Management and Outcomes of Wilms Tumor with Suprarenal Intravascular Extension: A Pediatric Surgical Oncology Research Collaborative Study.


Journal

Annals of surgery
ISSN: 1528-1140
Titre abrégé: Ann Surg
Pays: United States
ID NLM: 0372354

Informations de publication

Date de publication:
02 Jun 2023
Historique:
medline: 2 6 2023
pubmed: 2 6 2023
entrez: 2 6 2023
Statut: aheadofprint

Résumé

The purpose of this study was to describe management and outcomes from a contemporary cohort of children with Wilms Tumor (WT) complicated by inferior vena caval thrombus. The largest series of these patients was published almost two decades ago. Since then, neoadjuvant chemotherapy has been commonly used to manage these patients and outcomes have not been reported. Retrospective review from 19 North American centers between 2009-2019. Patient and disease characteristics, management, and outcomes were investigated and analyzed. Of 124 patients, 81% had favorable histology (FH), and 52% were stage IV. IVC thrombus level was infrahepatic in 53 (43%), intrahepatic in 32 (26%), suprahepatic in 14 (11%), and cardiac in 24 (19%). Neoadjuvant chemotherapy using a 3-drug regimen was administered in 82% and post-resection radiation in 90%. Thrombus level regression was 45% overall, with suprahepatic level showing the best response (62%). Cardiopulmonary bypass (CPB) was potentially avoided in 67%. Peri-operative complication rate was significantly lower following neoadjuvant chemotherapy ([25%] vs. Upfront surgery [55%]; P=0.005). CPB was not associated with higher complications (CPB [50%] vs. no CPB [27%]; P=0.08). Two-year event-free survival (EFS) was 93% and overall survival (OS) was 96%, higher in FH cases (FH 98% vs. unfavorable histology/anaplastic 82%; P=0.73). Neither incomplete resection nor viable thrombus cells affected EFS or OS. Multimodal therapy resulted in excellent outcomes, even with advanced stage disease and cardiac extension. Neoadjuvant chemotherapy decreased the need for CPB to facilitate resection. Complete thrombectomy may not always be necessary.

Sections du résumé

OBJECTIVE OBJECTIVE
The purpose of this study was to describe management and outcomes from a contemporary cohort of children with Wilms Tumor (WT) complicated by inferior vena caval thrombus.
SUMMARY BACKGROUND DATA BACKGROUND
The largest series of these patients was published almost two decades ago. Since then, neoadjuvant chemotherapy has been commonly used to manage these patients and outcomes have not been reported.
METHODS METHODS
Retrospective review from 19 North American centers between 2009-2019. Patient and disease characteristics, management, and outcomes were investigated and analyzed.
RESULTS RESULTS
Of 124 patients, 81% had favorable histology (FH), and 52% were stage IV. IVC thrombus level was infrahepatic in 53 (43%), intrahepatic in 32 (26%), suprahepatic in 14 (11%), and cardiac in 24 (19%). Neoadjuvant chemotherapy using a 3-drug regimen was administered in 82% and post-resection radiation in 90%. Thrombus level regression was 45% overall, with suprahepatic level showing the best response (62%). Cardiopulmonary bypass (CPB) was potentially avoided in 67%. Peri-operative complication rate was significantly lower following neoadjuvant chemotherapy ([25%] vs. Upfront surgery [55%]; P=0.005). CPB was not associated with higher complications (CPB [50%] vs. no CPB [27%]; P=0.08). Two-year event-free survival (EFS) was 93% and overall survival (OS) was 96%, higher in FH cases (FH 98% vs. unfavorable histology/anaplastic 82%; P=0.73). Neither incomplete resection nor viable thrombus cells affected EFS or OS.
CONCLUSIONS CONCLUSIONS
Multimodal therapy resulted in excellent outcomes, even with advanced stage disease and cardiac extension. Neoadjuvant chemotherapy decreased the need for CPB to facilitate resection. Complete thrombectomy may not always be necessary.

Identifiants

pubmed: 37264925
doi: 10.1097/SLA.0000000000005921
pii: 00000658-990000000-00480
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

Copyright © 2023 The Author(s). Published by Wolters Kluwer Health, Inc.

Déclaration de conflit d'intérêts

The authors report no conflicts of interest.

Auteurs

Bindi Naik-Mathuria (B)

Department of Surgery, Division of Pediatric Surgery, University of Texas Medical Branch, Galveston, TX.

Alan F Utria (AF)

Division of General and Thoracic Surgery, Seattle Children's Hospital; Department of Surgery, University of Washington School of Medicine, Seattle, WA.

Peter F Ehrlich (PF)

Section of Pediatric Surgery, Department of Surgery, C.S. Mott Children's Hospital, The University of Michigan, Ann Arbor, MI.

Jennifer H Aldrink (JH)

Division of Pediatric Surgery, Department of Surgery, Nationwide Children's Hospital, The Ohio State University College of Medicine, Columbus, OH.

Andrew J Murphy (AJ)

Department of Surgery, St. Jude Children's Research Hospital, Memphis, TN.

