Lupus anticoagulant-hypoprothrombinemia syndrome: A cerebral bleeding case report as systemic lupus erythematosus debut.

Adult Adulto Hipoprotrombinemia Hypoprothrombinaemia Inhibidor de la coagulación lúpica Lupus anticoagulant-hypoprothrombinaemia syndrome Lupus coagulation inhibitor Lupus eritematoso sistémico Systemic lupus erythematosus Síndrome de anticoagulante lúpico-hipoprotrombinemia

Journal

Reumatologia clinica
ISSN: 2173-5743
Titre abrégé: Reumatol Clin (Engl Ed)
Pays: Spain
ID NLM: 101717526

Informations de publication

Date de publication:
Apr 2023
Historique:
received: 15 11 2021
accepted: 23 02 2022
medline: 18 4 2023
entrez: 15 4 2023
pubmed: 16 4 2023
Statut: ppublish

Résumé

Lupus anticoagulant-hypoprothrombinaemia syndrome (LAHPS) is a rare disorder caused by the presence of lupus anticoagulant (LA) and acquired prothrombin deficiency, which may present with severe haemorrhagic manifestations. LAHPS is usually associated with systemic lupus erythematosus (SLE), or infections and it is more frequent in the paediatric population and female gender. We describe a 42-year-old man with thrombotic antiphospholipid syndrome (APS) on chronic anticoagulation treatment with acenocoumarol who presented with spontaneous intracranial bleeding, prolongation of prothrombin time (PT), activated partial thromboplastin time (APTT) and low factor II levels (after optimal anticoagulation reversal) as a debut of SLE.

Identifiants

pubmed: 37061283
pii: S2173-5743(23)00036-9
doi: 10.1016/j.reumae.2022.02.008
pii:
doi:

Substances chimiques

Lupus Coagulation Inhibitor 0
Prothrombin 9001-26-7

Types de publication

Case Reports

Langues

eng

Sous-ensembles de citation

IM

Pagination

223-227

Informations de copyright

Copyright © 2022 Elsevier España, S.L.U. and Sociedad Española de Reumatología y Colegio Mexicano de Reumatología. All rights reserved.

Auteurs

Miriam Lopez Pérez (ML)

Department of Hematology, Hospital Universitario Fundación Jiménez Díaz, Hospitales Quirón Públicos, IIS-FJD, Madrid, Spain. Electronic address: Miriam.lopez@hospitalreyjuancarlos.es.

Rosa Vidal Laso (RV)

Department of Hematology, Hospital Universitario Fundación Jiménez Díaz, Hospitales Quirón Públicos, IIS-FJD, Madrid, Spain.

Diego Velasco-Rodríguez (D)

Department of Hematology, Hospital Universitario Fundación Jiménez Díaz, Hospitales Quirón Públicos, IIS-FJD, Madrid, Spain.

Sara Martín-Herrero (S)

Department of Hematology, Hospital Universitario Fundación Jiménez Díaz, Hospitales Quirón Públicos, IIS-FJD, Madrid, Spain.

Inés Martinez Alfonzo (IM)

Department of Hematology, Hospital Universitario Fundación Jiménez Díaz, Hospitales Quirón Públicos, IIS-FJD, Madrid, Spain.

Aránzazu García-Raso (A)

Department of Hematology, Hospital Universitario Fundación Jiménez Díaz, Hospitales Quirón Públicos, IIS-FJD, Madrid, Spain.

Pilar Llamas-Sillero (P)

Department of Hematology, Hospital Universitario Fundación Jiménez Díaz, Hospitales Quirón Públicos, IIS-FJD, Madrid, Spain.

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Classifications MeSH