Changes in brain structure in subjects with resistance to thyroid hormone due to THRB mutations.

Diffusion tensor imaging Resistance to thyroid hormone Thyroid hormone receptor beta voxel based morphometry

Journal

Thyroid research
ISSN: 1756-6614
Titre abrégé: Thyroid Res
Pays: England
ID NLM: 101469037

Informations de publication

Date de publication:
06 Nov 2023
Historique:
received: 02 05 2023
accepted: 26 07 2023
medline: 18 8 2023
pubmed: 18 8 2023
entrez: 17 8 2023
Statut: epublish

Résumé

Being critical for brain development and neurocognitive function thyroid hormones may have an effect on behaviour and brain structure. Our exploratory study aimed to delineate the influence of mutations in the thyroid hormone receptor (TR) ß gene on brain structure. High-resolution 3D T1-weighted images were acquired in 21 patients with a resistance to thyroid hormone ß (RTHß) in comparison to 21 healthy matched-controls. Changes in grey and white matter, as well as cortical thickness were evaluated using voxel-based morphometry (VBM) and diffusion tensor imaging (DTI). RTHß patients showed elevated circulating fT4 & fT3 with normal TSH concentrations, whereas controls showed normal thyroid hormone levels. RTHß patients revealed significantly higher scores in a self-rating questionnaire for attention deficit hyperactivity disorder (ADHD). Imaging revealed alterations of the corticospinal tract, increased cortical thickness in bilateral superior parietal cortex and decreased grey matter volume in bilateral inferior temporal cortex and thalamus. RTHb patients exhibited structural changes in multiple brain areas. Whether these structural changes are causally linked to the abnormal behavioral profile of RTHß which is similar to ADHD, remains to be determined.

Sections du résumé

BACKGROUND BACKGROUND
Being critical for brain development and neurocognitive function thyroid hormones may have an effect on behaviour and brain structure. Our exploratory study aimed to delineate the influence of mutations in the thyroid hormone receptor (TR) ß gene on brain structure.
METHODS METHODS
High-resolution 3D T1-weighted images were acquired in 21 patients with a resistance to thyroid hormone ß (RTHß) in comparison to 21 healthy matched-controls. Changes in grey and white matter, as well as cortical thickness were evaluated using voxel-based morphometry (VBM) and diffusion tensor imaging (DTI).
RESULTS RESULTS
RTHß patients showed elevated circulating fT4 & fT3 with normal TSH concentrations, whereas controls showed normal thyroid hormone levels. RTHß patients revealed significantly higher scores in a self-rating questionnaire for attention deficit hyperactivity disorder (ADHD). Imaging revealed alterations of the corticospinal tract, increased cortical thickness in bilateral superior parietal cortex and decreased grey matter volume in bilateral inferior temporal cortex and thalamus.
CONCLUSION CONCLUSIONS
RTHb patients exhibited structural changes in multiple brain areas. Whether these structural changes are causally linked to the abnormal behavioral profile of RTHß which is similar to ADHD, remains to be determined.

Identifiants

pubmed: 37592301
doi: 10.1186/s13044-023-00176-2
pii: 10.1186/s13044-023-00176-2
pmc: PMC10433577
doi:

Types de publication

Journal Article

Langues

eng

Pagination

34

Informations de copyright

© 2023. BioMed Central Ltd., part of Springer Nature.

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Auteurs

Berenike Rogge (B)

Department of Neurology, University of Lübeck, Ratzeburger Allee 160, 23538, Lübeck, Germany.

Marcus Heldmann (M)

Department of Neurology, University of Lübeck, Ratzeburger Allee 160, 23538, Lübeck, Germany.
Department of Psychology II, University of Lübeck, Lübeck, Germany.

Krishna Chatterjee (K)

Wellcome-MRC Institute of Metabolic Science, University of Cambridge, Cambridge, UK.

Carla Moran (C)

Beacon Hospital, Dublin, Ireland.
St Vincent's University Hospital, Dublin, Ireland.
School of Medicine, University College Dublin, Dublin, Ireland.

Martin Göttlich (M)

Department of Psychology II, University of Lübeck, Lübeck, Germany.

Jan Uter (J)

Department of Neurology, University of Lübeck, Ratzeburger Allee 160, 23538, Lübeck, Germany.

Tobias A Wagner-Altendorf (TA)

Department of Neurology, University of Lübeck, Ratzeburger Allee 160, 23538, Lübeck, Germany.

Julia Steinhardt (J)

Department of Neurology, University of Lübeck, Ratzeburger Allee 160, 23538, Lübeck, Germany.

Georg Brabant (G)

Department of Internal Medicine I, University of Lübeck, Lübeck, Germany.

Thomas F Münte (TF)

Department of Neurology, University of Lübeck, Ratzeburger Allee 160, 23538, Lübeck, Germany.
Department of Psychology II, University of Lübeck, Lübeck, Germany.

Anna Cirkel (A)

Department of Neurology, University of Lübeck, Ratzeburger Allee 160, 23538, Lübeck, Germany. anna.cirkel@neuro.uni-luebeck.de.

Classifications MeSH