Pediatric chronic myeloid leukemia in myeloid blast crisis.

Blast Crisis Leukemia, Myelogenous, Chronic, BCR-ABL Positive Leukemia, Myeloid Leukemia, Myeloid, Acute Pediatrics

Journal

Autopsy & case reports
ISSN: 2236-1960
Titre abrégé: Autops Case Rep
Pays: Brazil
ID NLM: 101640070

Informations de publication

Date de publication:
2023
Historique:
received: 15 02 2022
accepted: 13 03 2023
medline: 27 4 2023
pubmed: 27 4 2023
entrez: 27 4 2023
Statut: epublish

Résumé

Chronic myeloid leukemia (CML) accounts for 2-3% of childhood leukemias. About 5% of cases present in a blastic phase of CML which clinically and morphologically mimics more common acute leukemias of childhood. We report a case of a 3-year-old male who presented with gradual onset swelling of the abdomen and extremities along with generalized weakness. Examination revealed massive splenomegaly, pallor, and pedal edema. Initial workup showed anemia, thrombocytopenia, and leukocytosis (120,000/uL) with a blast percentage of 35%. Blasts were positive for CD13, CD33, CD117, CD34 and HLA-DR, and stained negative for Myeloperoxidase and Periodic Acid Schiff. Fluorescence in situ hybridization was positive for b3a2/e14a2 junction BCR-ABL1 transcript and negative for RUNX1-RUNX1T1/t(8;21), clinching the diagnosis of CML in myeloid blast crisis. The patient expired within 17 days of diagnosis and initiation of therapy.

Identifiants

pubmed: 37101551
doi: 10.4322/acr.2023.426
pii: acrep122922
pmc: PMC10124558
doi:

Types de publication

Case Reports

Langues

eng

Pagination

e2023426

Informations de copyright

Copyright: © 2023 The Authors.

Déclaration de conflit d'intérêts

Conflict of interest: None.

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Auteurs

Biswajit Dey (B)

North Eastern Indira Gandhi Regional Institute of Health and Medical Sciences, Department of Pathology, Shillong, Meghalaya, India.

Anirban Dutta (A)

University of Hawaii John A. Burns School of Medicine, Department of Pediatrics, Honolulu, Hawaii, United States of America.

Classifications MeSH