A dual H-type tracheoesophageal fistula; why not being repaired simultaneously? A case report and review of literature.
Double fistula
Flexible bronchoscopy
H-type fistula
Infant
Surgery
Tracheoesophageal fistula
Journal
BMC pediatrics
ISSN: 1471-2431
Titre abrégé: BMC Pediatr
Pays: England
ID NLM: 100967804
Informations de publication
Date de publication:
19 06 2023
19 06 2023
Historique:
received:
21
06
2022
accepted:
06
03
2023
medline:
21
6
2023
pubmed:
20
6
2023
entrez:
19
6
2023
Statut:
epublish
Résumé
H-type Tracheoesophageal Fistula (TEF) is a particular type of congenital esophageal anomalies, in which patients present with non-specific symptoms that can result in delayed diagnosis. Here, we report two pediatric cases with a rarer variant called ‟dual H-type TEFˮ. We present two cases of H-type TEF. The first was a 45-day-old boy with feeding problem and cyanosis while feeding, and the second was a three-month-old girl with cough and choking after feeding from the first day of birth. In both cases, two separate TEFs were detected during diagnostic evaluation by flexible bronchoscopy. Both were repaired simultaneously through a cervical incision. The first patient deteriorated 13 days after the surgery, disturbancing in acid-base balance and expired unfortunately. Hence, it is necessary to consider the possibility of double TEF in any newly diagnosed H-type TEF.
Sections du résumé
BACKGROUND
H-type Tracheoesophageal Fistula (TEF) is a particular type of congenital esophageal anomalies, in which patients present with non-specific symptoms that can result in delayed diagnosis. Here, we report two pediatric cases with a rarer variant called ‟dual H-type TEFˮ.
CASE PRESENTATION
We present two cases of H-type TEF. The first was a 45-day-old boy with feeding problem and cyanosis while feeding, and the second was a three-month-old girl with cough and choking after feeding from the first day of birth. In both cases, two separate TEFs were detected during diagnostic evaluation by flexible bronchoscopy. Both were repaired simultaneously through a cervical incision. The first patient deteriorated 13 days after the surgery, disturbancing in acid-base balance and expired unfortunately.
CONCLUSION
Hence, it is necessary to consider the possibility of double TEF in any newly diagnosed H-type TEF.
Identifiants
pubmed: 37337161
doi: 10.1186/s12887-023-03945-y
pii: 10.1186/s12887-023-03945-y
pmc: PMC10278301
doi:
Types de publication
Review
Case Reports
Journal Article
Langues
eng
Sous-ensembles de citation
IM
Pagination
308Informations de copyright
© 2023. The Author(s).
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