Clinical deterioration following arterial switch surgery due to extensive aortopulmonary collaterals, unusual condition but worth considering: case report.

Aortopulmonary collaterals Arterial switch operation D-TGA MAPCA Transposition of great arteries

Journal

The Egyptian heart journal : (EHJ) : official bulletin of the Egyptian Society of Cardiology
ISSN: 2090-911X
Titre abrégé: Egypt Heart J
Pays: Germany
ID NLM: 9106952

Informations de publication

Date de publication:
30 Mar 2023
Historique:
received: 17 01 2023
accepted: 25 03 2023
medline: 31 3 2023
entrez: 30 3 2023
pubmed: 31 3 2023
Statut: epublish

Résumé

The occurrence of major aortopulmonary collateral arteries (MAPCAs) is infrequent in patients with D-transposition of great arteries (D-TGA) with intact ventricular septum (IVS). Hemodynamically significant MAPCAs may complicate the postoperative course of these patients after arterial switch operation (ASO). We present a rare case of neonatal D-TGA-IVS associated with extensive MAPCAs. After the ASO, the patient developed pulmonary hemorrhage, chest wall edema, and deterioration of lung compliance with the need for high-frequency ventilation (HFV). The patient also had a significant capillary leak with skin edema, high chest tube drainage, and high peritoneal drainage. Cardiac catheterization revealed extensive MAPCAs supplying the whole lung segments. After the catheter closure of most of these MAPCAs, the patient had clinical improvement. Although the occurrence of MAPCAs with D-TGA-IVS is infrequent, clinicians should suspect their presence in cases with unexplained heart failure, pulmonary hemorrhage, or cardiovascular compromise after ASO. Catheter closure of MAPCAs is feasible with an acceptable short-term outcome.

Sections du résumé

BACKGROUND BACKGROUND
The occurrence of major aortopulmonary collateral arteries (MAPCAs) is infrequent in patients with D-transposition of great arteries (D-TGA) with intact ventricular septum (IVS). Hemodynamically significant MAPCAs may complicate the postoperative course of these patients after arterial switch operation (ASO).
CASE PRESENTATION METHODS
We present a rare case of neonatal D-TGA-IVS associated with extensive MAPCAs. After the ASO, the patient developed pulmonary hemorrhage, chest wall edema, and deterioration of lung compliance with the need for high-frequency ventilation (HFV). The patient also had a significant capillary leak with skin edema, high chest tube drainage, and high peritoneal drainage. Cardiac catheterization revealed extensive MAPCAs supplying the whole lung segments. After the catheter closure of most of these MAPCAs, the patient had clinical improvement.
CONCLUSIONS CONCLUSIONS
Although the occurrence of MAPCAs with D-TGA-IVS is infrequent, clinicians should suspect their presence in cases with unexplained heart failure, pulmonary hemorrhage, or cardiovascular compromise after ASO. Catheter closure of MAPCAs is feasible with an acceptable short-term outcome.

Identifiants

pubmed: 36995490
doi: 10.1186/s43044-023-00349-2
pii: 10.1186/s43044-023-00349-2
pmc: PMC10063716
doi:

Types de publication

Journal Article

Langues

eng

Pagination

23

Informations de copyright

© 2023. The Author(s).

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Auteurs

Gaser Abdelmohsen (G)

Pediatric Cardiology Division, Department of Pediatrics, King Abdulaziz University, P.O Box 80215, Jeddah, 21589, Saudi Arabia. gaser_abdelmohsen81@yahoo.com.
Pediatric Cardiology Division, Department of Pediatrics, Cairo University, Cairo, 11562, Egypt. gaser_abdelmohsen81@yahoo.com.

Naif AlKhushi (N)

Pediatric Cardiology Division, Department of Pediatrics, King Abdulaziz University, P.O Box 80215, Jeddah, 21589, Saudi Arabia.

Abdullah Alassiri (A)

Faculty of Medicine, King Abdulaziz University, P.O Box 80215, Jeddah, 21589, Saudi Arabia.

Osman Al-Radi (O)

Cardiac Surgery Division, Department of Surgery, King Abdulaziz University, P.O Box 80215, Jeddah, 21589, Saudi Arabia.

Classifications MeSH