Late-Onset Pyloric Stenosis and Intussusception With Final Diagnosis of Food Proteins' Hypersensitivity in Schaaf-Yang Syndrome: A Case Report.

food allergy gastrointestinal disease pediatrics rare disease

Journal

JPGN reports
ISSN: 2691-171X
Titre abrégé: JPGN Rep
Pays: United States
ID NLM: 101773885

Informations de publication

Date de publication:
May 2022
Historique:
received: 28 02 2022
accepted: 28 03 2022
medline: 12 5 2023
pubmed: 12 5 2023
entrez: 11 5 2023
Statut: epublish

Résumé

Schaaf-Yang syndrome (SYS) is a rare neurodevelopmental disorder whose clinical spectrum includes neurodevelopment delay, dysmorphic features, and gastrointestinal symptoms such as feeding difficulties, gastroesophageal reflux, and chronic constipation. Given the small number of patients diagnosed with this syndrome, our aim is to describe novel clinical features that have not yet been reported. The patient we are describing is a 14-year-old male affected by a severe form of SYS. Initial clinical presentation included respiratory distress at birth, feeding difficulties, and neurodevelopmental delay. Since the age of 8 months, he had been tube fed with a semi-elemental formula, and this was well tolerated. At 9 years of age, the pathological mutation (variant

Identifiants

pubmed: 37168918
doi: 10.1097/PG9.0000000000000202
pmc: PMC10158381
doi:

Types de publication

Case Reports

Langues

eng

Pagination

e202

Informations de copyright

Copyright © 2022 The Author(s). Published by Wolters Kluwer Health, Inc. on behalf of the European Society for Pediatric Gastroenterology, Hepatology, and Nutrition and the North American Society for Pediatric Gastroenterology, Hepatology, and Nutrition.

Déclaration de conflit d'intérêts

The authors report no conflicts of interest.

Références

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Auteurs

Alessandra Mari (A)

From the Department of Pediatrics, Vittore Buzzi Children's Hospital, University of Milan, Milan, Italy.

Marco Ugo Andrea Sartorio (MUA)

From the Department of Pediatrics, Vittore Buzzi Children's Hospital, University of Milan, Milan, Italy.

Irene Degrassi (I)

Department of Pediatrics, Vittore Buzzi Children's Hospital, Milan, Italy.

Enza D'Auria (E)

From the Department of Pediatrics, Vittore Buzzi Children's Hospital, University of Milan, Milan, Italy.

Laura Fiori (L)

Department of Pediatrics, Vittore Buzzi Children's Hospital, Milan, Italy.

Dario Dilillo (D)

Department of Pediatrics, Vittore Buzzi Children's Hospital, Milan, Italy.

Marta Agostinelli (M)

From the Department of Pediatrics, Vittore Buzzi Children's Hospital, University of Milan, Milan, Italy.

Erica Pendezza (E)

Department of Pediatrics, Vittore Buzzi Children's Hospital, Milan, Italy.

Alessandra Bosetti (A)

Department of Pediatrics, Vittore Buzzi Children's Hospital, Milan, Italy.

Luciano Maestri (L)

Department of Pediatric Surgery, Vittore Buzzi Children's Hospital, Milan, Italy.

Gloria Pelizzo (G)

Department of Pediatric Surgery, Vittore Buzzi Children's Hospital, Milan, University of Milan, Milan, Italy.

Gian Vincenzo Zuccotti (GV)

From the Department of Pediatrics, Vittore Buzzi Children's Hospital, University of Milan, Milan, Italy.

Elvira Verduci (E)

From the Department of Pediatrics, Vittore Buzzi Children's Hospital, University of Milan, Milan, Italy.

Classifications MeSH