Pediatric Patients with Stage IV Rhabdomyosarcoma Significantly Benefit from Long-Term Maintenance Therapy: Results of the CWS-IV 2002 and the CWS DOK IV 2004-Trials.

children long-term maintenance therapy metastatic outcome rhabdomyosarcoma soft tissue sarcoma

Journal

Cancers
ISSN: 2072-6694
Titre abrégé: Cancers (Basel)
Pays: Switzerland
ID NLM: 101526829

Informations de publication

Date de publication:
30 Mar 2023
Historique:
received: 27 02 2023
revised: 22 03 2023
accepted: 24 03 2023
medline: 14 4 2023
entrez: 13 4 2023
pubmed: 14 4 2023
Statut: epublish

Résumé

Rhabdomyosarcoma (RMS) is the most common soft tissue sarcoma (STS) in childhood. Whereas more than 90% of patients with localized low-risk RMS can be cured, metastatic RMS have a dismal outcome, with survival rates of less than 30%. The HD CWS-96 trial showed an improved outcome for patients receiving maintenance therapy after completing intensive chemotherapy. Consequently, the international clinical trials CWS-IV 2002 and CWS DOK IV 2004 on metastatic disease of STS of the Cooperative Weichteilsarkom Studiengruppe (CWS) were designed in addition to the CWS-2002P trial for localized RMS disease. All patients received a multimodal intensive treatment regimen. To maintain remission, three options were compared: long-term maintenance therapy (LTMT) versus allogeneic hematopoietic stem cell transplantation (alloHSCT) versus high-dose chemotherapy (HDCT). A total of 176 pediatric patients with a histologically confirmed diagnosis of metastatic RMS or RMS-like tumor were included. A total of 89 patients receiving LTML showed a significantly better outcome, with an event-free survival (EFS) of 41% and an overall survival (OS) of 53%, than alloHSCT (

Identifiants

pubmed: 37046711
pii: cancers15072050
doi: 10.3390/cancers15072050
pmc: PMC10093505
pii:
doi:

Types de publication

Journal Article

Langues

eng

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Auteurs

Lars Tramsen (L)

Department of Pediatrics, University Hospital Schleswig-Holstein, Campus Kiel, 24105 Kiel, Germany.
Department for Children and Adolescents, University Hospital, Goethe-University, 60590 Frankfurt, Germany.

Konrad Bochennek (K)

Department for Children and Adolescents, University Hospital, Goethe-University, 60590 Frankfurt, Germany.

Monika Sparber-Sauer (M)

Center for Pediatric, Adolescent and Women's Medicine, Pediatric 5 (Oncology, Hematology, Immunology), Hospital of the State Capital Stuttgart, Olgahospital, Stuttgart Cancer Center, 70174 Stuttgart, Germany.
Faculty of Medicine, University Tuebingen, 72016 Tuebingen, Germany.

Emilia Salzmann-Manrique (E)

Department for Children and Adolescents, University Hospital, Goethe-University, 60590 Frankfurt, Germany.

Monika Scheer (M)

Department of Pediatric Oncology and Hematology, Charité-Universitätsmedizin Berlin, Augustenburger Platz 1, 13353 Berlin, Germany.

Tobias Dantonello (T)

Department of Pediatrics, Division of Pediatric Hematology and Oncology, Inselspital, Bern University Hospital, University of Bern, CH-3010 Bern, Switzerland.

Arndt Borkhardt (A)

Department of Pediatric Oncology, Hematology and Clinical Immunology, Medical Faculty, Heinrich Heine University, 40225 Duesseldorf, Germany.

Uta Dirksen (U)

Pediatrics III, University Hospital Essen, West German Cancer Center, 45147 Essen, Germany.
German Cancer Consortium site Essen, National Center for Tumor Diseases (NCT) Site Essen, 45147 Essen, Germany.

Anne Thorwarth (A)

Department of Pediatric Oncology and Hematology, Charité-Universitätsmedizin Berlin, Augustenburger Platz 1, 13353 Berlin, Germany.

Jeanette Greiner (J)

Pediatric Oncology and Hematology, Children's Hospital, Kantonsspital Aarau AG, CH-5001 Aarau, Switzerland.

Martin Ebinger (M)

Department of General Pediatrics and Pediatric Oncology and Hematology, University Children's Hospital, 72076 Tuebingen, Germany.

Jadwiga Weclawek-Tompol (J)

Department of Bone Marrow Transplantation, Pediatric Oncology and Haematology, University of Medicine Wroclaw, 50556 Wroclaw, Poland.

Ruth Ladenstein (R)

St. Anna-Kinderspital, Children's Cancer Research Institute (CCRI), 1090 Vienna, Austria.

Gustaf Ljungman (G)

Department of Women's and Children's Health, Pediatric Oncology, Uppsala University, 75185 Uppsala, Sweden.

Erika Hallmen (E)

Center for Pediatric, Adolescent and Women's Medicine, Pediatric 5 (Oncology, Hematology, Immunology), Hospital of the State Capital Stuttgart, Olgahospital, Stuttgart Cancer Center, 70174 Stuttgart, Germany.

Thomas Lehrnbecher (T)

Department for Children and Adolescents, University Hospital, Goethe-University, 60590 Frankfurt, Germany.

Ewa Koscielniak (E)

Center for Pediatric, Adolescent and Women's Medicine, Pediatric 5 (Oncology, Hematology, Immunology), Hospital of the State Capital Stuttgart, Olgahospital, Stuttgart Cancer Center, 70174 Stuttgart, Germany.
Faculty of Medicine, University Tuebingen, 72016 Tuebingen, Germany.

Thomas Klingebiel (T)

Department for Children and Adolescents, University Hospital, Goethe-University, 60590 Frankfurt, Germany.

Classifications MeSH