Rapid Resolution of Life-Threatening Hypertriglyceridemia after Evinacumab Administration in a Pediatric HSCT Recipient: A Case Report.
ANGPTL3-inhibitors
dyslipidemia
evinacumab
hypertriglyceridemia
lipid-lowering drugs
Journal
Pharmaceuticals (Basel, Switzerland)
ISSN: 1424-8247
Titre abrégé: Pharmaceuticals (Basel)
Pays: Switzerland
ID NLM: 101238453
Informations de publication
Date de publication:
27 Jul 2023
27 Jul 2023
Historique:
received:
09
07
2023
revised:
21
07
2023
accepted:
22
07
2023
medline:
26
8
2023
pubmed:
26
8
2023
entrez:
26
8
2023
Statut:
epublish
Résumé
Evinacumab, a human monoclonal antibody against angiopoietin-like protein 3 (ANGPTL3), has recently been approved by the U.S. Food and Drug Administration as an add-on therapy for homozygous familial hypercholesterolemia (HoFH) in patients of 12 years and older. Its role as a triglyceride-lowering drug is also emerging in the literature. However, it has not been approved for this indication yet, neither in the adult nor in the pediatric population. We describe the case of a 10-year-old boy who underwent an allogeneic hematopoietic stem cell transplant for acute lymphoblastic leukemia complicated by chronic graft-versus-host disease (GVHD) and presented life-threatening refractory hypertriglyceridemia due to the concomitant use of ruxolitinib and sirolimus. After the failure of the insulin treatment and due to the technical impossibility of performing lipid apheresis, the child underwent evinacumab treatment, obtaining a dramatic rapid reduction in triglyceride and cholesterol levels. This is the first report of a pediatric patient younger than 12 years in Europe receiving evinacumab to treat severe hypertriglyceridemia. The therapy with angiopoietin-like proteins inhibitors has been effective, safe, and well-tolerated in our patient, suggesting that evinacumab may be used in the pediatric population when other therapeutic strategies are ineffective or contraindicated.
Identifiants
pubmed: 37630982
pii: ph16081069
doi: 10.3390/ph16081069
pmc: PMC10457918
pii:
doi:
Types de publication
Case Reports
Langues
eng
Références
J Clin Endocrinol Metab. 2012 Sep;97(9):2969-89
pubmed: 22962670
Ther Adv Hematol. 2018 Jan;9(1):21-46
pubmed: 29317998
Nat Med. 2023 Mar;29(3):729-737
pubmed: 36879129
Bone Marrow Transplant. 2019 Aug;54(8):1372-1373
pubmed: 30804487
Curr Vasc Pharmacol. 2014;12(4):598-616
pubmed: 23627980
Curr Atheroscler Rep. 2022 Apr;24(4):265-275
pubmed: 35107763
Circulation. 2019 Aug 6;140(6):470-486
pubmed: 31242752
Endocrine. 2016 May;52(2):187-93
pubmed: 26754661
Bone Marrow Transplant. 2021 Jan;56(1):38-49
pubmed: 32587336
Clin Lymphoma Myeloma Leuk. 2015 Apr;15(4):214-221.e1
pubmed: 25682576
Nurse Pract. 2018 Oct;43(10):22-29
pubmed: 30153192
N Engl J Med. 2017 Jul 20;377(3):211-221
pubmed: 28538136
N Engl J Med. 2017 Dec 28;377(26):2565-2579
pubmed: 29281578
Pharmaceuticals (Basel). 2022 Nov 11;15(11):
pubmed: 36422519
Drugs. 2021 Jun;81(9):1101-1105
pubmed: 34003472
Circulation. 2019 Jun 18;139(25):e1046-e1081
pubmed: 30565953
Nephrol Dial Transplant. 2021 Mar 29;36(4):587-593
pubmed: 31891401
Handb Exp Pharmacol. 2022;272:337-348
pubmed: 34697665
Ann Transplant. 2008;13(2):46-53
pubmed: 18566560
Am J Physiol Endocrinol Metab. 2009 Aug;297(2):E271-88
pubmed: 19318514
Biosci Rep. 2019 Feb 22;39(2):
pubmed: 30737303
Case Rep Transplant. 2018 Nov 4;2018:4539757
pubmed: 30519495