12):
pubmed: 34959966
Pediatr Pulmonol. 2022 Apr;57(4):935-944
pubmed: 35018747
J Pathol. 2016 Jan;238(2):311-20
pubmed: 26365583
J Clin Endocrinol Metab. 2012 Apr;97(4):1082-93
pubmed: 22399505
Br J Nutr. 2019 Jan;121(2):195-201
pubmed: 30442206
Am J Respir Crit Care Med. 2018 Jan 15;197(2):214-224
pubmed: 28930490
N Engl J Med. 2010 Nov 18;363(21):1991-2003
pubmed: 21083385
Nutrition. 2019 Nov - Dec;67-68:110518
pubmed: 31473521
Nat Rev Gastroenterol Hepatol. 2016 Mar;13(3):175-85
pubmed: 26790364
Dig Dis Sci. 2016 Jan;61(1):198-207
pubmed: 26250833
J Pediatr. 2017 Feb;181S:S4-S15.e1
pubmed: 28129811
N Engl J Med. 2019 Nov 7;381(19):1809-1819
pubmed: 31697873
Clin Nutr. 1998 Oct;17(5):211-5
pubmed: 10205341
Front Endocrinol (Lausanne). 2022 Jul 12;13:935354
pubmed: 35903281

Auteurs

Michela Francalanci (M)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Vito Terlizzi (V)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Cristina Fevola (C)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Giulia Di Rosa (G)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Valentina Pierattini (V)

Meyer Children's Hospital IRCCS, Professional Dietetics, 50139 Florence, Italy.

Elena Roselli (E)

Meyer Children's Hospital IRCCS, Professional Dietetics, 50139 Florence, Italy.

Paolo Bonomi (P)

Freelance Statistician, 20146 Milan, Italy.

Maria Chiara Cavicchi (MC)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Valeria Galici (V)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Anna Silvia Neri (AS)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Chiara Bianchimani (C)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Silvia Campana (S)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Daniela Dolce (D)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Novella Ravenni (N)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Erica Camera (E)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Tommaso Orioli (T)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Giovanni Taccetti (G)

Meyer Children's Hospital IRCCS, Cystic Fibrosis Regional Reference Centre, Department of Paediatric Medicine, 50139 Florence, Italy.

Classifications MeSH