Timothy Lautz (T)

Division of Pediatric Surgery, Lurie Children's Hospital, Department of Surgery, Northwestern School of Medicine, Chicago, OH.

Roshni Dasgupta (R)

Division of Pediatric General and Thoracic Surgery, Cincinnati Children's Medical Center, Cincinnati, OH.

Scott S Short (SS)

Division of Pediatric Surgery, Department of Surgery, University of Utah, Primary Children's Hospital, Salt Lake City, UT.

Harold N Lovvorn (HN)

Department of Pediatric Surgery, Pediatric Pathology, and Section of Surgical Sciences, Vanderbilt University Medical Center, Nashville, TN.

Eugene S Kim (ES)

Division of Pediatric Surgery, Cedars-Sinai Medical Center, Los Angeles, CA.

Erica Newman (E)

Section of Pediatric Surgery, Department of Surgery, C.S. Mott Children's Hospital, The University of Michigan, Ann Arbor, MI.

Dave R Lal (DR)

Division of Pediatric Surgery, Medical College of Wisconsin, Children's Wisconsin, Milwaukee, WI.

Barrie S Rich (BS)

Division of Pediatric Surgery, Zucker School of Medicine at Hofstra/Northwell, Cohen Children's Medical Center, New Hyde Park, NY.

Nelson Piché (N)

Division of Pediatric Surgery, Centre Hospitalier Universitaire Ste-Justine, Université de Montréal, Montréal, Québec, Canada.

Zachary J Kastenberg (ZJ)

Division of Pediatric Surgery, Department of Surgery, University of Utah, Primary Children's Hospital, Salt Lake City, Utah.

Marcus M Malek (MM)

Division of Pediatric General and Thoracic Surgery, UPMC Children's Hospital of Pittsburgh, Pittsburgh, PA.

Richard D Glick (RD)

Division of Pediatric Surgery, Zucker School of Medicine at Hofstra/Northwell, Cohen Children's Medical Center, New Hyde Park, NY.

Robin T Petroze (RT)

Division of Pediatric Surgery, University of Florida, Gainesville, FL.

Stephanie F Polites (SF)

Department of Surgery, Mayo Clinic, Rochester, MN.

Richard Whitlock (R)

Department of Surgery, Baylor College of Medicine, Texas Children's Hospital, Houston, TX.

Elizabeth Alore (E)

Department of Surgery, Baylor College of Medicine, Texas Children's Hospital, Houston, TX.

Pattamon Sutthatarn (P)

Department of Surgery, St. Jude Children's Research Hospital, Memphis, TN.

Stephanie Y Chen (SY)

Division of Pediatric Surgery, Cedars-Sinai Medical Center, Los Angeles, CA.

Shannon Wong-Michalak (S)

Department of Surgery, Division of Pediatric Surgery, University of Texas Medical Branch, Galveston, TX.

Rodrigo Lp Romao (RL)

Division of General and Thoracic Surgery, Seattle Children's Hospital; Department of Surgery, University of Washington School of Medicine, Seattle, WA.

Ameer Al-Hadidi (A)

Division of Pediatric Surgery, Department of Surgery, Nationwide Children's Hospital, The Ohio State University College of Medicine, Columbus, OH.

Nathan S Rubalcava (NS)

Section of Pediatric Surgery, Department of Surgery, C.S. Mott Children's Hospital, The University of Michigan, Ann Arbor, MI.

John P Marquart (JP)

Division of Pediatric Surgery, Medical College of Wisconsin, Children's Wisconsin, Milwaukee, WI.

Hailey Gainer (H)

Division of Pediatric Surgery, Medical College of Wisconsin, Children's Wisconsin, Milwaukee, WI.

Mike Johnson (M)

Division of Pediatric General and Thoracic Surgery, Cincinnati Children's Medical Center, Cincinnati, OH.

Chloe Boehmer (C)

Division of Pediatric General and Thoracic Surgery, Cincinnati Children's Medical Center, Cincinnati, OH.

Hannah Rinehardt (H)

Division of Pediatric General and Thoracic Surgery, UPMC Children's Hospital of Pittsburgh, Pittsburgh, PA.

Natashia M Seemann (NM)

Department of Surgery, Baylor College of Medicine, Texas Children's Hospital, Houston, TX.

Jacob Davidson (J)

Department of Surgery, Baylor College of Medicine, Texas Children's Hospital, Houston, TX.

Valerie Polcz (V)

Division of Pediatric Surgery, University of Florida, Gainesville, FL.

Sarah B Lund (SB)

Department of Surgery, Mayo Clinic, Rochester, MN.

Katlyn G McKay (KG)

Department of Pediatric Surgery, Pediatric Pathology, and Section of Surgical Sciences, Vanderbilt University Medical Center, Nashville, TN.

Hernan Correa (H)

Department of Pediatric Surgery, Pediatric Pathology, and Section of Surgical Sciences, Vanderbilt University Medical Center, Nashville, TN.

David H Rothstein (DH)

Division of General and Thoracic Surgery, Seattle Children's Hospital; Department of Surgery, University of Washington School of Medicine, Seattle, WA.

Classifications MeSH