A 10-year experience in testicular tissue cryopreservation for boys under 18 years of age: What can be learned from 350 cases?

alkylating agent boys chemotherapy cryopreservation fertility preservation pediatric oncology prepubertal testicular tissue

Journal

Andrology
ISSN: 2047-2927
Titre abrégé: Andrology
Pays: England
ID NLM: 101585129

Informations de publication

Date de publication:
07 Jul 2023
Historique:
revised: 20 06 2023
received: 29 11 2022
accepted: 03 07 2023
pubmed: 7 7 2023
medline: 7 7 2023
entrez: 7 7 2023
Statut: aheadofprint

Résumé

A growing number of centers worldwide are preserving testicular tissue (TT) of young boys at risk of fertility loss to preserve their fertility. Data in this regard are scarce and experience sharing is essential to the optimization of the process. This report of our 10-year activity of pediatric fertility preservation (FP) has the objective to (1) improve knowledge regarding the feasibility, acceptability, safety, and potential usefulness of the procedure; (2) analyze the impact of chemotherapy on spermatogonia in the cryopreserved TT. For this retrospective study of data prospectively recorded, we included all boys under 18 years of age referred to the FP consultation of our academic network between October 2009 and December 2019. Characteristics of patients and cryopreservation of testicular tissue (CTT) were extracted from the clinical database. Univariate and multivariate analyses were used to assess factors associated with the risk of absence of spermatogonia in the TT. Three hundred and sixty-nine patients (7.2 years; 0.5-17.0) were referred to the FP consultation for malignant (70%) or non-malignant (30%) disease, of whom 88% were candidates for CTT, after a previous chemotherapy exposure (78%). The rate of recorded immediate adverse events was 3.5%, with painful episodes dominating. Spermatogonia were detected in the majority of TTs: 91.1% of those exposed to chemotherapy and 92.3% of those not exposed (p = 0.962). In multivariate analysis, the risk of absence of spermatogonia was almost three-fold higher in boys > 10 years of age ([OR] 2.74, 95% CI 1.09-7.26, p = 0.035) and four-fold higher in boys exposed to alkylating agents prior to CTT ([OR] 4.09, 95% CI 1.32-17.94, p = 0.028). This large series of pediatric FP shows that this procedure is well accepted, feasible, and safe in the short term, strengthening its place in the clinical care pathway of young patients requiring a highly gonadotoxic treatment. Our results demonstrate that CTT post-chemotherapy does not impair the chance to preserve spermatogonia in the TT except when the treatment includes alkylating agents. More data on post-CTT follow-up are still required to ensure the long-term safety and usefulness of the procedure.

Sections du résumé

BACKGROUND BACKGROUND
A growing number of centers worldwide are preserving testicular tissue (TT) of young boys at risk of fertility loss to preserve their fertility. Data in this regard are scarce and experience sharing is essential to the optimization of the process.
OBJECTIVES OBJECTIVE
This report of our 10-year activity of pediatric fertility preservation (FP) has the objective to (1) improve knowledge regarding the feasibility, acceptability, safety, and potential usefulness of the procedure; (2) analyze the impact of chemotherapy on spermatogonia in the cryopreserved TT.
MATERIALS AND METHODS METHODS
For this retrospective study of data prospectively recorded, we included all boys under 18 years of age referred to the FP consultation of our academic network between October 2009 and December 2019. Characteristics of patients and cryopreservation of testicular tissue (CTT) were extracted from the clinical database. Univariate and multivariate analyses were used to assess factors associated with the risk of absence of spermatogonia in the TT.
RESULTS RESULTS
Three hundred and sixty-nine patients (7.2 years; 0.5-17.0) were referred to the FP consultation for malignant (70%) or non-malignant (30%) disease, of whom 88% were candidates for CTT, after a previous chemotherapy exposure (78%). The rate of recorded immediate adverse events was 3.5%, with painful episodes dominating. Spermatogonia were detected in the majority of TTs: 91.1% of those exposed to chemotherapy and 92.3% of those not exposed (p = 0.962). In multivariate analysis, the risk of absence of spermatogonia was almost three-fold higher in boys > 10 years of age ([OR] 2.74, 95% CI 1.09-7.26, p = 0.035) and four-fold higher in boys exposed to alkylating agents prior to CTT ([OR] 4.09, 95% CI 1.32-17.94, p = 0.028).
DISCUSSION/CONCLUSION CONCLUSIONS
This large series of pediatric FP shows that this procedure is well accepted, feasible, and safe in the short term, strengthening its place in the clinical care pathway of young patients requiring a highly gonadotoxic treatment. Our results demonstrate that CTT post-chemotherapy does not impair the chance to preserve spermatogonia in the TT except when the treatment includes alkylating agents. More data on post-CTT follow-up are still required to ensure the long-term safety and usefulness of the procedure.

Identifiants

pubmed: 37418281
doi: 10.1111/andr.13493
doi:

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

© 2023 The Authors. Andrology published by Wiley Periodicals LLC on behalf of American Society of Andrology and European Academy of Andrology.

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Auteurs

Virginie Barraud-Lange (V)

Université Paris Cité, Paris, France.
Department of Reproductive Biology CECOS, AP-HP. Center-Université Paris Cite. Cochin Hospital, Paris, France.

Nicolas Boissel (N)

Université Paris Cité, Paris, France.
Department of Hematology, Adolescents and Young Adults Unit, AP-HP. North-Université Paris Cité. Saint-Louis Hospital, Paris, France.

Anne-Sophie Gille (AS)

Université Paris Cité, Paris, France.
Department of Reproductive Biology CECOS, AP-HP. Center-Université Paris Cite. Cochin Hospital, Paris, France.

