The causal mutation in ARR3 gene for high myopia and progressive color vision defect.


Journal

Scientific reports
ISSN: 2045-2322
Titre abrégé: Sci Rep
Pays: England
ID NLM: 101563288

Informations de publication

Date de publication:
02 06 2023
Historique:
received: 10 11 2022
accepted: 30 05 2023
medline: 5 6 2023
pubmed: 3 6 2023
entrez: 2 6 2023
Statut: epublish

Résumé

The ARR3 gene, also known as cone arrestin, belongs to the arrestin family and is expressed in cone cells, inactivating phosphorylated-opsins and preventing cone signals. Variants of ARR3 reportedly cause X-linked dominant female-limited early-onset (age < 7 years old) high myopia (< - 6D). Here, we reveal a new mutation (c.228T>A, p.Tyr76*) in ARR3 gene that can cause early-onset high myopia (eoHM) limited to female carriers. Protan/deutan color vision defects were also found in family members, affecting both genders. Using ten years of clinical follow-up data, we identified gradually worsening cone dysfunction/color vision as a key feature among affected individuals. We present a hypothesis that higher visual contrast due to the mosaic of mutated ARR3 expression in cones contributes to the development of myopia in female carriers.

Identifiants

pubmed: 37268727
doi: 10.1038/s41598-023-36141-0
pii: 10.1038/s41598-023-36141-0
pmc: PMC10238396
doi:

Substances chimiques

Arrestin 0

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

8986

Informations de copyright

© 2023. The Author(s).

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Auteurs

Lei Gu (L)

The First Affiliated Hospital, Zhejiang University School of Medicine, Hangzhou, China.

Peikuan Cong (P)

Key Laboratory of Growth Regulation and Translational Research of Zhejiang Province, School of Life Sciences, Westlake University, Hangzhou, China.

Qingyao Ning (Q)

The First Affiliated Hospital, Zhejiang University School of Medicine, Hangzhou, China.

Bo Jiang (B)

The First Affiliated Hospital, Zhejiang University School of Medicine, Hangzhou, China.

Jianyong Wang (J)

The First Affiliated Hospital, Zhejiang University School of Medicine, Hangzhou, China.

Hongguang Cui (H)

The First Affiliated Hospital, Zhejiang University School of Medicine, Hangzhou, China. 1189002@zju.edu.cn.

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Classifications MeSH