Prominent osteolysis in the maxilla: case report of an odontogenic fibroma mimicking a cyst.


Journal

BMC oral health
ISSN: 1472-6831
Titre abrégé: BMC Oral Health
Pays: England
ID NLM: 101088684

Informations de publication

Date de publication:
16 05 2023
Historique:
received: 09 02 2023
accepted: 03 05 2023
medline: 18 5 2023
pubmed: 17 5 2023
entrez: 16 5 2023
Statut: epublish

Résumé

Odontogenic fibroma (OF) is a rare benign odontogenic tumor of ectomesenchymal origin, mostly affecting the tooth-bearing portions of the jaws in middle-aged patients. Whilst small lesions tend to be clinically asymptomatic, varying unspecific clinical symptoms occur with an increase in size and may mimic odontogenic or other maxillofacial bone tumors, cysts, or fibro-osseous lesions of the jaws. A 31-year-old female patient presented with a hard, non-fluctuating protrusion in the vestibule of the upper right maxilla. It was visualized on cone beam computed tomography (CBCT) as space-occupying osteolysis with the displacement of the floor and facial wall of the maxillary sinus, mimicking a cyst-like lesion. The tissue was surgically removed and identified as an OF in the histopathological examination. One year after the surgery, restitution of regular sinus anatomy and physiological intraoral findings were observed. This case report emphasizes that rare entities, like the maxillary OF presented, often demonstrate nonspecific clinical and radiological findings. Nevertheless, clinicians need to consider rare entities as possible differential diagnoses and plan the treatment accordingly. Histopathological examination is essential to conclude the diagnosis. OF rarely recur after proper enucleation.

Sections du résumé

BACKGROUND
Odontogenic fibroma (OF) is a rare benign odontogenic tumor of ectomesenchymal origin, mostly affecting the tooth-bearing portions of the jaws in middle-aged patients. Whilst small lesions tend to be clinically asymptomatic, varying unspecific clinical symptoms occur with an increase in size and may mimic odontogenic or other maxillofacial bone tumors, cysts, or fibro-osseous lesions of the jaws.
CASE PRESENTATION
A 31-year-old female patient presented with a hard, non-fluctuating protrusion in the vestibule of the upper right maxilla. It was visualized on cone beam computed tomography (CBCT) as space-occupying osteolysis with the displacement of the floor and facial wall of the maxillary sinus, mimicking a cyst-like lesion. The tissue was surgically removed and identified as an OF in the histopathological examination. One year after the surgery, restitution of regular sinus anatomy and physiological intraoral findings were observed.
CONCLUSIONS
This case report emphasizes that rare entities, like the maxillary OF presented, often demonstrate nonspecific clinical and radiological findings. Nevertheless, clinicians need to consider rare entities as possible differential diagnoses and plan the treatment accordingly. Histopathological examination is essential to conclude the diagnosis. OF rarely recur after proper enucleation.

Identifiants

pubmed: 37194038
doi: 10.1186/s12903-023-03008-9
pii: 10.1186/s12903-023-03008-9
pmc: PMC10189911
doi:

Types de publication

Case Reports Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

297

Informations de copyright

© 2023. The Author(s).

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Auteurs

Clemens Raabe (C)

Department of Oral Surgery and Stomatology, School of Dental Medicine, ZMK Bern, University of Bern, Bern, Switzerland. clemens.raabe@unibe.ch.

Matthias Dettmer (M)

Institute of Pathology, University of Bern, Bern, Switzerland.
Institute of Pathology, Klinikum Stuttgart, Katharinenhospital, Stuttgart, Germany.

Daniel Baumhoer (D)

Bone Tumor Reference Center at the Institute of Pathology, University Hospital Basel, University of Basel, Basel, Switzerland.

Valerie G A Suter (VGA)

Department of Oral Surgery and Stomatology, School of Dental Medicine, ZMK Bern, University of Bern, Bern, Switzerland.

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Classifications MeSH