Pseudocystic inflammatory demyelinating lesions in multiple sclerosis: A clinical, radiological, and pathological description.

MRI Pseudocystic lesions atypical inflammatory demyelinating lesions histopathology multiple sclerosis tumefactive demyelinating lesions

Journal

Multiple sclerosis (Houndmills, Basingstoke, England)
ISSN: 1477-0970
Titre abrégé: Mult Scler
Pays: England
ID NLM: 9509185

Informations de publication

Date de publication:
09 2023
Historique:
medline: 15 9 2023
pubmed: 25 8 2023
entrez: 25 8 2023
Statut: ppublish

Résumé

Pseudocystic inflammatory demyelinating lesions (PIDLs) are poorly described in MS and might represent a diagnostic challenge. We described the clinical, radiological, pathological, and follow-up characteristics of 13 PIDL in 9 MS patients. We constituted a single-center retrospective case series of PIDLs in MS, defined on MRI as expansive cyst-like lesions, with a fluid-signal content, and a diameter of 1 cm or more. PIDL often occurred at first event (56%), were often asymptomatic (69%), and encircled by a hypo-T2 diffusion-restricted rim and a thin ring-like gadolinium enhancement (100%) on magnetic resonance imaging (MRI). Associated typical MS lesions were constant. Biopsies from two PIDLs displayed classical features of active MS, except for unusual edema. PIDLs are clinically unremarkable and associated with a good outcome. Their easily recognizable MRI features could help avoid biopsy.

Sections du résumé

BACKGROUND
Pseudocystic inflammatory demyelinating lesions (PIDLs) are poorly described in MS and might represent a diagnostic challenge.
OBJECTIVES
We described the clinical, radiological, pathological, and follow-up characteristics of 13 PIDL in 9 MS patients.
METHODS
We constituted a single-center retrospective case series of PIDLs in MS, defined on MRI as expansive cyst-like lesions, with a fluid-signal content, and a diameter of 1 cm or more.
RESULTS
PIDL often occurred at first event (56%), were often asymptomatic (69%), and encircled by a hypo-T2 diffusion-restricted rim and a thin ring-like gadolinium enhancement (100%) on magnetic resonance imaging (MRI). Associated typical MS lesions were constant. Biopsies from two PIDLs displayed classical features of active MS, except for unusual edema.
CONCLUSION
PIDLs are clinically unremarkable and associated with a good outcome. Their easily recognizable MRI features could help avoid biopsy.

Identifiants

pubmed: 37622206
doi: 10.1177/13524585231193345
doi:

Substances chimiques

Contrast Media 0
Gadolinium AU0V1LM3JT

Types de publication

Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

1340-1344

Auteurs

Florent Cluse (F)

Service de Neurologie, Sclérose en Plaques, Pathologies de la Myéline et Neuro-inflammation, Hôpital Pierre Wertheimer, Hospices Civils de Lyon, Bron, France.
Electroneuromyography and Neuromuscular Diseases Unit, Hôpital Pierre Wertheimer, Hospices Civils de Lyon, Bron, France.

Tanguy Fenouil (T)

Institut de Pathologie Multisite-Site Est, Groupement Hospitalier Est, Hospices Civils de Lyon, Bron, France.

Sandra Vukusic (S)

Service de Neurologie, Sclérose en Plaques, Pathologies de la Myéline et Neuro-inflammation, Hôpital Pierre Wertheimer, Hospices Civils de Lyon, Bron, France.
Observatoire Français de la Sclérose en Plaques, Centre de Recherche en Neurosciences de Lyon, Lyon, France.
Université de Lyon, Université Claude Bernard Lyon 1, Lyon, France.
Eugène Devic EDMUS Foundation against Multiple Sclerosis, State-Approved Foundation, Bron, France.

François Ducray (F)

Service de Neuro-oncologie, Hôpital Pierre Wertheimer, Hospices Civils de Lyon, Bron, France.

François Cotton (F)

Service de Radiologie, Centre Hospitalier Lyon-Sud, Hospices Civils de Lyon, Pierre-Bénite, France.
Creatis-LRMN, CNRS UMR 5220, Inserm U630, Université Claude Bernard Lyon 1, Villeurbanne, France.

Romain Marignier (R)

Service de Neurologie, Sclérose en Plaques, Pathologies de la Myéline et Neuro-inflammation, Hôpital Pierre Wertheimer, Hospices Civils de Lyon, Bron, France.
Université de Lyon, Université Claude Bernard Lyon 1, Lyon, France.

Françoise Durand-Dubief (F)

Service de Neurologie, Sclérose en Plaques, Pathologies de la Myéline et Neuro-inflammation, Hôpital Pierre Wertheimer, Hospices Civils de Lyon, Bron, France.
Université de Lyon, Université Claude Bernard Lyon 1, Lyon, France.

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Classifications MeSH