Camille Jean (C)

Université Paris Cité, Paris, France.
Department of Reproductive Biology CECOS, AP-HP. Center-Université Paris Cite. Cochin Hospital, Paris, France.

Leslie Sitbon (L)

Biomega-Bioclinic, Department Intercommunal Hospital of Créteil, Assisted Reproductive Biology, Créteil, France.

Benoit Schubert (B)

Eurofins Biomnis Laboratory, Institut Rhonalpin IVF Center, Clinique du Val d'Ouest, Ecully, France.

Karima Yakouben (K)

Department of Pediatric Immunology and Hematology, APHP. North-Université Paris Cité. Robert Debré Hospital, Paris, France.

Mony Fahd (M)

Department of Pediatric Immunology and Hematology, APHP. North-Université Paris Cité. Robert Debré Hospital, Paris, France.

Matthieu Peycelon (M)

Université Paris Cité, Paris, France.
Department of Pediatric Surgery and Urology, Centre de Référence des Malformations Rares des Voies Urinaires (MARVU), Inserm UMR 1141 NeuroDev, APHP. North-Université Paris Cité. Robert-Debré Hospital, Paris, France.

Annabel Paye-Jaouen (A)

Department of Pediatric Surgery and Urology, Centre de Référence des Malformations Rares des Voies Urinaires (MARVU), Inserm UMR 1141 NeuroDev, APHP. North-Université Paris Cité. Robert-Debré Hospital, Paris, France.

Céline Chalas (C)

Department of Reproductive Biology CECOS, AP-HP. Center-Université Paris Cite. Cochin Hospital, Paris, France.

Alexis Vanhaesebrouck (A)

Interdisciplinary Research Institute on Social issues (IRIS), UMR 8156-997, Sorbonne Paris North University, Aubervilliers, France.
Department of Legal and Social Medicine, AP-HP, Jean-Verdier Hospital, Bondy, France.
Department of Social Epidemiology, Sorbonne University, INSERM, Pierre Louis Institute of Epidemiology and Public Health, Paris, France.

François Doz (F)

Université Paris Cité, Paris, France.
Curie Institute, SIREDO Center (Care, Innovation, Research in Pediatric, Adolescent and Young Adult Oncology, Paris, France.

Aurore Surun (A)

Curie Institute, SIREDO Center (Care, Innovation, Research in Pediatric, Adolescent and Young Adult Oncology, Paris, France.

Lauriane Lemelle (L)

Curie Institute, SIREDO Center (Care, Innovation, Research in Pediatric, Adolescent and Young Adult Oncology, Paris, France.

Sabine Sarnacki (S)

Université Paris Cité, Paris, France.
Department of Visceral and Urological Pediatric Surgery, AP-HP. Center-Université Paris Cité. Necker Hospital, Paris, France.

Bénédicte Neven (B)

Université Paris Cité, Paris, France.
Department of Immuno-Hematology and Pediatric Rheumatology, APHP. Center-Université Paris Cité. Necker-Enfant Malades Hospital, Paris, France.

Pascale Philippe-Chomette (P)

AP-HP. North-Université Paris Cité, Paris, France.

Christelle Dufour (C)

Department of Pediatric Oncology, Gustave Roussy Institute, Villejuif, France.

Charlotte Rigaud (C)

Department of Pediatric Oncology, Gustave Roussy Institute, Villejuif, France.

Guy Leverger (G)

Sorbonne University, Paris, France.
Department of Pediatric Onco-Hematology, AP-HP. Sorbonne University. Armand Trousseau Hospital, Paris, France.

Marie-Dominique Tabone (MD)

Department of Pediatric Onco-Hematology, AP-HP. Sorbonne University. Armand Trousseau Hospital, Paris, France.

Sabine Irtan (S)

Sorbonne University, Paris, France.
Department of Pediatric Surgery, AP-HP. Sorbonne University. Armand Trousseau Hospital, Paris, France.

Corinne Pondarée (C)

Pediatric Department Sickle Cell Referral Center, Intercommunal Hospital of Créteil, Créteil, France.
University Paris XII, INSERM U 955, Créteil, France.

Harry Lezeau (H)

Department of Visceral, Urological and Traumatological Surgery, Intercommunal Hospital of Créteil, Créteil, France.

Gilles Lenaour (G)

Sorbonne University, Paris, France.

Mathilde Sibony (M)

Université Paris Cité, Paris, France.
Department of Pathology, AP-HP. Center-Université Paris Cité. Cochin Hospital, Paris, France.

Eva Comperat (E)

Sorbonne University, Paris, France.
Department of Pathology, AP-HP. Sorbonne University. Pitié-Salpêtrière Hospital, Paris, France.

Isabelle Brocheriou (I)

Sorbonne University, Paris, France.
Department of Pathology, AP-HP. Sorbonne University. Pitié-Salpêtrière Hospital, Paris, France.

Jean Philippe Wolf (JP)

Université Paris Cité, Paris, France.
Department of Reproductive Biology CECOS, AP-HP. Center-Université Paris Cite. Cochin Hospital, Paris, France.

Jean-Hugue Dalle (JH)

Université Paris Cité, Paris, France.
Department of Pediatric Immunology and Hematology, APHP. North-Université Paris Cité. Robert Debré Hospital, Paris, France.

Catherine Poirot (C)

Department of Reproductive Biology CECOS, AP-HP. Center-Université Paris Cite. Cochin Hospital, Paris, France.
Department of Hematology, Adolescents and Young Adults Unit, AP-HP. North-Université Paris Cité. Saint-Louis Hospital, Paris, France.
Sorbonne University, Paris, France.

Classifications MeSH