DOT1L regulates chromatin reorganization and gene expression during sperm differentiation.


Journal

EMBO reports
ISSN: 1469-3178
Titre abrégé: EMBO Rep
Pays: England
ID NLM: 100963049

Informations de publication

Date de publication:
05 06 2023
Historique:
revised: 31 03 2023
received: 17 10 2022
accepted: 13 04 2023
medline: 6 6 2023
pubmed: 26 4 2023
entrez: 26 4 2023
Statut: ppublish

Résumé

Spermatozoa have a unique genome organization. Their chromatin is almost completely devoid of histones and is formed instead of protamines, which confer a high level of compaction and preserve paternal genome integrity until fertilization. Histone-to-protamine transition takes place in spermatids and is indispensable for the production of functional sperm. Here, we show that the H3K79-methyltransferase DOT1L controls spermatid chromatin remodeling and subsequent reorganization and compaction of the spermatozoon genome. Using a mouse model in which Dot1l is knocked-out (KO) in postnatal male germ cells, we found that Dot1l-KO sperm chromatin is less compact and has an abnormal content, characterized by the presence of transition proteins, immature protamine 2 forms and a higher level of histones. Proteomic and transcriptomic analyses performed on spermatids reveal that Dot1l-KO modifies the chromatin prior to histone removal and leads to the deregulation of genes involved in flagellum formation and apoptosis during spermatid differentiation. As a consequence of these chromatin and gene expression defects, Dot1l-KO spermatozoa have less compact heads and are less motile, which results in impaired fertility.

Identifiants

pubmed: 37099396
doi: 10.15252/embr.202256316
pmc: PMC10240200
doi:

Substances chimiques

Chromatin 0
Histones 0
Dot1l protein, mouse EC 2.1.1.-

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

e56316

Informations de copyright

© 2023 The Authors. Published under the terms of the CC BY 4.0 license.

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Auteurs

Mélina Blanco (M)

Université Paris Cité, INSERM, CNRS, Institut Cochin, Paris, France.

Laila El Khattabi (L)

Université Paris Cité, INSERM, CNRS, Institut Cochin, Paris, France.
Chromosomal Genomics Unit, Medical Genetics Department, Sorbonne Université and APHP, Hôpital Armand Trousseau, Paris, France.

Clara Gobé (C)

Université Paris Cité, INSERM, CNRS, Institut Cochin, Paris, France.

Marion Crespo (M)

University Grenoble Alpes, CEA, INSERM, UA13 BGE, CNRS, CEA, FR2048, Grenoble, France.
ADLIN Science, Pépinière « Genopole Entreprises », Evry, France.

Manon Coulée (M)

Université Paris Cité, INSERM, CNRS, Institut Cochin, Paris, France.

Alberto de la Iglesia (A)

Université Paris Cité, INSERM, CNRS, Institut Cochin, Paris, France.
Molecular Biology of Reproduction and Development Research Group, Department of Biomedical Sciences, Faculty of Medicine and Health Sciences, Institut d'Investigacions Biomèdiques August Pi I Sunyer (IDIBAPS), Fundació Clínic per a la Recerca Biomèdica, Universitat de Barcelona (UB), Barcelona, Spain.

Côme Ialy-Radio (C)

Université Paris Cité, INSERM, CNRS, Institut Cochin, Paris, France.

Clementine Lapoujade (C)

Université de Paris and Université Paris-Saclay, iRCM/IBFJ CEA, UMR Stabilité Génétique Cellules Souches et Radiations, Laboratoire des Cellules Souches Germinales, Fontenay-aux-Roses, France.

Maëlle Givelet (M)

Université de Paris and Université Paris-Saclay, iRCM/IBFJ CEA, UMR Stabilité Génétique Cellules Souches et Radiations, Laboratoire des Cellules Souches Germinales, Fontenay-aux-Roses, France.

Marion Delessard (M)

Université Paris Cité, INSERM, CNRS, Institut Cochin, Paris, France.

Ivan Seller-Corona (I)

Université Paris Cité, INSERM, CNRS, Institut Cochin, Paris, France.

Kosuke Yamaguchi (K)

Institute for Quantitative Biosciences, The University of Tokyo, Tokyo, Japan.

Nadège Vernet (N)

Institut de Génétique et de Biologie Moléculaire et Cellulaire (IGBMC), Département de Génétique Fonctionnelle et Cancer, CNRS, INSERM, Université de Strasbourg, Illkirch, France.

Fred Van Leeuwen (F)

Division of Gene Regulation, Netherlands Cancer Institute, Amsterdam, The Netherlands.

Alban Lermine (A)

MOABI-APHP Bioinformatics Platform-I&D-DSI, Assistance Publique-Hôpitaux de Paris, Paris, France.

Yuki Okada (Y)

Institute for Quantitative Biosciences, The University of Tokyo, Tokyo, Japan.

Romain Daveau (R)

MOABI-APHP Bioinformatics Platform-I&D-DSI, Assistance Publique-Hôpitaux de Paris, Paris, France.

Rafael Oliva (R)

Molecular Biology of Reproduction and Development Research Group, Department of Biomedical Sciences, Faculty of Medicine and Health Sciences, Institut d'Investigacions Biomèdiques August Pi I Sunyer (IDIBAPS), Fundació Clínic per a la Recerca Biomèdica, Universitat de Barcelona (UB), Barcelona, Spain.
Biochemistry and Molecular Genetics Service, Clinic Barcelona, Barcelona, Spain.

Pierre Fouchet (P)

Université de Paris and Université Paris-Saclay, iRCM/IBFJ CEA, UMR Stabilité Génétique Cellules Souches et Radiations, Laboratoire des Cellules Souches Germinales, Fontenay-aux-Roses, France.

Ahmed Ziyyat (A)

Université Paris Cité, INSERM, CNRS, Institut Cochin, Paris, France.
Service d'Histologie, d'Embryologie, Biologie de la Reproduction, AP-HP, Hôpital Cochin, Paris, France.

Delphine Pflieger (D)

University Grenoble Alpes, CEA, INSERM, UA13 BGE, CNRS, CEA, FR2048, Grenoble, France.

Julie Cocquet (J)

Université Paris Cité, INSERM, CNRS, Institut Cochin, Paris, France.

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