Retrospective National "Real Life" Experience of the SFCE with the Metronomic MEMMAT and MEMMAT-like Protocol.

ATRT angiogenesis brain tumors immunotherapy medulloblastoma metronomic chemotherapy pediatric oncology pharmacology

Journal

Journal of clinical medicine
ISSN: 2077-0383
Titre abrégé: J Clin Med
Pays: Switzerland
ID NLM: 101606588

Informations de publication

Date de publication:
10 Feb 2023
Historique:
received: 30 12 2022
revised: 02 02 2023
accepted: 08 02 2023
entrez: 25 2 2023
pubmed: 26 2 2023
medline: 26 2 2023
Statut: epublish

Résumé

Relapses in pediatric high-risk brain tumors remain unmet medical needs. Over the last 15 years, metronomic chemotherapy has gradually emerged as an alternative therapeutic approach. This is a national retrospective study of patients with relapsing pediatric brain tumors treated according to the MEMMAT or MEMMAT-like regimen from 2010 to 2022. Treatment consisted of daily oral thalidomide, fenofibrate, and celecoxib, and alternating 21-day cycles of metronomic etoposide and cyclophosphamide associated with bevacizumab and intraventricular chemotherapy. Forty-one patients were included. The most frequent malignancies were medulloblastoma (22) and ATRT (8). Overall, the best responses were CR in eight patients (20%), PR in three patients (7%), and SD in three patients (7%), for a clinical benefit rate of 34%. The median overall survival was 26 months (IC95% = 12.4-42.7), and median EFS was 9.7 months (IC95% = 6.0-18.6). The most frequent grade ¾ toxicities were hematological. Dose had to be adjusted in 27% of the cases. There was no statistical difference in outcome between full or modified MEMMAT. The best setting seems to be when MEMMAT is used as a maintenance and at first relapse. The metronomic MEMMAT combination can lead to sustained control of relapsed high-risk pediatric brain tumors.

Sections du résumé

BACKGROUND BACKGROUND
Relapses in pediatric high-risk brain tumors remain unmet medical needs. Over the last 15 years, metronomic chemotherapy has gradually emerged as an alternative therapeutic approach.
PATIENTS AND METHODS METHODS
This is a national retrospective study of patients with relapsing pediatric brain tumors treated according to the MEMMAT or MEMMAT-like regimen from 2010 to 2022. Treatment consisted of daily oral thalidomide, fenofibrate, and celecoxib, and alternating 21-day cycles of metronomic etoposide and cyclophosphamide associated with bevacizumab and intraventricular chemotherapy.
RESULTS RESULTS
Forty-one patients were included. The most frequent malignancies were medulloblastoma (22) and ATRT (8). Overall, the best responses were CR in eight patients (20%), PR in three patients (7%), and SD in three patients (7%), for a clinical benefit rate of 34%. The median overall survival was 26 months (IC95% = 12.4-42.7), and median EFS was 9.7 months (IC95% = 6.0-18.6). The most frequent grade ¾ toxicities were hematological. Dose had to be adjusted in 27% of the cases. There was no statistical difference in outcome between full or modified MEMMAT. The best setting seems to be when MEMMAT is used as a maintenance and at first relapse.
CONCLUSIONS CONCLUSIONS
The metronomic MEMMAT combination can lead to sustained control of relapsed high-risk pediatric brain tumors.

Identifiants

pubmed: 36835950
pii: jcm12041415
doi: 10.3390/jcm12041415
pmc: PMC9967517
pii:
doi:

Types de publication

Journal Article

Langues

eng

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Auteurs

Camille Winnicki (C)

Department of Pediatric Immunology, Hematology and Oncology, Children Hospital of La Timone, Assistance Publique Hôpitaux de Marseille, 13005 Marseille, France.

Pierre Leblond (P)

Department of Pediatric Oncology, Institut d'Hématologie et d'Oncologie Pédiatrique, Centre Léon Bérard, 69008 Lyon, France.

Franck Bourdeaut (F)

SIREDO Pediatric Oncology Center, Curie Institute, 75005 Paris, France.

Anne Pagnier (A)

Department of Pediatric Immunohematology and Oncology, University Hospital, 38043 Grenoble, France.

Gilles Paluenzela (G)

Department of Pediatric Hematology-Oncology, Centre Hospitalo-Universitaire de Montpellier, 34000 Montpellier, France.

Pascal Chastagner (P)

Pediatric Oncology, University Hospital of Nancy, 54000 Nancy, France.

Gwenaelle Duhil-De Benaze (G)

Department of Pediatric Oncology, Centre Hospitalier Universitaire, University Côte d'Azur, 06108 Nice, France.

Victoria Min (V)

Department of Pediatric Immunology, Hematology and Oncology, Children Hospital of La Timone, Assistance Publique Hôpitaux de Marseille, 13005 Marseille, France.

Hélène Sudour-Bonnange (H)

Oscar-Lambret Center, Department of Pediatric Oncology & AYA Unit, 59020 Lille, France.

Catherine Piette (C)

Department of Pediatric Oncology, Centre Hospitalo-Universitaire de Liège, 4000 Liège, Belgium.

Natacha Entz-Werle (N)

Pediatric Onco-Hematology Department-Pediatrics III, University Hospital of Strasbourg, 67091 Strasbourg, France.

Sylvie Chabaud (S)

Department of Statistics, Centre Léon Bérard, 69373 Lyon, France.

Nicolas André (N)

Department of Pediatric Immunology, Hematology and Oncology, Children Hospital of La Timone, Assistance Publique Hôpitaux de Marseille, 13005 Marseille, France.
Centre de Recherche en Cancérologie de Marseille, Aix-Marseille Université, Inserm, CNRS, 13273 Marseille, France.
Metronomics Global Health Initiative, 13385 Marseille, France.

Classifications MeSH