Paraneoplastic pemphigus/paraneoplastic autoimmune multiorgan syndrome: Part I. clinical overview and pathophysiology.

CLL Castleman disease bronchiolitis obliterans non-Hodgkin lymphoma paraneoplastic paraneoplastic autoimmune multiorgan syndrome paraneoplastic pemphigus pemphigus plakin

Journal

Journal of the American Academy of Dermatology
ISSN: 1097-6787
Titre abrégé: J Am Acad Dermatol
Pays: United States
ID NLM: 7907132

Informations de publication

Date de publication:
17 Aug 2023
Historique:
received: 24 03 2023
revised: 24 07 2023
accepted: 07 08 2023
pubmed: 20 8 2023
medline: 20 8 2023
entrez: 19 8 2023
Statut: aheadofprint

Résumé

Paraneoplastic pemphigus/paraneoplastic autoimmune multiorgan syndrome (PNP/PAMS) is a highly fatal autoimmune blistering disease. The condition occurs in patients with underlying benign or malignant neoplasms, most commonly lymphoproliferative disorders. Both humoral and cell-mediated immunities contribute to the pathogenesis, and autoantibodies against plakin family proteins are characteristic. Patients typically present with severe stomatitis and polymorphous skin lesions, which are often resistant to treatment. Bronchiolitis obliterans (BO) is a frequent complication which contributes to the high mortality rate of PNP/PAMS. Given the rarity of this disorder and heterogeneity of clinical presentation, clinicians should maintain a high index of suspicion for PNP/PAMS to avoid delayed diagnosis. In this first part of a two-part continuing medical education (CME) series, risk factors, pathogenesis, and clinical features of PNP/PAMS are discussed.

Identifiants

pubmed: 37597771
pii: S0190-9622(23)02512-4
doi: 10.1016/j.jaad.2023.08.020
pii:
doi:

Types de publication

Journal Article Review

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

Copyright © 2023 American Academy of Dermatology, Inc. Published by Elsevier Inc. All rights reserved.

Déclaration de conflit d'intérêts

Conflicts of interest None disclosed.

Auteurs

Hannah J Anderson (HJ)

Department of Dermatology, Thomas Jefferson University, Philadelphia, Pennsylvania.

Simo Huang (S)

Department of Dermatology, Thomas Jefferson University, Philadelphia, Pennsylvania.

Jason B Lee (JB)

Department of Dermatology, Thomas Jefferson University, Philadelphia, Pennsylvania. Electronic address: jason.lee@jefferson.edu.

Classifications MeSH