Pulmonary hypertension secondary to interstitial fibrosis with pulmonary venous lesions masquerading pulmonary veno-occlusive disease.

interstitial fibrosis pulmonary edema pulmonary hypertension pulmonary veno‐occlusive disease targeted pulmonary arterial hypertension drugs

Journal

Respirology case reports
ISSN: 2051-3380
Titre abrégé: Respirol Case Rep
Pays: United States
ID NLM: 101631052

Informations de publication

Date de publication:
Jul 2023
Historique:
received: 15 03 2023
accepted: 29 05 2023
medline: 12 6 2023
pubmed: 12 6 2023
entrez: 12 6 2023
Statut: epublish

Résumé

We present a 41-year-old man with idiopathic interstitial pneumonia and pulmonary hypertension (PH) in the setting of a non-autoimmune background whose clinical presentation masqueraded pulmonary veno-occlusive disease (PVOD). Because of no histological evidence of venous occlusion in his previous lung biopsy, phosphodiesterase type-5 inhibitor was given, resulting in sudden onset of pulmonary edema. At autopsy, there were histological features of interstitial fibrosis with occlusion of the lobular septal veins and venules. Clinical presentations of PH due to interstitial fibrosis with pulmonary venous lesions may simulate those of PVOD and careful diagnostic and therapeutic approaches are required.

Identifiants

pubmed: 37303310
doi: 10.1002/rcr2.1179
pii: RCR21179
pmc: PMC10257537
doi:

Types de publication

Case Reports

Langues

eng

Pagination

e01179

Informations de copyright

© 2023 The Authors. Respirology Case Reports published by John Wiley & Sons Australia, Ltd on behalf of The Asian Pacific Society of Respirology.

Déclaration de conflit d'intérêts

None declared.

Références

Eur Respir J. 2019 Jan 24;53(1):
pubmed: 30545968
Eur Respir J. 2016 May;47(5):1518-34
pubmed: 27009171
Nat Genet. 2014 Jan;46(1):65-9
pubmed: 24292273
Eur Respir J. 2009 Jan;33(1):189-200
pubmed: 19118230
Am J Respir Crit Care Med. 2013 Sep 15;188(6):733-48
pubmed: 24032382
Hum Pathol. 2007 Jan;38(1):60-5
pubmed: 16949908

Auteurs

Hiroki Nakayama (H)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.

Masayuki Ishida (M)

Department of Pulmonary Medicine Chikamori Hospital Kochi-shi Japan.

Hiroshi Nakaoka (H)

Department of Pulmonary Medicine Chikamori Hospital Kochi-shi Japan.

Yuki Nishimura (Y)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.

Ryu-Ichirou Imai (RI)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.

Hiroki Sugane (H)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.

Hayato Hosoda (H)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.

Yoko Nakaoka (Y)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.

Koji Nishida (K)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.

Shu-Ichi Seki (SI)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.

Sho-Ichi Kubokawa (SI)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.

Kazuya Kawai (K)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.

Naohisa Hamashige (N)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.

Yoshinori Doi (Y)

Department of Cardiology Chikamori Hospital Kochi-shi Japan.
Cardiomyopathy Institute, Chikamori Hospital Kochi-shi Japan.

Classifications MeSH